JOS Case Reports最新文献

筛选
英文 中文
Osteochondritis dissecans of the medial humeral trochlea in a competitive tennis player: A rare case and surgical insight 一例网球选手肱骨内侧滑车夹层性骨软骨炎:一例罕见病例及外科观察
JOS Case Reports Pub Date : 2026-06-01 Epub Date: 2026-01-12 DOI: 10.1016/j.joscr.2025.12.001
Akira Kinoda , Kazuki Sato , Yuichi Yamada , Yoshihiro Maruko , Takuji Iwamoto , Noboru Matsumura , Taku Suzuki , Yasuhiro Kiyota , Masato Yoshida
{"title":"Osteochondritis dissecans of the medial humeral trochlea in a competitive tennis player: A rare case and surgical insight","authors":"Akira Kinoda ,&nbsp;Kazuki Sato ,&nbsp;Yuichi Yamada ,&nbsp;Yoshihiro Maruko ,&nbsp;Takuji Iwamoto ,&nbsp;Noboru Matsumura ,&nbsp;Taku Suzuki ,&nbsp;Yasuhiro Kiyota ,&nbsp;Masato Yoshida","doi":"10.1016/j.joscr.2025.12.001","DOIUrl":"10.1016/j.joscr.2025.12.001","url":null,"abstract":"<div><h3>Background</h3><div>Osteochondritis dissecans of the medial humeral trochlea is exceptionally rare, with no prior reports in tennis players.</div></div><div><h3>Case presentation</h3><div>A 14-year-old elite female tennis athlete presented with 6 months of medial left elbow pain exacerbated by serving. Examination revealed tenderness over the humeroulnar joint and a mild extension deficit. Computed tomography identified a loose osteochondral fragment posteromedial to the trochlea. Fat-suppressed T2-weighted magnetic resonance imaging demonstrated a hypointense line between the parent bone and fragment, leading to a diagnosis of osteochondritis dissecans. Surgery exposed and reattached the fragment using two 2.5 mm bone pegs. Radiographic union was achieved within 4 months, allowing a gradual return to serving. Six months after the surgery, she resumed unrestricted play.</div></div><div><h3>Conclusion</h3><div>We performed bone-peg grafting for medial trochlear osteochondritis dissecans in a tennis player's elbow and achieved favorable outcomes.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 2","pages":"Pages 29-34"},"PeriodicalIF":0.0,"publicationDate":"2026-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"148060325","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
A case of focused extracorporeal shock wave therapy in a person with plantar fasciitis and hemophilia A 聚焦体外冲击波治疗足底筋膜炎合并A型血友病1例
JOS Case Reports Pub Date : 2026-06-01 Epub Date: 2026-01-14 DOI: 10.1016/j.joscr.2026.01.002
Takeshi Seki , Toshinori Masaoka , Toshiyuki Tateiwa , Ryui Miyashita , Yushi Chikasawa , Tsunehito Ishida , Kagehiro Amano , Ei Kinai , Kengo Yamamoto
{"title":"A case of focused extracorporeal shock wave therapy in a person with plantar fasciitis and hemophilia A","authors":"Takeshi Seki ,&nbsp;Toshinori Masaoka ,&nbsp;Toshiyuki Tateiwa ,&nbsp;Ryui Miyashita ,&nbsp;Yushi Chikasawa ,&nbsp;Tsunehito Ishida ,&nbsp;Kagehiro Amano ,&nbsp;Ei Kinai ,&nbsp;Kengo Yamamoto","doi":"10.1016/j.joscr.2026.01.002","DOIUrl":"10.1016/j.joscr.2026.01.002","url":null,"abstract":"<div><h3>Background</h3><div>People with hemophilia often experience chronic musculoskeletal pain, but invasive treatments are avoided due to bleeding risk. Extracorporeal shock wave therapy (ESWT) is widely used for refractory tendinopathies, yet its application in hemophilia is rarely reported.</div></div><div><h3>Case presentation</h3><div>A 28-year-old man with severe hemophilia A and bilateral plantar fasciitis unresponsive to conservative therapy underwent focused ESWT after factor VIII replacement. Pain markedly improved after the first session and remained lower at 12 months without hemorrhagic complications.</div></div><div><h3>Conclusion</h3><div>Low-to medium-energy ESWT for plantar fasciitis can be safely performed in people with hemophilia when adequate coagulation factor activity is maintained.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 2","pages":"Pages 40-43"},"PeriodicalIF":0.0,"publicationDate":"2026-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"148060327","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
