Åsa Okhiria, Christina Persson, Monica Blom Johansson, Fatemeh Jabbari, Malin Hakelius, Daniel Nowinski
{"title":"How Cleft Type and Width Affect the Rate of Secondary Palatal Surgery and Articulation Proficiency in 5-Year-Olds With Cleft Palate.","authors":"Åsa Okhiria, Christina Persson, Monica Blom Johansson, Fatemeh Jabbari, Malin Hakelius, Daniel Nowinski","doi":"10.1177/10556656251340816","DOIUrl":"https://doi.org/10.1177/10556656251340816","url":null,"abstract":"<p><p>ObjectiveTo investigate the association of cleft type and width with the frequency of secondary palatal surgery, articulation, and velopharyngeal function (VPF).DesignA cross-sectional study.SettingA single multidisciplinary craniofacial team at a university hospital.Patients100 patients with a non-syndromic cleft lip and or soft and hard palate born between 2000 and 2015 and treated with a 2-stage palatoplasty. Twenty-one had cleft on the soft and hard palate (SHCP), 17 had bilateral cleft lip and palate (BCLP), and 62 had unilateral cleft lip and palate (UCLP).Main outcome measuresThe impact of cleft type and width on the rate of secondary palatal surgery, the percent of correct consonants (PCC), and PCC adjusted for age (PCC-A), and the composite score for velopharyngeal competence (VPC-Sum) at 5 years of age. Articulation errors were divided into cleft speech characteristics (CSCs) and developmental speech characteristics (DSCs), and the types of errors were compared between the groups.ResultsNeither cleft type nor cleft width was associated with the need for secondary palatal surgery or VPC-Sum. Cleft width but not cleft type was significantly associated with PCC and PCC-A. There were no significant differences between cleft types regarding CSCs or DSCs. The types of errors did not differ between cleft types.ConclusionsCleft width predicted PCC and PCC-A and should be included in analyses to identify factors that may impact different outcomes. Cleft type does not seem to be a reliable predictor.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251340816"},"PeriodicalIF":1.1,"publicationDate":"2025-05-14","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144081267","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Malin Schaar Johansson, Magnus Becker, Mia Stiernman, Kristina Klintö
{"title":"Velopharyngeal Competence in Children With Cleft Palate: Related Factors and Longitudinal Development.","authors":"Malin Schaar Johansson, Magnus Becker, Mia Stiernman, Kristina Klintö","doi":"10.1177/10556656251339880","DOIUrl":"https://doi.org/10.1177/10556656251339880","url":null,"abstract":"<p><p>ObjectiveTo identify factors associated with velopharyngeal competence at 10 years of age in children with cleft palate, and examine the longitudinal development of velopharyngeal competence.DesignRegistry-based cohort study.SettingRegional public care university hospitals in Sweden.ParticipantsA total of 507 children born with a cleft palate with or without cleft lip/alveolus.Main Outcome MeasuresVelopharyngeal competence according to speech language pathologists' ratings corresponding to the VPC-Rate with and without consideration of intervening secondary speech-improving surgery.ResultsChildren with additional conditions had significantly lower odds of velopharyngeal competence with no intervening speech-improving surgery than those without (OR 0.60, 95% CI 0.37-0.99). Children who had primary palatal surgery after 25 months of age (OR 0.23, 95% CI 0.11-0.49) or in more than 1 stage (OR 0.49, 95% CI 0.31-0.78), also had lower odds of a positive outcome, but these results may have been impacted by differences in cleft subtypes. Prevalence of velopharyngeal competence regardless of intervening surgery was 85% at age 5 years and 93% at age 10 years. For 17 children, velopharyngeal dysfunction emerged after 5 years of age.ConclusionsAdditional conditions were associated with decreased odds of velopharyngeal competence with no intervening surgery at 10 years of age. Whether primary palatal surgery performed late and in multiple stages also decreases odds of velopharyngeal competence should be investigated further. Prevalence of velopharyngeal competence increased from 5 to 10 years of age. Speech follow-up in children with cleft palate should continue until at least 10 years of age.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251339880"},"PeriodicalIF":1.1,"publicationDate":"2025-05-13","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144038991","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Management of Protruding Premaxilla in Bilateral Complete Cleft Lip and Palate Using an Intraoral Orthodontic Appliance: A Case Report.","authors":"Lingyu Zhang, Lanlei Wang","doi":"10.1177/10556656251340542","DOIUrl":"https://doi.org/10.1177/10556656251340542","url":null,"abstract":"<p><p>Protruding premaxilla is common in patients with bilateral cleft lip and palate. A 4-year-old patient with protruding premaxilla and an overjet of 10.3 mm following cleft lip repair was treated using an intraoral removable orthodontic appliance with intra-maxillary traction, supplemented by lip-closure exercises. After 2 months of treatment, the results demonstrated retracted premaxilla, reducing the anterior overjet to within normal limits, enhanced lip-closure at rest, and improved canine relationship and midline. The removable appliance yielded clinically satisfactory results for this patient, who had missed orthopedic treatments or exhibited suboptimal orthopedic outcomes during neonatal period.