JOS Case ReportsPub Date : 2025-03-27DOI: 10.1016/j.joscr.2025.02.003
Shuro Furuichi, Hirosuke Endo, Shigeru Mitani
{"title":"A case of Aitken Classification Type A proximal femoral focal deficiency treated with plate fixation for pseudarthrosis","authors":"Shuro Furuichi, Hirosuke Endo, Shigeru Mitani","doi":"10.1016/j.joscr.2025.02.003","DOIUrl":"10.1016/j.joscr.2025.02.003","url":null,"abstract":"<div><h3>Background</h3><div>Proximal femoral focal deficiency is a rare congenital anomaly with diverse clinical features and significant treatment challenges.</div></div><div><h3>Case presentation</h3><div>A female patient was diagnosed with Aitken type A proximal femoral focal deficiency at 1 month of age and surgically managed. She began walking after 17 months. At 34 months, she developed progressive varus and flexion deformities of the femur and complained of thigh pain. At 38 months, we excised the pseudoarthrosis, corrected the deformity, and performed plate fixation. At 4 years, growth suppression surgery was performed on the unaffected left leg. At 7 years, the affected lower limb was 13.5 cm shorter than the contralateral limb, requiring a 12-cm shoe lift.</div></div><div><h3>Conclusions</h3><div>A patient with Aitken type A proximal femoral focal deficiency presented with pseudarthrosis of the femur and was successfully treated surgically, resulting in thigh pain resolution.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 91-95"},"PeriodicalIF":0.0,"publicationDate":"2025-03-27","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908446","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2025-03-17DOI: 10.1016/j.joscr.2025.02.002
Narimichi Takino, Takuya Nakamura, Hideji Nishida
{"title":"Bilateral neglected femoral neck fracture due to vitamin D deficiency osteomalacia treated with total hip arthroplasty: A case report","authors":"Narimichi Takino, Takuya Nakamura, Hideji Nishida","doi":"10.1016/j.joscr.2025.02.002","DOIUrl":"10.1016/j.joscr.2025.02.002","url":null,"abstract":"<div><h3>Background</h3><div>Bilateral femoral neck fractures in young adults are rare and often result from trauma or underlying conditions like osteomalacia. Osteomalacia-related fractures are often treated late due to poor bone quality and untreated metabolic issues. In this case, the patient presented with a high-positioned dislocated hip resulting from old femoral neck fractures, which were successfully treated with total hip arthroplasty (THA).</div></div><div><h3>Case presentation</h3><div>A 31-year-old man with severe food allergies and atopic dermatitis developed bilateral femoral neck fractures due to vitamin D deficiency-induced osteomalacia. Poor bone quality initially made surgery unfeasible, leaving him wheelchair-bound for 13 years. After treating the vitamin D deficiency and improving bone quality, bilateral THA was performed at age 44. Fifteen weeks postoperatively, the patient was able to walk independently.</div></div><div><h3>Conclusions</h3><div>Osteomalacia-associated fractures require complex management due to delayed treatment. Recovery in this case was achieved by addressing osteomalacia first, followed by bilateral THA.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 87-90"},"PeriodicalIF":0.0,"publicationDate":"2025-03-17","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908445","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2025-03-16DOI: 10.1016/j.joscr.2025.02.001
Yuki Yoshida, Takeshi Ikegami
{"title":"Glenosphere dissociation combined with nonunion of a clavicular fracture following reverse shoulder arthroplasty","authors":"Yuki Yoshida, Takeshi Ikegami","doi":"10.1016/j.joscr.2025.02.001","DOIUrl":"10.1016/j.joscr.2025.02.001","url":null,"abstract":"<div><h3>Background</h3><div>Reverse shoulder arthroplasty (RSA) effectively improves outcomes for cuff tear arthropathy but carries a risk of complications. Glenosphere dissociation is a rare complication, and its occurrence with a shoulder girdle fracture has not been reported.</div></div><div><h3>Case presentation</h3><div>A 77-year-old female who had undergone RSA presented with chronic shoulder pain and a palpable mass. Imaging revealed glenosphere dissociation and clavicular nonunion with scapular malalignment. Surgical intervention included replacing the glenosphere and polyethylene liner, stabilizing the shoulder. Postoperative care involved sling immobilization, leading to pain relief and no recurrent dislocation despite limited functional recovery due to scapular malalignment.</div></div><div><h3>Conclusion</h3><div>We presented a rare case of glenosphere dissociation combined with clavicular nonunion following RSA. While pain relief was achieved by repairing the dislocation, clavicular nonunion contributing to scapular malalignment may hinder functional recovery. Surgical intervention for clavicular stabilization may be necessary in cases prioritizing shoulder function.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 83-86"},"PeriodicalIF":0.0,"publicationDate":"2025-03-16","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908444","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Gorham disease presenting as progressive osteolysis subsequent to a femoral neck fracture in a young patient: A rare case report","authors":"Daigo Shiraishi, Junya Shimizu, Makoto Emori, Yasutaka Murahashi, Ima Kosukegawa, Atsushi Teramoto","doi":"10.1016/j.joscr.2025.01.001","DOIUrl":"10.1016/j.joscr.2025.01.001","url":null,"abstract":"<div><h3>Background</h3><div>Gorham disease is characterized by unexplained osteolysis of bones over a period of several months, with the osteolytic areas being replaced by lymphovascular proliferation. The progression of the disease is unpredictable, as the expansion of the lesions may stop abruptly and regress spontaneously. Gorham disease is very rare and difficult to diagnose.