{"title":"Long-term outcomes of bone marrow blood transfusion combined with low-intensity pulsed ultrasound and external fixation in early-stage Preiser’s disease: A 10-year follow-up case report","authors":"Akira Ikumi , Takeshi Ogawa , Yuki Hara , Yuichi Yoshii , Naoyuki Ochiai , Masashi Yamazaki","doi":"10.1016/j.joscr.2025.05.003","DOIUrl":"10.1016/j.joscr.2025.05.003","url":null,"abstract":"<div><h3>Background</h3><div>Preiser’s disease, or avascular necrosis of the scaphoid, is a relatively rare condition, and its optimal treatment remains uncertain, especially in the early stages.</div></div><div><h3>Case presentation</h3><div>We described a case of a 37-year-old woman with stage I Preiser’s disease, who underwent bone marrow blood transfusion combined with low-intensity pulsed ultrasound and external fixation. Over a 10-year follow-up period, her wrist function was preserved, and disease progression was prevented.</div></div><div><h3>Conclusion</h3><div>This case highlights the long-term outcomes of bone marrow blood transfusion and low-intensity pulsed ultrasound for early-stage Preiser’s disease. While the combination of these treatments appeared effective, further studies are needed to determine the individual contributions of each modality.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 7-11"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414391","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Successful treatment of pediatric scaphoid nonunion with a vascularized bone graft: A report of four cases","authors":"Ryosuke Koshio , Hirotaka Akezuma , Ichiro Okano , Keikichi Kawasaki , Yoshifumi Kudo","doi":"10.1016/j.joscr.2025.10.001","DOIUrl":"10.1016/j.joscr.2025.10.001","url":null,"abstract":"<div><h3>Background</h3><div>Scaphoid fractures are rare in children, and the occurrence of nonunion is even more uncommon. While vascularized bone grafting (VBG) has been shown to be effective in adult scaphoid nonunion, the commonly used distal radius VBG carries a risk of growth plate injury in pediatric patients. This study reports the outcomes of VBG from the second metacarpal base for scaphoid nonunion in teenagers with open epiphysial line.</div></div><div><h3>Case presentation</h3><div>Since 2001, we treated four pediatric patients (≤14 years) with scaphoid nonunion using second metacarpal VBG. Grafts were harvested from the second metacarpal base, preserving the dorsal metacarpal artery, and fixed with headless screws and K-wires. Bone union was achieved in all cases. Although one case showed incomplete correction of DISI deformity, all patients had favorable outcomes in terms of range of motion and Mayo Wrist Scores.</div></div><div><h3>Conclusions</h3><div>Second metacarpal VBG achieved bone union and good function in pediatric scaphoid nonunion. Nonetheless, the potential limitations in correcting DISI deformity should be considered.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 21-24"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414348","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Symptomatic os vesalianum pedis triggered by gouty tophus: A case report","authors":"Yoshimasa Taniguchi , Tomonobu Hagio , Tetsuro Ishimatsu , Yuki Sugino , Seiya Tomonaga , Ryo Fukagawa , Ichiro Yoshimura , Takuaki Yamamoto","doi":"10.1016/j.joscr.2025.08.001","DOIUrl":"10.1016/j.joscr.2025.08.001","url":null,"abstract":"<div><h3>Background</h3><div>Os Vesalianum Pedis (OVP) is an accessory bone at the base of the fifth metatarsal. While rare, symptomatic cases requiring surgery may arise following sports injuries or trauma. We present a unique case of symptomatic OVP induced by gouty tophi.</div></div><div><h3>Case report</h3><div>A 25-year-old male with recurrent gout attacks had discontinued medication without supervision. One month before presentation, he experienced worsening foot pain that persisted despite resuming medication, prompting a visit to our department. Physical examination revealed swelling and tenderness in both lateral feet. Blood tests showed elevated uric acid and C-reactive protein. Imaging studies demonstrated osteolysis, marginal sclerosis, and erosion at the fifth metatarsal base. Surgical resection of the OVP relieved the pain completely.</div></div><div><h3>Conclusion</h3><div>This is the first reported case of OVP induced by gouty tophi. Prolonged hyperuricemia likely promoted tophus formation, impairing mobility between the fifth metatarsal and OVP, resulting in pain.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 16-20"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414349","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2026-03-01Epub Date: 2025-05-31DOI: 10.1016/j.joscr.2025.05.002
