JOS Case ReportsPub Date : 2025-09-01Epub Date: 2025-03-16DOI: 10.1016/j.joscr.2025.02.001
Yuki Yoshida, Takeshi Ikegami
{"title":"Glenosphere dissociation combined with nonunion of a clavicular fracture following reverse shoulder arthroplasty","authors":"Yuki Yoshida, Takeshi Ikegami","doi":"10.1016/j.joscr.2025.02.001","DOIUrl":"10.1016/j.joscr.2025.02.001","url":null,"abstract":"<div><h3>Background</h3><div>Reverse shoulder arthroplasty (RSA) effectively improves outcomes for cuff tear arthropathy but carries a risk of complications. Glenosphere dissociation is a rare complication, and its occurrence with a shoulder girdle fracture has not been reported.</div></div><div><h3>Case presentation</h3><div>A 77-year-old female who had undergone RSA presented with chronic shoulder pain and a palpable mass. Imaging revealed glenosphere dissociation and clavicular nonunion with scapular malalignment. Surgical intervention included replacing the glenosphere and polyethylene liner, stabilizing the shoulder. Postoperative care involved sling immobilization, leading to pain relief and no recurrent dislocation despite limited functional recovery due to scapular malalignment.</div></div><div><h3>Conclusion</h3><div>We presented a rare case of glenosphere dissociation combined with clavicular nonunion following RSA. While pain relief was achieved by repairing the dislocation, clavicular nonunion contributing to scapular malalignment may hinder functional recovery. Surgical intervention for clavicular stabilization may be necessary in cases prioritizing shoulder function.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 83-86"},"PeriodicalIF":0.0,"publicationDate":"2025-09-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908444","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Nonunion of fourth metatarsal base stress fracture in athletes treated with locking plate fixation and iliac bone grafting: A three-case report","authors":"Shota Morimoto, Futoshi Morio, Toshiya Tachibana, Tomoya Iseki","doi":"10.1016/j.joscr.2024.08.003","DOIUrl":"10.1016/j.joscr.2024.08.003","url":null,"abstract":"<div><h3>Background</h3><div>Fourth metatarsal base stress fractures have been reported to cause complications, such as a substantial rate of delayed union and nonunion when treated nonoperatively. This report details three cases of nonunion of basal stress fractures of the fourth metatarsal in athletes who were successfully treated with a combination of locking plate fixation and iliac bone grafting.</div></div><div><h3>Case presentation</h3><div>Three male athletes presented with nonunion of fourth metatarsal base stress fracture and underwent surgical treatment. In all cases, the nonunion site was decorticated, and iliac cancellous bone was grafted to the nonunion site. The bone fragments were reduced in a correct bone alignment and fixed using a locking plate. All the athletes obtained bone union and returned to the original sport at 12 weeks postoperatively.</div></div><div><h3>Conclusions</h3><div>Surgical treatment combining locking plate fixation and iliac bone grafting for nonunion of a fourth metatarsal base stress fracture in athletes produced satisfactory results.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 44-47"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169677","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Chronic tibial osteomyelitis by Cutibacterium (Propionibacterium) acnes with characteristic imaging findings","authors":"Taiga Furukawa, Tomoaki Fukui, Yohei Kumabe, Ryosuke Kuroda, Keisuke Oe","doi":"10.1016/j.joscr.2024.11.002","DOIUrl":"10.1016/j.joscr.2024.11.002","url":null,"abstract":"<div><h3>Background</h3><div>Osteomyelitis caused by <em>Cutibacterium (Propionibacterium) acnes</em> (<em>C. acnes</em>) is rare, and there are no reports on the use of the Masquelet technique for its treatment.</div></div><div><h3>Case presentation</h3><div>A 21-year-old male patient visited a local hospital after spraining his left leg. Abnormal linear changes were noted on radiography and magnetic resonance imaging (MRI); however, the leg pain improved over time. Four years later, the patient was referred to our department because he experienced left leg pain again without any particular trigger, and a new linear lesion was found on imaging. Osteomyelitis was suspected. Curettage and filling with vancomycin-loaded bone cement were performed. Intraoperative tissue culture revealed <em>C. acnes</em>. Two months later, the cement was removed, and autologous iliac bone grafting was performed. Bony union was confirmed 5 months after the last surgery.</div></div><div><h3>Conclusion</h3><div>Osteomyelitis caused by <em>C. acnes</em> can show characteristic imaging findings.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 58-62"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169680","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Stress fracture of the talar body associated with talocalcaneal coalition in a female basketball player treated by a combination of osteosynthesis using screw fixation and resection of coalition: A case report","authors":"Shota Morimoto, Tomoya Iseki, Futoshi Morio, Toshiya Tachibana","doi":"10.1016/j.joscr.2024.08.001","DOIUrl":"10.1016/j.joscr.2024.08.001","url":null,"abstract":"<div><h3>Background</h3><div>This report details the case of a 15-year-female basketball player who was surgically treated for a stress fracture of the talar body associated with talocalcaneal coalition.