</div></div><div><h3>Case presentation</h3><div>A 19-year-old male patient was referred to our hospital for further examination of osteolytic lesions after a femoral neck fracture. Histopathological analysis of the first biopsy resulted in the diagnosis of a hemangioma. However, because of progressive osteolysis, a second biopsy was performed; and he was diagnosed with Gorham disease. He underwent a wide resection and total hip arthroplasty. Two years postoperatively, he was able to walk unassisted and he had no signs of recurrence.</div></div><div><h3>Conclusions</h3><div>When osteolytic lesions are present in young patients, the differential diagnosis should include Gorham disease.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 79-82"},"PeriodicalIF":0.0,"publicationDate":"2025-02-19","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908443","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"New visualization of cervical nerve roots by ultrasound: Identification by 0–1 sign","authors":"Yuyu Ishimoto , Hiroshi Iwasaki , Kotaro Oda , Hiroshi Yamada","doi":"10.1016/j.joscr.2024.12.003","DOIUrl":"10.1016/j.joscr.2024.12.003","url":null,"abstract":"<div><h3>Introduction</h3><div>Ultrasound-guided cervical nerve root block is an effective technique that avoids radiation exposure. However, there is currently no standard technique for visualizing cervical nerve roots using ultrasound. The most common method is to search for the cervical nerve by moving the transducer from the brachial plexus in the direction of the head, using nerves and the scalene muscle as landmarks. However, this approach often poses difficulties for novice ultrasound operators because it can be difficult to identify these landmarks. We propose a new technique to visualize the cervical nerve root by using the common carotid artery and the C6 anterior tubercle as landmarks. Our aim was to quantitatively measure the anatomical positions of these landmarks to facilitate identification by novice ultrasound operators.</div></div><div><h3>Case reports</h3><div>Included in this study were 32 healthy volunteers (19 men, 13 women; mean age, 34.5 ± 10.5 years) who provided informed consent to inclusion in the study. The new technique called the ‘0–1 sign’ as the common carotid artery and the C6 anterior tubercle are morphologically likened to ‘0’ and ‘1’, respectively. Our aim was to measure the distance between the ‘0’ and ‘1’ and the distance of ‘1’ from the skin so as to allow beginners in ultrasound to quickly locate these landmarks.</div></div><div><h3>Conclusions</h3><div>Our new procedure for cervical nerve root visualization under ultrasound uses the 0–1 sign as an indicator. The results suggested that the 0–1 sign technique is a simple and effective method for cervical nerve root visualization and may serve as a reliable reference for ultrasound-guided cervical nerve root blocks.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 71-74"},"PeriodicalIF":0.0,"publicationDate":"2025-01-21","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908441","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"A severe equinovarus foot in a child with primary lymphedema","authors":"Mami Sugano , Toru Yamaguchi , Yoshihisa Kawakami , Tomoyuki Nakamura , Haruhisa Yanagida , Kazuyuki Takamura","doi":"10.1016/j.joscr.2024.12.004","DOIUrl":"10.1016/j.joscr.2024.12.004","url":null,"abstract":"<div><h3>Background</h3><div>Primary lymphedema is a rare disease, and there is no study on the treatment of joint disability or foot deformity with lymphedema.</div></div><div><h3>Case presentation</h3><div>A 6 years and 9 months old boy with primary congenital lymphedema presented with a severe untreated equinovarus foot. The posteromedial release was performed, and 1 year later, he gained a plantigrade foot and the ability to stand and walk with Ankle-Foot Orthoses.</div></div><div><h3>Conclusion</h3><div>Reports describing the treatment of foot deformities associated with primary congenital lymphedema are lacking. We successfully treated an acquired severe equinovarus foot considering the skin fragility associated with lymphedema.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 75-78"},"PeriodicalIF":0.0,"publicationDate":"2025-01-21","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908442","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Two cases of treatment of the seymour fracture complicated by pyogenic arthritis with antibiotic-impregnated calcium phosphate paste granules","authors":"Koki Hosozawa , Ryoichi Shibuya , Satoshi Miyamura , Toru Iwahashi , Takeshi Fuji","doi":"10.1016/j.joscr.2024.12.001","DOIUrl":"10.1016/j.joscr.2024.12.001","url":null,"abstract":"<div><h3>Background</h3><div>Seymour fractures are physeal fractures of the distal phalanx in children. These fractures are difficult to treat because they frequently lead to infections. We report two cases of Seymour fractures complicated by pyogenic arthritis, treated with vancomycin-impregnated paste granules of calcium phosphate cement, that showed good outcomes.