{"title":"Tibial fracture arising from bone amyloidosis: A case study","authors":"Akane Yamamoto , Tomoaki Fukui , Takahiro Niikura , Kenichi Sawauchi , Masato Komatsu , Ryosuke Kuroda , Keisuke Oe","doi":"10.1016/j.joscr.2024.07.002","DOIUrl":"10.1016/j.joscr.2024.07.002","url":null,"abstract":"<div><h3>Background</h3><div>Amyloidosis, a disease characterized by the deposition of abnormal proteins in various organs, leads to functional disorders. Here, we report the case of a 63-year-old man with AL amyloid deposition in the tibial shaft that resulted in a tibial fracture.</div></div><div><h3>Case presentation</h3><div>Amyloid bone cysts typically occur in the joints and vertebrae of patients undergoing hemodialysis; however, in this case, the patient was not undergoing dialysis, and the deposition site was the tibial shaft. We performed curettage and osteosynthesis using a plate, and satisfactory patient recovery was observed at a 1.5-year postoperative follow-up.</div></div><div><h3>Conclusions</h3><div>Amyloidosis may cause functional impairment due to amyloid deposits in multiple organs and other complications; therefore, systemic examination is necessary.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 19-23"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141841727","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Anterior intraosseous arthroscopic treatment of talar chondroblastoma: A case report","authors":"Myongsu Ha , Kenjiro Wakabayashi , Hikotaro Umemura , Yukie Yakita , Masaki Hasegawa , Hiroki Yonezu , Yoshiaki Tsuboi , Hideki Murakami","doi":"10.1016/j.joscr.2024.06.003","DOIUrl":"10.1016/j.joscr.2024.06.003","url":null,"abstract":"<div><h3>Background</h3><div>Chondroblastoma is a rare benign bone tumor that accounts for 1–2% of all primary bone tumors. Typically, chondroblastoma occurs in the epiphysis of a long bone, and approximately 4 % of all chondroblastomas occur in the talus. The treatment of talar body chondroblastoma is challenging the talus is surrounded by the tibia, fibula, and other tarsal bones.</div></div><div><h3>Case presentation</h3><div>Here we report the case of a 15-year-old boy who developed chondroblastoma of the talar body. We performed tumor curetting, cancellous bone grafting, and β-tricalcium phosphate transplantation for using anterior intraosseous arthroscopy. The patient with no obvious recurrence 18 months after the surgery.</div></div><div><h3>Conclusion</h3><div>Arthroscopic treatment for tumors of the talar body is safe, provides good visibility, and is less invasive.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 1-4"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143487994","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Pediatric epithelioid haemangioma with intra- and exra-articular involvement around the hip joint: A case report","authors":"Masayuki Morishita , Makiko Yoshida , Shinichi Satsuma , Hitomi Kitamura , Azusa Yoneda , Izumi Komoto , Maki Kinugasa , Ryosuke Sakata , Daisuke Kobayashi","doi":"10.1016/j.joscr.2024.06.005","DOIUrl":"10.1016/j.joscr.2024.06.005","url":null,"abstract":"<div><h3>Background</h3><div>Intra-articular tumors of the hip are rare in pediatric patients, often leading to delayed diagnosis and mismanagement. Improved imaging techniques have enhanced detection. However, differentiating benign from malignant tumors remains challenging. Additionally, managing these tumors in children require considering the impact on growth and long-term functions.</div></div><div><h3>Case presentation</h3><div>A 6-year-old boy presented with right lower extremity pain that worsened after a fall. Radiographs revealed cortical irregularities in the greater trochanter and the medial calcar of the femur. Magnetic resonance imaging showed irregular masses, and an incisional biopsy confirmed epithelioid haemangioma (EH). Post-biopsy, the patient's hip pain improved despite residual limping, avoiding further surgery.</div></div><div><h3>Conclusion</h3><div>This pediatric EH case emphasizes the importance of accurate diagnosis and tailored treatment in rare cases. Although partial resection improved symptoms, continued monitoring is vital due to the unpredictability of pediatric EH. Genetic analysis can potentially enhance diagnostic accuracy in future cases.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 14-18"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141851159","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2025-03-01Epub Date: 2024-07-14DOI: 10.1016/j.joscr.2024.07.001
Hiroki Fujita , Toshiya Nosaka , Atsushi Teramoto