Yuta Watanabe , Naofumi Asano , Tsuyoshi Mizuma , Satoshi Kamio , Sayaka Yamaguchi , Tomoaki Mori , Hajime Okita , Robert Nakayama , Masaya Nakamura
{"title":"Epithelioid angiosarcoma arising within a schwannoma of the back: A case report","authors":"Yuta Watanabe , Naofumi Asano , Tsuyoshi Mizuma , Satoshi Kamio , Sayaka Yamaguchi , Tomoaki Mori , Hajime Okita , Robert Nakayama , Masaya Nakamura","doi":"10.1016/j.joscr.2025.05.002","DOIUrl":"10.1016/j.joscr.2025.05.002","url":null,"abstract":"<div><h3>Background</h3><div>Schwannomas are benign tumors that commonly occur in peripheral nerves, and their malignant transformation is extremely rare.</div></div><div><h3>Case presentation</h3><div>A 53-year-old man was aware of a mass in his right back for eight years. As the mass increased in size and became painful, he was referred to our hospital. Magnetic resonance imaging (MRI) revealed a 3 cm mass within the muscle layer. The tumor margins were regular, but it was heterogeneously contrasted. A needle biopsy suggested schwannoma, and we performed a resection. However, pathologically, the tumor was found to be composed of a benign schwannoma, an epithelioid angiosarcoma, and diagnosed an epithelioid angiosarcoma arising from a benign schwannoma. We performed an additional wide resection, and there has been no recurrence for four years after surgery.</div></div><div><h3>Conclusions</h3><div>We present a rare case of epithelioid angiosarcoma that developed within a schwannoma. If progressive symptoms are present, malignant transformation should be considered.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 1-6"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414390","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Bilateral tibial stress fracture and stress reaction: A report of 14 cases","authors":"Hiroaki Nishimoto , Junji Ohnishi , Lars Engebretsen , Tetsuo Yamaguchi","doi":"10.1016/j.joscr.2025.06.001","DOIUrl":"10.1016/j.joscr.2025.06.001","url":null,"abstract":"<div><h3>Background</h3><div>Several studies have reported that stress fractures (SFs) and stress reactions (SRs) rarely occur simultaneously in both tibiae.</div></div><div><h3>Case presentation</h3><div>This study of 14 athletes (11 males and 3 females) diagnosed with bilateral tibial SFs or SRs demonstrated that SFs and SRs occurred most frequently in July and September (21 % each). The mean age was 17.0 ± 4.0 and 15.6 ± 2.1 years in the SF and SR groups, respectively. SFs and SRs showed a high incidence in the mid-tibia, with minimal side-to-side difference.</div></div><div><h3>Conclusions</h3><div>Bilateral tibial SFs and SRs were more common in young male athletes, especially in summer. These injuries commonly occurred in the mid-tibia, with minimal side-to-side differences in fracture height. Anterior SFs were treated surgically, whereas posteromedial SFs and SRs were treated conservatively, allowing a return to competition.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 12-15"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414347","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Kaposiform hemangioendothelioma diagnosed following elbow painful contracture in an adolescent patient: A case report","authors":"Yoko Tanabe , Robert Nakayama , Kayoko Uno , Yutaka Kurebayashi , Yosuke Yamamoto , Satoshi Kamio , Sayaka Yamaguchi , Tomoaki Mori , Naofumi Asano , Yohei Masugi , Taiki Nozaki , Noriko Aramaki , Masaya Nakamura","doi":"10.1016/j.joscr.2025.03.001","DOIUrl":"10.1016/j.joscr.2025.03.001","url":null,"abstract":"<div><h3>Background</h3><div>Kaposiform hemangioendothelioma is a rare, locally invasive vascular tumor of intermediate malignancy that most frequently involves the extremities. Most cases manifest in infancy and are associated with life-threatening consumptive coagulopathy, known as the Kasabach–Merritt phenomenon, acute pain, and functional limitations.