</div></div><div><h3>Case presentation</h3><div>A 15-year-old female basketball player presented with a stress fracture of the talar body associated with a talocalcaneal coalition. <u>The patient underwent surgical treatment with a combination of osteosynthesis using screw fixation and resection of the coalition in hope to reducing the risk of refracture and ensuring her return to original sport.</u> At 12 weeks after the surgery, the bone union was achieved, and the patient was able to return to her original sport at her pre-injury level.</div></div><div><h3>Conclusions</h3><div>In conclusion, stress fractures of the talus associated with talocalcaneal coalition should be considered as a rare cause of atraumatic ankle pain. In addition, this surgical technique may be an effective option for stress fractures of the talus associated with talocalcaneal coalition.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 35-39"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169675","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Spinal meningeal melanocytoma with extensive dura mater pigmentation: Review of meningeal melanocytic tumors with GNAQ mutations","authors":"Kazumichi Yagura , Shu Takahashi , Kazuyuki Segami , Yusuke Oshita , Genshu Tate , Koji Kanzaki , Tomoaki Toyone , Yoshifumi Kudo","doi":"10.1016/j.joscr.2024.10.001","DOIUrl":"10.1016/j.joscr.2024.10.001","url":null,"abstract":"<div><h3>Background</h3><div>Meningeal melanocytoma is an extremely rare benign tumor. Although gross total resection of the tumor is the most effective therapy, consensus regarding the management of adjacent pigmented dura mater is lacking. Here, we present a case of meningeal melanocytoma with extensive dura mater pigmentation and discuss the importance of <em>GNAQ</em> mutations in making the diagnosis.</div></div><div><h3>Case presentation</h3><div>A 37-year-old woman presented with bilateral leg weakness. Magnetic resonance imaging revealed a thoracic intradural extramedullary mass. A solid blackish tumor wrapped in dark-pigmented dura mater was excised. No neoplasms were detected in the dura mater or on cerebrospinal fluid analysis. Genetic analysis revealed a <em>GNAQ</em> mutation. The mass was diagnosed as a meningeal melanocytoma. No recurrence was observed during 2 years of follow-up.</div></div><div><h3>Conclusions</h3><div>Histopathological analysis of the dura mater and cytological analysis of the cerebrospinal fluid is useful for deciding whether to administer adjuvant therapy.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 48-52"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169678","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Osteochondral fragment fixation for Freiberg's disease: A report of three cases","authors":"Ryo Fukagawa , Ichiro Yoshimura , Tomonobu Hagio , Tetsuro Ishimatsu , Yuki Sugino , Seiya Tomonaga , Yoshimasa Taniguchi , Takuaki Yamamoto","doi":"10.1016/j.joscr.2024.11.001","DOIUrl":"10.1016/j.joscr.2024.11.001","url":null,"abstract":"<div><h3>Background</h3><div>Freiberg's disease is characterized by osteonecrosis of the metatarsal head and is most common in teenage girls who play sports. Various treatment options are selected depending on the disease progression. When conservative measures fail, dorsiflexion osteotomy or osteochondral grafting are often performed. However, each approach has its drawbacks. Herein, we present three cases in which Freiberg's disease was effectively managed with osteochondral fragment fixation, circumventing the limitations associated with traditional treatment methods.</div></div><div><h3>Case presentation</h3><div>We describe three teenagers with Frieberg's disease who failed to respond to conservative treatment. The osteochondral fragment was stabilized using absorbable pins, thereby preserving the articular cartilage and maintaining the joint congruity. All three patients achieved substantial pain relief and functional improvement postoperatively.</div></div><div><h3>Conclusion</h3><div>Osteochondral fragment fixation is a promising alternative for the management of Freiberg's disease. This approach offers a valuable addition to the treatment armamentarium, providing patients with a minimally invasive yet effective solution for their condition.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 53-57"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169679","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Two cases of treatment of the seymour fracture complicated by pyogenic arthritis with antibiotic-impregnated calcium phosphate paste granules","authors":"Koki Hosozawa , Ryoichi Shibuya , Satoshi Miyamura , Toru Iwahashi , Takeshi Fuji","doi":"10.1016/j.joscr.2024.12.001","DOIUrl":"10.1016/j.joscr.2024.12.001","url":null,"abstract":"<div><h3>Background</h3><div>Seymour fractures are physeal fractures of the distal phalanx in children. These fractures are difficult to treat because they frequently lead to infections. We report two cases of Seymour fractures complicated by pyogenic arthritis, treated with vancomycin-impregnated paste granules of calcium phosphate cement, that showed good outcomes.</div></div><div><h3>Case presentation</h3><div>Two teenagers injured their fingers during rugby. They visited the outpatient clinic several days after the injury, presenting with purulent material discharge from the nail bed detachment. X-ray and MRI showed physeal fractures with associated inflammation, resulting in the diagnosis of Seymour fractures complicated by pyogenic arthritis and osteomyelitis. The wounds were irrigated and debrided, and the bone defect was filled with vancomycin-impregnated paste granules of calcium phosphate cement. While the growth plates closed prematurely, no recurrence of infection occurred.