{"title":"Treatment for congenital unilateral hip dislocation with ipsilateral below-knee hemimelia: A case report","authors":"Hiroki Fujita , Toshiya Nosaka , Atsushi Teramoto","doi":"10.1016/j.joscr.2024.07.001","DOIUrl":"10.1016/j.joscr.2024.07.001","url":null,"abstract":"<div><h3>Background</h3><div>The Pavlik harness or overhead traction have been widely recognized as conservative treatment for congenital hip dislocation. To our knowledge, there are no case reports of a patient with congenital unilateral hip dislocation and ipsilateral below-knee hemimelia being treated using overhead traction.</div></div><div><h3>Case presentation</h3><div>We performed overhead traction using a prosthetic socket and subsequent Lorenz casting in an eleven-month-old boy suffering from congenital right hip dislocation, ipsilateral femoral hypoplasia, and below-knee hemimelia. Redislocation had not occurred as of age three. Despite remnant acetabular deficiency, he obtained independent walking using a right below-knee prosthesis.</div></div><div><h3>Conclusions</h3><div>This is the first report of conservative overhead traction using this specialized tool and subsequent immobilization for a patient with the aforementioned teratologic hip dislocation. This prosthetic socket has the potential to avoid complications associated with skeletal traction, as well as to help reassure parents.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 1","pages":"Pages 10-13"},"PeriodicalIF":0.0,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141695945","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Successful treatment of a recalcitrant nonunion after periprosthetic femoral fracture using a cementless long stem with interlocking screws inserted via a locking plate: A case report","authors":"Masashi Sato, Hisatoshi Ishikura , Naoto Kaminaga, Takeyuki Tanaka, Sakae Tanaka","doi":"10.1016/j.joscr.2024.05.003","DOIUrl":"10.1016/j.joscr.2024.05.003","url":null,"abstract":"<div><h3>Background</h3><div>Nonunion after periprosthetic femoral fracture is a recalcitrant challenge for hip surgeons.</div></div><div><h3>Case presentation</h3><div>A 55-year-old man underwent hemiarthroplasty for right femoral head osteonecrosis at another hospital. Two weeks after surgery, he developed a periprosthetic femoral fracture. He was referred to our hospital because of nonunion of the fracture site even after five surgeries. Surgery was performed using a cementless long stem combined with a locking plate. Three locking screws were passed through the distal holes of the stem to improve fixation. Bone union was achieved, and he was able to walk six months after surgery.</div></div><div><h3>Conclusions</h3><div>A cementless long stem with interlocking screws inserted via a locking plate offers rigid stability and bone union. Our report is relevant because it highlights a surgical option for recalcitrant nonunion after periprosthetic femoral fractures.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 196-200"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141414945","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Long-term efficacy of eribulin in patients with advanced myxoid liposarcoma resistant to trabectedin: A case report","authors":"Kazuma Arai , Koichi Okajima , Yuki Ishibashi , Yusuke Tsuda , Shinji Kohsaka , Yoichi Yasunaga , Kohichi Takada , Makoto Emori , Tetsuo Ushiku , Katsutoshi Oda , Kiyoshi Miyagawa , Hiroyuki Aburatani , Hiroyuki Mano , Sakae Tanaka , Hiroshi Kobayashi","doi":"10.1016/j.joscr.2024.06.002","DOIUrl":"10.1016/j.joscr.2024.06.002","url":null,"abstract":"<div><h3>Background</h3><div>Myxoid liposarcoma is sensitive to trabectedin, but less sensitive to eribulin.</div></div><div><h3>Case presentation</h3><div>A 47-year-old man presented to our hospital with a right leg mass, biopsy of which revealed myxoid liposarcoma. Surgical resection was performed and perioperative chemotherapy was administered. Eighteen years postoperatively, the patient developed pericardial metastasis causing cardiac tamponade, and radiotherapy was administered. One year later, mesenteric metastasis occurred and the tumor was resected. One year later to this, multiple metastases, including recurrent mesenteric metastases, occurred. As the metastases progressed after two cycles of trabectedin treatment, eribulin was initiated, resulting in a partial response. Eribulin was continued for 18 months without severe adverse events. Genetic testing of the resected mesenteric tumor revealed a <em>PIK3CA</em> (p.H1047R) mutation, and immunohistochemistry for phosphorylated AKT was negative.</div></div><div><h3>Conclusions</h3><div>This report of long-term successful treatment of trabectedin-resistant myxoid liposarcoma with eribulin suggests sensitivity mechanism to eribulin in myxoid liposarcoma with <em>PIK3CA</em> mutation.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 209-213"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143152399","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Chipping corrective osteotomy and autologous bone graft for malrotation with nonunion of a subtrochanteric femoral fracture: A case report","authors":"Masaki Takahashi, Juji Ito, Takeshi Sameshima, Michiaki Takagi, Yuya Takakubo","doi":"10.1016/j.joscr.2024.06.001","DOIUrl":"10.1016/j.joscr.2024.06.001","url":null,"abstract":"<div><h3>Background</h3><div>With subtrochanteric femoral fractures, it is often difficult to achieve appropriate positioning after reduction, and these fractures have a high risk of nonunion and malrotation. We report a case in which chipping corrective (CCO)was performed for nonunion and malrotation after subtrochanteric femoral fracture repair.