Surgical Case Reports最新文献

{"title":"Thoracoscopic Congenital Esophageal Stenosis Repair and Thal Fundoplication by Right Thoracic Approach: A Case Report.","authors":"Kazuya Nagayabu, Wataru Sumida, Kazuki Ota, Yasuyuki Ono","doi":"10.70352/scrj.cr.24-0180","DOIUrl":"https://doi.org/10.70352/scrj.cr.24-0180","url":null,"abstract":"<p><strong>Introduction: </strong>Congenital esophageal stenosis (CES) is a rare clinical condition found in 1 in 25000-50000 live births. Surgical treatment is required when endoscopic balloon dilatation is ineffective. Laparoscopic and thoracoscopic approaches are selected based on lesion location. Gastroesophageal reflux (GER) is often observed as a postoperative complication that necessitates additional fundoplication. We report a case of CES in the lower third of the esophagus that was treated with simultaneous thoracoscopic resection and Thal fundoplication using the right thoracic approach.</p><p><strong>Case presentation: </strong>The patient was a 6-month-old boy who presented with vomiting after consuming solid food. Although he had been previously treated by a physician, he was referred to our hospital for further examination because of persistent symptoms at 1 year and 7 months of age. As his oral intake was insufficient, he was thin compared with his twin brother. On esophagography, an abruptly narrowing lesion was found at the Th9-10 level, and congenital esophageal stenosis was diagnosed. Since balloon dilatation under upper gastrointestinal endoscopy was ineffective, the patient was treated surgically. Thoracoscopic esophagectomy (end-to-end anastomosis) and fundoplication (Thal procedure) were simultaneously performed via the right thoracic cavity. Although transient postoperative gastric paresis due to vagus nerve injury was observed, the patient improved with medical treatment and was discharged on postoperative day 14. He is currently able to ingest solid food orally, without GER.</p><p><strong>Conclusions: </strong>CES can be a surgical indication for a thoracoscopic approach, depending on the site of the lesion. This is the first case in which anti-reflux surgery was performed simultaneously with thoracoscopic CES repair. We consider that this technique is useful for preventing not only GER, but also anastomotic leakage.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11982622/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144039610","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Left S3 + S8 Segmentectomy with Rare Interlobar A3 Vascular Anomaly: A Case Report.","authors":"Hiroki Imabayashi, Takahide Toyoda, Kazuhisa Tanaka, Yuki Sata, Terunaga Inage, Hajime Tamura, Masako Chiyo, Yukiko Matsui, Hidemi Suzuki","doi":"10.70352/scrj.cr.24-0013","DOIUrl":"https://doi.org/10.70352/scrj.cr.24-0013","url":null,"abstract":"<p><strong>Introduction: </strong>Segmentectomy is being accepted as a valid operative procedure for small peripheral non-small cell lung cancer. Understanding pulmonary artery (PA) variations is essential to ensure safe and reliable surgeries. Herein, we report a case of left S3 and S8 segmentectomy involving a complete interlobar branch of the left A3, a relatively rare anomaly reported in less than 0.56% of cases in previous studies.</p><p><strong>Case presentation: </strong>A woman in her sixties was referred to our hospital with two nodules in the left upper lobe anterior segment (S3, 1.1 × 0.8 cm) and the lower lobe anterior basal segment (S8, 1.8 × 1.7 cm), suggestive of double primary lung cancer. Preoperative thin-slice computed tomography (CT) and three-dimensional CT revealed a vascular anomaly in which the entire left A3 branched from the interlobar PA. Left S3 and S8 segmentectomies were performed via thoracotomy. The interlobar A3 branched at nearly the same level as the A6. After cutting the V3b and V3c veins, the intersegmental plane and the interlobar A3 were sequentially divided using staplers. To prevent torsion of the remaining lung, the edges of the apico-posterior segment (S1+2) and the lingular segment were loosely secured with silk sutures. The operative times were 4 h and 8 min with minimal blood loss. Pathological examination revealed that both nodules were squamous cell carcinomas of the lungs (pT1bN0M0, pStage IA2). The patient remained recurrence-free for over 1 year.