</div></div><div><h3>Conclusion</h3><div>In Seymour fractures complicated by pyogenic arthritis, vancomycin-impregnated paste granules of calcium phosphate cement are effective in controlling infection.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 63-66"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169589","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Lipoma arborescens and synovial chondromatosis with subacromial bursal effusion","authors":"Shu Yoshizawa, Hiroyasu Ikegami, Takanori Shintaku, Misato Sakamoto, Takahiro Maeda, Tomoyasu Honma, Yoshiro Musha, Hideaki Ishii","doi":"10.1016/j.joscr.2024.08.002","DOIUrl":"10.1016/j.joscr.2024.08.002","url":null,"abstract":"<div><h3>Background</h3><div>Lipoma arborescens (LA) is a disease in which mature adipose tissue grows within joints and bursae, predominantly in the knee joint, but rarely in other joints. In this paper, we report a case of synovial chondromatosis of the subacromial bursa diagnosed as LA.</div></div><div><h3>Case presentation</h3><div>A 74-year-old female patient had a mass in her right shoulder; MRI showed diffuse villous proliferation of the synovium within the subacromial bursa, and revealed a chemical shift artifact. We suspected LA and two nodules in the long head of the biceps tendon appeared to be chondromatosis. The surgery was performed and the subacromial bursa and nodules was removed. After histopathologic examination, a diagnosis of LA and synovial chondromatosis was made. Five years after surgery, there was no tumor recurrence.</div></div><div><h3>Conclusions</h3><div>LA can be diagnosed by MRI. Recognition of clinical and imaging findings is essential for early diagnosis and treatment.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 40-43"},"PeriodicalIF":0.0,"publicationDate":"2025-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169676","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Single-cell RNA profiling of the primary tumor and metastatic lymph node lesions in a patient with clear cell sarcoma of soft tissue: A case report","authors":"Yusuke Tsuda , Hiroyuki Okada , Kotoe Katayama , Toshihide Hirai , Jyunya Miyahara , Liuzhe Zhang , Yasunori Omata , Kasumi Abe , Yutaka Suzuki , Sakae Tanaka , Hiroshi Kobayashi","doi":"10.1016/j.joscr.2024.07.003","DOIUrl":"10.1016/j.joscr.2024.07.003","url":null,"abstract":"<div><h3>Background</h3><div>There was no report which evaluated the cellular constitution and cell–cell interactions in clear cell sarcoma of soft tissue.</div></div><div><h3>Case presentation</h3><div>A 47-year-old woman underwent surgical excision of clear cell sarcoma in right knee and inguinal lymph node metastasis after neo-adjuvant chemotherapy. However, she died due to liver and para-aortic lymph node metastasis. Single-cell RNA sequencing of the primary tumor and metastatic lymph node samples revealed the accumulation of <em>CTLA4</em><sup><em>+</em></sup><em>/CD4</em><sup><em>+</em></sup> regulatory and <em>LAG3</em><sup>+</sup>/<em>CD8</em><sup>+</sup> exhausted T cells particularly in the metastatic lymph node. NicheNet analysis indicated that these T cell states were induced by the interplay of T cells with tumor cells, macrophages, B cells, fibroblasts, and endothelial cell.</div></div><div><h3>Conclusions</h3><div>The cellular constitution of immune and stromal cell types and their properties suggested the presence of T cell immunosuppression in the clear cell sarcoma microenvironment.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 24-33"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141850463","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Atlantoaxial subluxation correction using the magerl and brooks techniques in patients with metatropic dysplasia: A report on a case involving siblings","authors":"Toshiyuki Ogata , Satoshi Suzuki , Yohei Takahashi , Satoshi Nori , Osahiko Tsuji , Narihito Nagoshi , Mitsuru Yagi , Kota Watanabe , Masaya Nakamura , Morio Matsumoto","doi":"10.1016/j.joscr.2024.06.004","DOIUrl":"10.1016/j.joscr.2024.06.004","url":null,"abstract":"<div><h3>Background</h3><div>Metatropic dysplasia (MD) is a form of skeletal dysplasia characterized by short limbs, stature, and kyphoscoliosis. Cervical instability and odontoid hypoplasia are reported as relatively common symptoms; however, surgical treatment is rarely reported. Although upper cervical spine surgery in pediatric patients is challenging because of their peculiar tissue biology, few studies have demonstrated the use of Magerl screws.</div></div><div><h3>Case presentation</h3><div>We describe two sibling cases that were successfully treated for atlantoaxial subluxation of MD using Magerl and Brooks techniques in which bone union of the vertebrae was achieved. C1–C2 fusion surgery for treating atlantoaxial subluxation in pediatric patients with MD is rare.</div></div><div><h3>Conclusions</h3><div>The present report is doubly remarkable by the unprecedented use of the Magerl and Brooks techniques and because the patients were siblings. The use of the Magerl and Brooks techniques achieved good efficacy, but careful consideration is required in the insertion of transarticular screws.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 5-9"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143487689","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}