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251340542"},"PeriodicalIF":1.1,"publicationDate":"2025-05-13","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144055078","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Ashlie A Elver, Clay Thames, Nancy K Perry, Laura S Humphries, Ian C Hoppe
{"title":"Navigating Coding Challenges in Craniofacial Surgery: A National Survey Analysis on CPT Variability.","authors":"Ashlie A Elver, Clay Thames, Nancy K Perry, Laura S Humphries, Ian C Hoppe","doi":"10.1177/10556656251338640","DOIUrl":"https://doi.org/10.1177/10556656251338640","url":null,"abstract":"<p><p>ObjectiveAccurate current PROCEDURAL TERMINOLOGY (CPT) coding is essential to healthcare costs and fair reimbursement. In craniofacial (CF) surgery, specific codes for procedures like mandibular distraction and cranial remodeling are lacking, leading to unclear standards that may undervalue complex techniques. This study hypothesizes variability in billing exists and aims to characterize these trends.Design & SettingA 21-question survey was distributed via email.ParticipantsMembers of the American Society of Maxillofacial Surgeons and American Society of Craniofacial Surgeons.Main Outcomes MeasuresRespondents selected CPT codes for six clinical vignettes: mandibular distraction (MDO), fronto-orbital advancement (FOA), posterior vault distraction (PVD) & reconstruction (PVR), cranial springs (CS), and le fort III distraction (LFD). Details of training and practice environment were recorded. Chi-squared analysis compared trends.ResultsOf 338 recipients, 36 completed responses (10.7%). For MDO, 60.6% used orthopedic fixation codes (20690/92) with mandibular osteotomy. Temporalis flaps (15733) were billed separately by 23.5% when performed for FOA. Half of respondents billed for each distractor in MDO and PVD. Billing additional codes was more common in academia, fellowship-trained, integrated trained, and high-volume CF practices (<i>p</i>-values = .04, .001, .034, .036). Neurosurgical craniectomy codes were more common than cranioplasty codes for PVR, CS, and PVD.ConclusionsThis study reveals inconsistent billing practices among CF surgeons driven by insufficient CPT codes. Variable approaches to billing, influenced by training and practice backgrounds, risks undervaluation of CF services. Multidisciplinary efforts are needed to create a more robust billing system to ensure fair compensation and equitable delivery of CF care.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251338640"},"PeriodicalIF":1.1,"publicationDate":"2025-05-08","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144043942","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Jessica L Chee-Williams, Kelly N Cordero, Kari M Lien, Chelsea L Sommer, Natalie R Wombacher, Nancy J Scherer
{"title":"Can Hypernasality be Reliably Rated Using the American English Phrase Sample as a Part of the Cleft Audit Protocol for Speech-Augmented-Americleft Modification (CAPS-A-AM) Protocol?","authors":"Jessica L Chee-Williams, Kelly N Cordero, Kari M Lien, Chelsea L Sommer, Natalie R Wombacher, Nancy J Scherer","doi":"10.1177/10556656251339884","DOIUrl":"https://doi.org/10.1177/10556656251339884","url":null,"abstract":"<p><p><i>Background</i>The American English Phrase Sample is an alternative repetition stimulus that can be used as a part of the Cleft Audit Protocol for Speech-Augmented-Americleft Modification.<i>Problem</i>Reliability for rating hypernasality is unknown when the phrase sample is used.<i>Solution</i>Assessed intra- and interrater reliability for rating hypernasality.<i>What we did</i>Intrarater reliability was <i>k</i> = 0.76-0.91 and interrater reliability was <i>k</i> = 0.63-0.77. The phrase sample had the same reliability for rating hypernasality as the sentence sample.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251339884"},"PeriodicalIF":1.1,"publicationDate":"2025-05-08","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144055053","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Molly F MacIsaac, Javier F Quintana, Jamilla Vieux, JoAnn C DeRosa, S Alex Rottgers, Jordan N Halsey