</div></div><div><h3>Case presentation</h3><div>A 61-year-old man sustained a left femoral subtrochanteric fracture. Bone union was not achieved 2 years after the initial surgery. Additional surgery with CCO was performed 2 years and 9 months after the initial surgery. One year after CCO, bone union had been achieved circumferentially, and the difference in anteversion of the femoral neck from the opposite side had decreased from 49.3° preoperatively to 2.4° postoperatively.</div></div><div><h3>Conclusions</h3><div>CCO is useful for nonunion of subtrochanteric femoral fractures with malrotation. To our knowledge, there are no previous reports of CCO for postoperative nonunion of subtrochanteric femoral fractures.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 205-208"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141415643","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Retroperitoneal continuous local antibiotic perfusion for surgical site infection after lumbar lateral interbody fusion: A case report","authors":"Yawara Eguchi , Noritaka Suzuki , Sumihisa Orita , Kazuhide Inage , Miyako Narita , Yasuhiro Shiga , Masahiro Inoue , Soichiro Tokeshi , Kohei Okuyama , Shuhei Ohyama , Yasuchika Aoki , Junichi Nakamura , Shigeo Hagiwara , Yuya Kawarai , Tsutomu Akazawa , Masao Koda , Hiroshi Takahashi , Seiji Ohtori","doi":"10.1016/j.joscr.2024.05.002","DOIUrl":"10.1016/j.joscr.2024.05.002","url":null,"abstract":"<div><h3>Background</h3><div>Surgical site infection (SSI) after instrumented spinal surgery (ISS) is one of the most serious surgical complications. Treatment is often difficult, with many cases requiring removal of the implant.</div></div><div><h3>Case presentation</h3><div>An 80-year-old man developed refractory MRSA SSI after L4-5 Oblique Lateral Interbody Fusion surgery for a multiply operated back. Local debridement and retroperitoneal continuous local antibiotic perfusion (CLAP) were performed to preserve the implant. One month later, a second CLAP was performed for T6-7 suppurative spondylitis that had disseminated remotely to the thoracic spine. Following this, the lumbar spine and thoracic spine abscess, inflammatory response, and low back pain were reduced dramatically, and the implant was saved.</div></div><div><h3>Conclusion</h3><div>Even in the case of SSI after refractory anterior ISS, CLAP is a procedure worth trying first, as it is easy to install and manage, and will possibly control infection to preserve the implant.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 190-195"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143152741","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Pediatric gymnast with type 1 manubriosternal joint dislocation recovered by remodeling with conservative treatment: A case report","authors":"Hideki Hiraiwa , Tadahiro Sakai , Shinya Ishizuka , Hiroki Oba , Takafumi Mizuno , Takashi Tsukahara , Shiro Imagama","doi":"10.1016/j.joscr.2024.05.001","DOIUrl":"10.1016/j.joscr.2024.05.001","url":null,"abstract":"","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 187-189"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141277242","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"An alternative goal of conservative treatment in elite pediatric athletes with lumbar spondylolysis: A case report and literature review","authors":"Shutaro Fujimoto , Shunsuke Tamaki , Kosuke Sugiura , Makoto Takeuchi , Masatoshi Morimoto , Fumitake Tezuka , Kazuta Yamashita , Koichi Sairyo","doi":"10.1016/j.joscr.2024.05.004","DOIUrl":"10.1016/j.joscr.2024.05.004","url":null,"abstract":"<div><h3>Background</h3><div>The main conservative treatment strategies for lumbar spondylolysis are bone healing and pain management. Bone healing requires cessation of sports, which may be difficult for pediatric athletes.</div></div><div><h3>Case presentation</h3><div>A 15-year-old female athlete had bilateral L2 spondylolysis (right: very-early stage; left: progressive). Radiographs suggested vertebral maturity. Although bone healing could be expected on both sides, we aimed for continuation of play because she was a candidate for a national-level team attending an international competition. We implemented strenuous athletic rehabilitation based on joint-by-joint theory to reduce lumbar spine loading. A pars fracture led to pseudoarthrosis, but she continued playing and participated in the competition without problem.</div></div><div><h3>Conclusions</h3><div>In pediatric patients with spondylolysis and low risk of slippage, treatment aimed at continuation of play and pain management rather than bone healing may be considered, particularly in elite athletes. Strenuous athletic rehabilitation, including thoracic spine mobilization, is essential in such cases.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 201-204"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141411807","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}