</p><p><strong>Conclusions: </strong>Complete interlobar branching of the left A3 is uncommon. During left S3 segmentectomy in cases involving an interlobar A3, the S1+2 and lingular segments may become solitary blocks, necessitating measures to prevent torsion.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC12055235/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144049249","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Primary Cardiac Myxofibrosarcoma: A Case Report.","authors":"Takuya Matsushiro, Tomoki Tamura, Tetsuya Horai, Kento Misumi, Nobuyuki Inoue","doi":"10.70352/scrj.cr.24-0035","DOIUrl":"https://doi.org/10.70352/scrj.cr.24-0035","url":null,"abstract":"<p><strong>Introduction: </strong>Primary cardiac tumors are rare, with malignant myxofibrosarcoma cases being particularly uncommon, while cardiac myxoma is a common diagnosis in clinical practice. We present a case of cardiac myxofibrosarcoma, whose clinical course was quite unusual.</p><p><strong>Case presentation: </strong>A 67-year-old woman with no prior history of cardiac tumors was admitted for dyspnea and was found to have a 60 mm tumor in the left atrium. Despite initial resection, the tumor recurred twice, and a subsequent pleural mass biopsy revealed metastasis of myxofibrosarcoma. Retrospective analysis confirmed that the pathological findings of all the resected tumors were consistent with myxofibrosarcoma. Chemotherapy with doxorubicin was initiated, but severe side effects led to its discontinuation. The tumors continued to grow, causing significant pain, and she passed away a year later.</p><p><strong>Conclusions: </strong>The differential diagnosis of cardiac myxofibrosarcoma is challenging due to its similarity to benign myxomas. Accurate diagnosis requires thorough histological and immunohistochemical evaluation is essential.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC12066236/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144027892","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Pneumatocele Development after Deceased-Donor Liver Transplantation for Multiple Hepatic Cysts due to Autosomal Dominant Polycystic Kidney Disease: A Case Report.","authors":"Atsushi Yoshiyama, Mitsuaki Kawashima, Sodai Nagata, Takahito Fukushima, Koji Aze, Yue Cong, Keita Nakao, Masayuki Nakao, Gouji Toyokawa, Chihiro Konoeda, Kiyoshi Hasegawa, Masaaki Sato","doi":"10.70352/scrj.cr.24-0005","DOIUrl":"10.70352/scrj.cr.24-0005","url":null,"abstract":"<p><strong>Introduction: </strong>A pneumatocele is a cystic change in the lung that can develop as a sequelae of infection, inflammation, positive-pressure ventilation, thoracic trauma, and rarely after lung resection. Pneumatocele development triggered by an extrathoracic etiology is rare. Herein, we report a case of a pneumatocele that developed after a deceased-donor liver transplantation.</p><p><strong>Case presentation: </strong>A 57-year-old woman with a diagnosis of autosomal dominant polycystic kidney disease underwent deceased-donor liver transplantation for polycystic liver disease. She did not have any background lung disease, although her right lower lobe was mostly atelectatic due to a remarkably elevated diaphragm. The liver transplant itself was uneventful. A small hole was made in the right diaphragm during the dissection of the liver, but it was successfully repaired without any injury to the lung. On postoperative day 1, the chest radiograph revealed a round hypertranslucency on the right side, which was initially considered subphrenic air retention, and no further evaluation was made at that time. Given that the hypertranslucency persisted, follow-up computed tomography was performed on postoperative day 18, and revealed an air-fluid level above the diaphragm in the right thoracic cavity. Thoracoscopic investigation revealed an intrathoracic hematoma within a pneumatocele in the right lower lobe, which was not detected in the pretransplant computed tomography. The hematoma was removed, and the pneumatocele was resected.</p><p><strong>Conclusions: </strong>We experienced a case of a pneumatocele that developed after deceased-donor liver transplantation for multiple hepatic cysts due to autosomal dominant polycystic kidney disease. Although the mechanisms are speculative, the pneumatocele might have been triggered by the sudden alleviation of the elevated diaphragm and reinflation of the atelectatic lung.