{"title":"Streamlined Preoperative Evaluation of Velopharyngeal Dysfunction: A Single-Session Protocol for Speech MRI and Carotid MRA.","authors":"Molly F MacIsaac, Javier F Quintana, Jamilla Vieux, JoAnn C DeRosa, S Alex Rottgers, Jordan N Halsey","doi":"10.1177/10556656251338964","DOIUrl":"https://doi.org/10.1177/10556656251338964","url":null,"abstract":"<p><p>ObjectiveTo evaluate the feasibility and utility of a dual-imaging protocol integrating speech magnetic resonance imaging (MRI) and carotid magnetic resonance angiography (MRA) for assessment of velopharyngeal dysfunction (VPD).DesignProspective case series.SettingSingle tertiary care institution.PatientsSix pediatric patients with VPD.Main Outcome Measure(s)Image quality, velopharyngeal and vascular assessment, and impact on surgical decision-making.ResultsSpeech MRI consistently provided key velopharyngeal metrics, including levator veli palatini orientation and velopharyngeal gap size. Carotid MRA successfully mapped the vascular course, identifying one case of carotid medialization. Integration of both studies streamlined preoperative planning, influencing surgical technique selection and posterior pharyngeal flap design in cases with vascular anomalies.ConclusionA dual-imaging VPD protocol provides comprehensive anatomical and vascular data in a single nonsedated session. This approach enhances diagnostic accuracy, improves surgical planning, and reduces patient burden by eliminating the need for separate imaging sessions and repeated anesthesia exposure.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251338964"},"PeriodicalIF":1.1,"publicationDate":"2025-05-08","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144043943","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Amanda J Osborn, Rachel M Roberts, Diana S Dorstyn
{"title":"Psychosocial Support for Australian Families Impacted by Craniosynostosis: A Qualitative Study.","authors":"Amanda J Osborn, Rachel M Roberts, Diana S Dorstyn","doi":"10.1177/10556656251337824","DOIUrl":"https://doi.org/10.1177/10556656251337824","url":null,"abstract":"<p><p>ObjectiveFamilies impacted by a craniofacial condition have reported mixed experiences of psychosocial support; however, the experience of Australian parents is not yet known. The current study therefore explores the psychosocial experiences, and needs, of Australian parents whose child has been diagnosed with craniosynostosis.DesignQualitative data were obtained from 21 online narrative interviews with parents of children with non-syndromic and syndromic craniosynostosis. Interviews were transcribed and reflexive thematic analysis was used to generate themes.ResultsFour themes were developed: (1) communication and trust in clinical care; (2) challenges in health system processes and communication; (3) challenges and strengths of family support networks; and (4) absence of psychological support in the clinical journey.ConclusionsThere is a lack of psychosocial support provided to families living with craniosynostosis in Australia. Parents have requested that psychological assistance and related supports be readily provided as an aspect of standard, family-centered care.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251337824"},"PeriodicalIF":1.1,"publicationDate":"2025-05-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144038987","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Association Between Oral Microbiome in Children Undergoing Palatoplasty and Surgical Site Infection.","authors":"Suryakala Chandrasekaran, Swathi Sunil Rao, Vikram Shetty","doi":"10.1177/10556656251335181","DOIUrl":"10.1177/10556656251335181","url":null,"abstract":"<p><p>ObjectiveTo determine the prevalent preoperative oral microbial flora in children undergoing palatoplasty and its association with surgical site infection (SSI).DesignProspective observational longitudinal study.SettingSingle-center study done at tertiary care institute of Craniofacial surgery during the period of October 2022 to April 2024.ParticipantsThe study participants were the children posted for palatoplasty in our institution. Children with other major anomalies, immunodeficiency, and systemic illness were excluded. A total of 30 consecutive samples were enrolled during the study period, and all were followed up to finish the study.InterventionsSubgingival plaque samples were taken preoperatively and one postoperatively in the event of SSI and culture sensitivity analysis was done to detect pathogenic micro-organisms.Outcome measuresRisk analysis done for the baseline characteristics.ResultsMost common pathogenic organism seen preoperatively was <i>Streptococcus mitis</i> (34.8%) followed by <i>Klebsiella pneumoniae</i> (26%) and <i>Staphylococcus aureus</i> (26%). Bottle-fed children and those with preoperative infections had an adjusted odds ratio of 36.56 (<i>P</i> = .004) and 5.71 (<i>P</i> = .05), respectively, for colonization by pathogenic flora. The incidence of SSI was 25.8% in the population, with <i>K pneumoniae</i> as the most common cause (75%). The children who were underweight and had past hospital admission had an odds ratio of 16.67 (<i>P</i> = .002) and 10.2 (<i>P</i> = .009) for developing SSI.ConclusionWe conclude that bottle feeding and past infections play a role in colonization by pathogenic flora. <i>Klebsiella pneumoniae</i> is the common organism causing SSI, and nutrition status plays a role in development of SSI.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"10556656251335181"},"PeriodicalIF":1.1,"publicationDate":"2025-05-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144065127","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Alyssa B Valenti, Naikhoba Munabi, Chioma G Obinero, Michelle Demetres, Matthew R Greives, Thomas A Imahiyerobo