</div></div><div><h3>Case presentation</h3><div>We present an extremely rare case of kaposiform hemangioendothelioma in a 15-year-old girl who had had no remarkable symptoms other than skin erythema until she developed severe pain and elbow contracture during adolescence. Although marginal tumor resection necessitated concurrent triceps tendon resection, her symptoms resolved without recurrence over a 2-year follow-up.</div></div><div><h3>Conclusions</h3><div>This case highlights that probably congenital kaposiform hemangioendothelioma may not cause significant symptoms until adolescence and the importance of resection for symptomatic resectable lesions.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 97-101"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610538","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Tibial-hindfoot turn-up plasty following proximal femur and periacetabular resection for unplanned sarcoma resection: A case report","authors":"Daniela Kristina Carolino, Hirohisa Katagiri, Junji Wasa, Hideki Murata, Kan Ito, Shunichi Toki, Mitsuru Takahashi, Ryo Satake","doi":"10.1016/j.joscr.2025.05.001","DOIUrl":"10.1016/j.joscr.2025.05.001","url":null,"abstract":"<div><h3>Introduction</h3><div>Various reconstruction options are available following femoral resection for malignancies or complex cases with femoral involvement. Tibia-hindfoot osteomusculocutaneous rotationplasty, a rare reconstruction alternative introduced by Peterson in 1997, is a modification of the original technique of total tibial turn up proposed by Sauerbruch in 1922. However, data on the outcomes of this procedure are lacking.</div></div><div><h3>Case report</h3><div>A 50-year-old male patient with a 15-year history of right hip pain underwent unplanned resection, followed by total hip arthroplasty for clear cell chondrosarcoma of the femoral head and neck, with tibial-hindfoot turn-up plasty subsequently performed as a salvage procedure. Thirty-two months postoperatively, he was ambulatory with a prosthetic leg and a single crutch.</div></div><div><h3>Conclusion</h3><div>Benefits of tibial-hindfoot turn-up plasty include a longer stump for better prosthesis fitting, and better functional outcomes than hemipelvectomy. Furthermore, unlike a tumor prosthesis, revision is unlikely, and compared with rotationoplasty, this results in better cosmesis and fewer vascular complications.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 114-118"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610542","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2025-12-01Epub Date: 2025-05-03DOI: 10.1016/j.joscr.2025.04.001
Takumi Kaku , Yoto Oh , Toshitaka Yoshii
{"title":"Urethral injury secondary to advanced fragility fracture of the pelvis: A case report","authors":"Takumi Kaku , Yoto Oh , Toshitaka Yoshii","doi":"10.1016/j.joscr.2025.04.001","DOIUrl":"10.1016/j.joscr.2025.04.001","url":null,"abstract":"<div><h3>Background</h3><div>Fragility fracture of the pelvic ring (FFP) is rarely associated with urinary tract complications. We experienced a case of advanced FFP with urethral injury as late complications.</div></div><div><h3>Case presentation</h3><div>The patient was an 83-year-old woman with no trauma episode who was admitted to our hospital due to acute groin pain. After several examinations, we diagnosed urethral rupture, urine leakage with bacterial contamination, urinary retention, and advanced FFP. We immediately performed cystostomy, puncture drainage for urine leakage, and antibiotic administration. Three weeks later, as the leakage and infection were controlled, internal fixation was performed for the FFP. Although she could walk alone with a cane at 1 year after the surgery, complete bone union was not achieved.</div></div><div><h3>Conclusion</h3><div>This case was the advanced FFP complicated with urethral rupture, and the sequential treatments for each urinary retention, infection, and pelvic ring instability resulted in an acceptable outcome. Surgeons should recognize that chronic instability and repetitive friction in FFPs may be factors of urinary tract complications.