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11937134/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143721311","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Adult Cystic Intestinal Duplication of the Ileum Laparoscopically Resected after Preoperative Diagnosis with Cine Magnetic Resonance Imaging and Abdominal Ultrasound: A Case Report.","authors":"Takashi Takeda, Katsuki Danno, Tadafumi Fukata, Itsuko Nakamichi, Kei Yamamoto, Masaya Higashiguchi, Kozo Noguchi, Takafumi Hirao, Mitsugu Sekimoto, Yoshio Oka","doi":"10.70352/scrj.cr.25-0015","DOIUrl":"10.70352/scrj.cr.25-0015","url":null,"abstract":"<p><strong>Introduction: </strong>Small bowel duplication in adults is an uncommon congenital anomaly that often presents with nonspecific symptoms, such as abdominal pain, vomiting, or constipation, which complicates diagnosis. Imaging techniques such as computed tomography (CT) and ultrasonography are commonly used, and cine magnetic resonance imaging (MRI) has emerged as a promising modality for diagnosing duplication cysts by capturing peristaltic movements. Surgical resection is the definitive treatment for preventing complications such as obstruction, infection, or malignant transformation.</p><p><strong>Case presentation: </strong>A woman in her thirties visited the emergency department with persistent lower abdominal pain. Physical examination and laboratory tests, including those for tumor markers, were unremarkable. CT revealed a cystic mass near the uterus, and pelvic MRI revealed a cystic lesion that had migrated during follow-up imaging. Cine MRI showed peristaltic movements within the lesion, and abdominal ultrasonography confirmed a cystic structure with wall movements resembling intestinal peristalsis. Based on these findings, the diagnosis of a noncommunicating small bowel duplication cyst was made.The patient underwent a laparoscopic single-port partial resection of the ileum. A cystic lesion located 75 cm proximal to the terminal ileum was excised along with a segment of the small intestine. Histopathological examination revealed a duplicated cyst lined with the small intestinal mucosa, confirming the diagnosis. The postoperative course was uneventful, and the patient was discharged 1 week postoperatively.</p><p><strong>Conclusion: </strong>This case highlights the utility of cine MRI and ultrasonography in the preoperative diagnosis of small bowel duplication cysts. In particular, cine MRI provides dynamic visualization of peristaltic movements within the cyst, enabling a confident diagnosis. The migration of the cyst observed on serial MRI examinations further corroborated the origin of this duplication. These findings emphasize the importance of advanced imaging modalities in the diagnosis of rare intestinal anomalies. Preoperative diagnosis of small bowel duplication cysts can be significantly enhanced by using cine MRI and ultrasonography to detect peristaltic movements. These modalities offer critical insights that aid timely surgical intervention and improve outcomes.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11973249/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143804009","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Sclerosing Angiomatoid Nodular Transformation of the Laparoscopically Resected Spleen: Case Reports and Review of the Literature.","authors":"Shingo Yamasaki, Hiroto Nishino, Takayuki Anazawa, Yuki Teramoto, Takahiro Nishio, Shoichi Kageyama, Kazuyuki Nagai, Yoichiro Uchida, Hironori Haga, Etsuro Hatano","doi":"10.70352/scrj.cr.24-0057","DOIUrl":"10.70352/scrj.cr.24-0057","url":null,"abstract":"<p><strong>Introduction: </strong>Most splenic tumors are benign; however, it is essential to differentiate them from malignant tumors, such as malignant lymphoma and metastatic tumors. Sclerosing angiomatoid nodular transformation (SANT) is a relatively rare benign tumor that has been reported recently. Splenectomy is performed in most cases of SANT because of the challenges associated with a definitive diagnosis. However, in some cases, SANT can be diagnosed through endoscopic ultrasound-guided fine-needle aspiration (EUS-FNA), and these cases are subsequently followed up. In this report, we present 2 cases of splenic SANT that underwent laparoscopic resection. In Case 1, atypical imaging findings required EUS-FNA for further evaluation. Case 2 exhibited typical imaging findings of SANT, and therefore, EUS-FNA was not performed.