</div></div><div><h3>Case presentation</h3><div>Two teenagers injured their fingers during rugby. They visited the outpatient clinic several days after the injury, presenting with purulent material discharge from the nail bed detachment. X-ray and MRI showed physeal fractures with associated inflammation, resulting in the diagnosis of Seymour fractures complicated by pyogenic arthritis and osteomyelitis. The wounds were irrigated and debrided, and the bone defect was filled with vancomycin-impregnated paste granules of calcium phosphate cement. While the growth plates closed prematurely, no recurrence of infection occurred.</div></div><div><h3>Conclusion</h3><div>In Seymour fractures complicated by pyogenic arthritis, vancomycin-impregnated paste granules of calcium phosphate cement are effective in controlling infection.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 63-66"},"PeriodicalIF":0.0,"publicationDate":"2025-01-04","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169589","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Operative treatment of neglected painful costal cartilage nonunion in a karate player","authors":"Masayoshi Ikeda , Daisuke Nakajima , Yuka Kobayashi , Ikuo Saito","doi":"10.1016/j.joscr.2024.12.002","DOIUrl":"10.1016/j.joscr.2024.12.002","url":null,"abstract":"<div><h3>Background</h3><div>Costal cartilage fractures are one of the common traumas in contact sports, and persistent pain from its nonunion severely limits sports activities. We report the surgical treatment of a karate athlete with this type of trauma.</div></div><div><h3>Case presentation</h3><div>A 35-year-old man sustained a seventh costal cartilage fracture from a kick to the left chest during a karate match a year ago. The patient had a residual deformity of the chest rib area and reported persistent and chronic pain. Operatively, the displaced costal cartilage fracture ends were freshened, reduced, and fixed with nonabsorbable threads. Postoperatively, the patient reengaged in sports activities without disabling painful symptoms.</div></div><div><h3>Conclusions</h3><div>Surgical treatment is an option for painful displaced costal cartilage nonunion in contact sports athletes.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 3","pages":"Pages 67-70"},"PeriodicalIF":0.0,"publicationDate":"2024-12-27","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144908440","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Chronic tibial osteomyelitis by Cutibacterium (Propionibacterium) acnes with characteristic imaging findings","authors":"Taiga Furukawa, Tomoaki Fukui, Yohei Kumabe, Ryosuke Kuroda, Keisuke Oe","doi":"10.1016/j.joscr.2024.11.002","DOIUrl":"10.1016/j.joscr.2024.11.002","url":null,"abstract":"<div><h3>Background</h3><div>Osteomyelitis caused by <em>Cutibacterium (Propionibacterium) acnes</em> (<em>C. acnes</em>) is rare, and there are no reports on the use of the Masquelet technique for its treatment.</div></div><div><h3>Case presentation</h3><div>A 21-year-old male patient visited a local hospital after spraining his left leg. Abnormal linear changes were noted on radiography and magnetic resonance imaging (MRI); however, the leg pain improved over time. Four years later, the patient was referred to our department because he experienced left leg pain again without any particular trigger, and a new linear lesion was found on imaging. Osteomyelitis was suspected. Curettage and filling with vancomycin-loaded bone cement were performed. Intraoperative tissue culture revealed <em>C. acnes</em>. Two months later, the cement was removed, and autologous iliac bone grafting was performed. Bony union was confirmed 5 months after the last surgery.</div></div><div><h3>Conclusion</h3><div>Osteomyelitis caused by <em>C. acnes</em> can show characteristic imaging findings.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 2","pages":"Pages 58-62"},"PeriodicalIF":0.0,"publicationDate":"2024-12-05","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"144169680","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Successful treatment of a recalcitrant nonunion after periprosthetic femoral fracture using a cementless long stem with interlocking screws inserted via a locking plate: A case report","authors":"Masashi Sato, Hisatoshi Ishikura , Naoto Kaminaga, Takeyuki Tanaka, Sakae Tanaka","doi":"10.1016/j.joscr.2024.05.003","DOIUrl":"10.1016/j.joscr.2024.05.003","url":null,"abstract":"<div><h3>Background</h3><div>Nonunion after periprosthetic femoral fracture is a recalcitrant challenge for hip surgeons.</div></div><div><h3>Case presentation</h3><div>A 55-year-old man underwent hemiarthroplasty for right femoral head osteonecrosis at another hospital. Two weeks after surgery, he developed a periprosthetic femoral fracture. He was referred to our hospital because of nonunion of the fracture site even after five surgeries. Surgery was performed using a cementless long stem combined with a locking plate. Three locking screws were passed through the distal holes of the stem to improve fixation. Bone union was achieved, and he was able to walk six months after surgery.</div></div><div><h3>Conclusions</h3><div>A cementless long stem with interlocking screws inserted via a locking plate offers rigid stability and bone union. Our report is relevant because it highlights a surgical option for recalcitrant nonunion after periprosthetic femoral fractures.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"3 4","pages":"Pages 196-200"},"PeriodicalIF":0.0,"publicationDate":"2024-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"141414945","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}