{"title":"\"Healthcare Disparities in the Care of Children with Craniosynostosis in the United States: A Systematic Review\".","authors":"Alyssa B Valenti, Naikhoba Munabi, Chioma G Obinero, Michelle Demetres, Matthew R Greives, Thomas A Imahiyerobo","doi":"10.1177/10556656231222318","DOIUrl":"10.1177/10556656231222318","url":null,"abstract":"<p><p>BackgroundHealthcare inequity is a pressing concern in pediatric populations with craniofacial conditions. Little is known about the barriers to care affecting children with craniosynostosis. This systematic review investigates disparities impacting care for children with craniosynostosis in the U.S.MethodsA comprehensive literature search was performed in the following databases from inception to December 2022: Ovid MEDLINE, Ovid EMBASE, and The Cochrane Library. Studies were screened for eligibility by two authors. All original articles that focused on disparities in access, treatment, or outcomes of craniosynostosis surgery were included. Studies describing disparities in other countries, those not written English, and review articles were excluded (Figure 1).ResultsAn initial database search revealed 607 citations of which 21 met inclusion criteria (Figure 1). All included studies were retrospective reviews of databases or cohorts of patients. The results of our study demonstrate that barriers to access in treatment for craniosynostosis disproportionally affect minority children, children of non-English speaking parents and those of lower socioeconomic status or with Medicaid. Black and Hispanic children, non-English speaking patients, and children without insurance or with Medicaid were more likely to present later for evaluation, ultimately undergoing surgery at an older age. These patients were also more likely to experience complications and require blood transfusions compared to their more privileged, white peers.ConclusionsThere is a discrepancy in treatment received by minority patients, patients with Medicaid, and those who are non-English speaking. Further research is needed to describe the specific barriers that prevent equitable care for these patients.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"744-753"},"PeriodicalIF":1.1,"publicationDate":"2025-05-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"138832599","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Kathleen A Kapp-Simon, Meredith Albert, Todd C Edwards, Salene M Jones, Claudia Crilly Bellucci, Janine Rosenberg, Donald L Patrick, Carrie L Heike
{"title":"Developmental Risk for Infants with Cleft Lip with or Without Cleft Palate Based on Caregiver-Proxy Reports.","authors":"Kathleen A Kapp-Simon, Meredith Albert, Todd C Edwards, Salene M Jones, Claudia Crilly Bellucci, Janine Rosenberg, Donald L Patrick, Carrie L Heike","doi":"10.1177/10556656231225304","DOIUrl":"10.1177/10556656231225304","url":null,"abstract":"<p><p>Objectives(1) Assess caregiver-reported development in infants born with cleft lip ± alveolus (CL ± A) and cleft lip and palate (CLP); (2) determine factors associated with increased developmental risk; and (3) determine consistency of developmental risk before and after surgery for cleft lip.DesignProspective, longitudinal assessment of development. Time (T) 1, prior to lip closure; T2, 2 months post lip closure.SettingThree US craniofacial teams and online parent support groups.Participants123 total caregivers (96% mothers); 100 at T1, 92 at T2, and 69 at both T1 and T2.MeasureAges and Stages Questionnaire-3 (ASQ-3): Communication, Gross Motor, Fine Motor, Problem Solving, Personal Social Domains.ResultsAt T1 47%; at T2 42% passed all 5 Domains; 36% of infants pass all 5 Domains at both T1 and T2. Infants with CLP were at greatest risk on Communication [<i>B</i> = 1.449 (CI = .149-20.079), <i>p</i> = .038; Odds Ratio (OR) = 4.3 (CI = .923-19.650)] and Gross Motor Domains [<i>B</i> = 1.753 (CI = .316-20.605), <i>p</i> = .034; OR = 5.8 (CI = 1.162-28.671)]. Male infants were at greatest risk on Fine Motor [<i>B</i> = 1.542 (CI = .495-20.005), <i>p</i> = .009; OR = 4.7 (CI = 1.278-17.101)] and Problem Solving Domains [<i>B</i> = 1.200 (CI = .118-19.708), <i>p</i> = .044; OR = 3.3 (CI = .896-12.285)].ConclusionsBased on caregiver report, infants with CL ± A and CLP meet referral criteria at a high rate. Infants with CLP and male infants were at greatest risk. Regular developmental screening is recommended.</p>","PeriodicalId":49220,"journal":{"name":"Cleft Palate-Craniofacial Journal","volume":" ","pages":"786-800"},"PeriodicalIF":1.1,"publicationDate":"2025-05-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11231059/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"139404882","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}