</p><p><strong>Case presentation: </strong>Case 1: A 47-year-old female was found to have a 26 mm tumor in the spleen on abdominal ultrasonography during follow-up for gallbladder polyps. Abdominal computed tomography (CT), magnetic resonance imaging (MRI), and positron emission tomography-CT were performed. EUS-FNA was performed because of the high surgical risk associated with pulmonary hypertension and because hemangioendothelioma, an intermediate malignancy, was suspected. Subsequently, laparoscopic splenectomy was performed, and SANT was diagnosed. Case 2: A 46-year-old female had an incidental detection of a tumor in the spleen on CT. SANT was suspected based on CT and MRI findings. Malignancy could not be completely ruled out owing to the gradual growth of the mass; therefore, the patient was referred to our hospital for surgery. Laparoscopic splenectomy was performed, and SANT was subsequently diagnosed.</p><p><strong>Conclusion: </strong>SANT is a benign tumor that is difficult to diagnose; however, in some cases, it can be diagnosed using EUS-FNA. We report 2 cases of SANT of the spleen that underwent laparoscopic resection. In cases where the diagnosis is confirmed through imaging or histological examination, disease management with follow-up and without surgery is a possible alternative.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11973248/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143804020","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"A Case of Induction Chemoimmunotherapy and Sleeve Lobectomy to Avoid Pneumonectomy for Central Squamous Cell Lung Cancer.","authors":"Ayaka Asakawa, Ryota Ishizawa, Yukitaka Sato, Yuya Ishikawa, Ryo Wakejima, Hironori Ishibashi, Kenichi Okubo","doi":"10.70352/scrj.cr.24-0069","DOIUrl":"10.70352/scrj.cr.24-0069","url":null,"abstract":"<p><strong>Introduction: </strong>Recently, neoadjuvant immunotherapy plus chemotherapy has been provided for patients with stage II-III resectable lung cancer. We report a case in which a pneumonectomy was avoided by administrating neoadjuvant chemoimmunotherapy.</p><p><strong>Case presentation: </strong>An 81-year-old man presented with a cough. Examination showed squamous cell lung cancer in the right lower lobe extending to the central side of the upper lobe, which would have required a pneumonectomy for complete resection. Neoadjuvant chemoimmunotherapy was administered to reduce the extent of pulmonary resection due to the patient's advanced age and impaired pulmonary function. Post-treatment examination showed tumor size reduction, and bronchoscopy showed disappearance of right upper bronchial erythema and persistent erythema of the bronchus intermedius. A sleeve right lower lobectomy was performed. Histopathological findings revealed complete resection of the cancerous lesion and a major pathological response.</p><p><strong>Conclusions: </strong>Sleeve lobectomy after preoperative chemoimmunotherapy for an elder patient with low pulmonary function was safe and efficient.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11879256/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143558039","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Long-Term Survival after Treatment with Induction Therapy and Surgery for Mediastinal Carcinoma of Unknown Primary.","authors":"Yasushi Sakamaki, Naoya Takada, Yuya Kogita, Nanami Hiraiwa","doi":"10.70352/scrj.cr.24-0011","DOIUrl":"10.70352/scrj.cr.24-0011","url":null,"abstract":"<p><strong>Introduction: </strong>Carcinoma of unknown primary (CUP) is rarely located in the mediastinum. Most cases are revealed to be metastatic lymph node carcinoma, which carries a poor prognosis. The optimal treatment for CUP confined to the mediastinum is yet to be established, and the long-term outcome of induction therapy in combination with surgery for mediastinal CUP is unclear.</p><p><strong>Case presentation: </strong>A 46-year-old man with no history of malignancy was diagnosed with anterior mediastinal adenocarcinoma through biopsy. The patient underwent chemoradiation for the tumor, which was initially suspected as invasive T4 lung cancer. After a favorable response to presurgical therapy, the tumor was deemed more likely a mediastinal tumor, and it was completely resected simultaneously with the thymus, the partial left lung, and the partial left innominate vein. The tumor contained histologic features identifiable as a lymph node tissue and lacked any thymic tissue, which led to the final diagnosis as metastatic lymph node adenocarcinoma; however, its origin was unknown. No signs of recurrence were detected for 13 years after surgery.