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 102-105"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610539","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Sequential multimodal management of methicillin-resistant Staphylococcus aureus-infected tibial pseudoarthrosis: A case report on the application of an antibiotic-loaded cement spacer and the continuous local antibiotic perfusion technique across three stages","authors":"Yosuke Kaneko , Yunhan Ji , Sho Nojiri , Kazue Hayakawa , Nobuyuki Fujita","doi":"10.1016/j.joscr.2025.04.002","DOIUrl":"10.1016/j.joscr.2025.04.002","url":null,"abstract":"<div><h3>Background</h3><div>Infected pseudoarthrosis requires effective infection control and successful bone union. Hence, this pathology is challenging to manage.</div></div><div><h3>Case presentation</h3><div>Herein, we report on a 41-year-old male patient who presented with methicillin-resistant <em>Staphylococcus aureus</em>-infected pseudoarthrosis after a primary surgery at another institution. After debridement, cement spacer insertion, and application of an intra-soft tissue antibiotic perfusion (iSAP) system for infection control, the final stage of bone fixation surgery with allogeneic bone grafting was performed. During the postoperative course, low-intensity pulsed ultrasound (LIPUS) was conducted. Ultimately, both infection control and bone union were achieved. At the latest follow-up, the patient had regained normal gait and was able to return to work.</div></div><div><h3>Conclusion</h3><div>Comprehensive treatment strategies must be considered for challenging pathologies such as infected pseudoarthrosis.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 106-109"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610540","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
JOS Case ReportsPub Date : 2025-12-01Epub Date: 2025-05-07DOI: 10.1016/j.joscr.2025.04.003
Giulia Masci , Valeria Calogero , Luca Basiglini , Marco Giordano , Martina Marsiolo , Angelo Gabriele Aulisa , Francesco Falciglia
{"title":"Achilles tendon rupture in previously treated clubfoot: Is there a correlation? A pediatric case report and a literature review","authors":"Giulia Masci , Valeria Calogero , Luca Basiglini , Marco Giordano , Martina Marsiolo , Angelo Gabriele Aulisa , Francesco Falciglia","doi":"10.1016/j.joscr.2025.04.003","DOIUrl":"10.1016/j.joscr.2025.04.003","url":null,"abstract":"<div><h3>Backgrounds</h3><div>Achilles tendon rupture in children is very rare. The cause could be traumatic or non-traumatic such as clubfoot deformity, auto-immune, infectious or genetic diseases with collagen alterations. Regarding clubfoot, only a few case reports of Achilles tendon injury in previously treated feet diagnosed with this deformity are available in the literature. The most accepted treatment for clubfoot is represented by the Ponseti method which includes manipulations, corrective casts and Achilles tendon tenotomy. After surgery, the tendon fibres appear to heal properly.</div></div><div><h3>Case report</h3><div>We present the case of a 14-year-old girl who was referred to the emergency department for intense right ankle pain aroused while running, which resulted in a ruptured Achilles tendon. She had a history of bilateral clubfoot previously treated in her neonatal age with the Ponseti method including Achilles tendon tenotomy. The actual tendon lesion was treated surgically with an open terminus-terminal tenorrhaphy and immobilisation with a cast. Full recovery occurred after 2 months.</div></div><div><h3>Discussion and conclusions</h3><div>This study presents a rare case of Achilles tendon injury in previously treated clubfoot. Treatment of clubfoot is necessary to avoid invalidating sequelae. Achilles tenotomy is a widely accepted and effective procedure and studies have shown that tendon quality and muscle strength at week 12 are comparable to those of a normal tendon and the remodelling process continues up to three years later. Further studies are needed to investigate the possible link between clubfoot treatment and the later rupture of the Achilles tendon.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 110-113"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610541","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}