</p><p><strong>Conclusions: </strong>Our case suggests that even patients with mediastinal CUP deemed an advanced disease can achieve long-term survival after undergoing induction therapy and definitive surgery.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11867736/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143524503","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"The Usefulness of Intraoperative Indocyanine Green Fluorescence Imaging in Surgical Treatment of Refractory Chylothorax in Pediatric Patients: A Case Report.","authors":"Kanji Ishizu, Kanta Araki, Koji Kagisaki, Hideto Ozawa","doi":"10.70352/scrj.cr.24-0112","DOIUrl":"10.70352/scrj.cr.24-0112","url":null,"abstract":"<p><strong>Introduction: </strong>Chylothorax is one of the complications in cardiovascular surgery. Although prolonged chylothorax leads to critical status and is associated with high mortality, its treatment has not been well established. We present a successful case of surgical treatment of chylothorax in a neonate using indocyanine green to identify the site of lymphatic leakage.</p><p><strong>Case presentation: </strong>The patient with complete atrioventricular septal defect, patent ductus arteriosus, pulmonary hypertension, and chromosomal abnormality with trisomy 21 underwent pulmonary artery banding and patent ductus arteriosus ligation through median sternotomy. The postoperative course was complicated with chylothorax; conservative treatment was not effective, so surgical treatment was selected. Indocyanine green was injected subcutaneously between the first and second toes on the left side 30 min before surgery to identify the site of leakage. We could detect the lymphatic leakage from the para-aortic lymph node by indocyanine green camera in the left thoracic cavity, and the leakage sites could be closed with interrupted sutures.</p><p><strong>Conclusion: </strong>Identification of lymphatic leakage sites using indocyanine green could be an effective technique in the surgical treatment of chylothorax in pediatric patients.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11850031/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143493538","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"A Unique Case of Intra-Abdominal Diffuse Lymphangiomatosis Mimicking a Pseudomyxoma Peritonei.","authors":"Andreas R R Weiss, Georg F Weber, Maximilian Brunner, Robert Grützmann, Abbas Agaimy, Christian Krautz","doi":"10.70352/scrj.cr.24-0037","DOIUrl":"10.70352/scrj.cr.24-0037","url":null,"abstract":"<p><strong>Introduction: </strong>Localized cystic lymphangiomas (CL) are rare benign tumors deriving from the lymphatic system. CL is diagnosed more frequently in children than in the adult population and, although commonly affecting the cervical and axillary regions, can develop in various parts of the body. Abdominal cystic lymphangioma (ACL) comprises less than 5% of all CL cases.</p><p><strong>Case presentation: </strong>A 35-year-old female patient with a history of benign appendectomy in childhood was transferred to our tertiary center for the operative management of a suspected extensive pseudomyxoma peritonei (PMP). In accordance with the multidisciplinary team discussion, cytoreductive surgery with hyperthermic intraperitoneal chemotherapy was planned. Intraoperatively, a typical \"jelly belly\" with high disease burden throughout the abdominal cavity and the small pelvis was found. A multi-visceral resection with complete cytoreduction (CCR 0) was performed. The postoperative histopathological findings revealed a diffuse, partially cystic lymphangiomatosis involving the peritoneum extensively without evidence of PMP or malignancy.</p><p><strong>Conclusions: </strong>ACLs are uncommon in the adult population, and diffuse peritoneal involvement is even rarer. Surgical management with complete resection is the preferred treatment option. Other benign cysts, as well as infectious diseases and malignancy, should be considered during the preoperative workup.</p>","PeriodicalId":22096,"journal":{"name":"Surgical Case Reports","volume":"11 1","pages":""},"PeriodicalIF":0.7,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11865471/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143524502","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}