A rare case of spinal epidural lipomatosis secondary to pituitary Cushing disease presenting with progressive paraparesis 一个罕见的脊髓硬膜外脂肪瘤病继发于垂体库欣病,表现为进行性麻痹
JOS Case Reports Pub Date : 2026-06-01 Epub Date: 2026-02-13 DOI: 10.1016/j.joscr.2026.02.001
Masahiro Hirahata, Muneyoshi Fujita, Tomoaki Kitagawa, Hirotaka Kawano
{"title":"A rare case of spinal epidural lipomatosis secondary to pituitary Cushing disease presenting with progressive paraparesis","authors":"Masahiro Hirahata,&nbsp;Muneyoshi Fujita,&nbsp;Tomoaki Kitagawa,&nbsp;Hirotaka Kawano","doi":"10.1016/j.joscr.2026.02.001","DOIUrl":"10.1016/j.joscr.2026.02.001","url":null,"abstract":"<div><h3>Background</h3><div>Spinal epidural lipomatosis (SEL) is a rare condition characterized by excessive epidural fat accumulation. Although most cases are secondary to long-term corticosteroid use, SEL due to Cushing disease (CD) is extremely uncommon.</div></div><div><h3>Case presentation</h3><div>A 62-year-old woman presented with progressive paraparesis due to SEL associated with thoracic kyphosis from osteoporotic vertebral fractures. Emergency decompression was performed, followed by endocrine evaluation that revealed pituitary CD. The patient regained full neurological function after surgery.</div></div><div><h3>Conclusions</h3><div>This case represents the third reported instance of SEL caused by pituitary CD requiring spinal surgery. Early recognition and prompt decompression are essential for recovery.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 2","pages":"Pages 44-49"},"PeriodicalIF":0.0,"publicationDate":"2026-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"148060342","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Subcutaneous flexor pollicis longus tendon rupture caused by scapho-trapezio-trapezoidal osteoarthritis: A case report of wide-awake surgery 舟状-梯形-梯形骨关节炎致拇长屈肌腱断裂:全清醒手术一例
JOS Case Reports Pub Date : 2026-06-01 Epub Date: 2026-03-02 DOI: 10.1016/j.joscr.2026.02.004
Seishiro Matsumoto , Takuya Uemura , Yusuke Miyashima , Sadahiko Konishi , Hidetomi Terai
{"title":"Subcutaneous flexor pollicis longus tendon rupture caused by scapho-trapezio-trapezoidal osteoarthritis: A case report of wide-awake surgery","authors":"Seishiro Matsumoto ,&nbsp;Takuya Uemura ,&nbsp;Yusuke Miyashima ,&nbsp;Sadahiko Konishi ,&nbsp;Hidetomi Terai","doi":"10.1016/j.joscr.2026.02.004","DOIUrl":"10.1016/j.joscr.2026.02.004","url":null,"abstract":"<div><h3>Background</h3><div>Subcutaneous flexor pollicis longus (FPL) tendon rupture caused by scapho-trapezio-trapezoidal (STT) osteoarthritis is rare. Wide-awake surgery under local anesthesia has become widespread in tendon-related hand surgeries because surgeons can precisely evaluate a patient's voluntary active finger motion.</div></div><div><h3>Case presentation</h3><div>Herein, we present the first case of an 86-year-old woman with FPL tendon rupture secondary to asymptomatic STT osteoarthritis treated with wide-awake tendon grafting. Intraoperatively, the FPL tendon completely ruptured owing to friction from the osteophyte in the STT joint. After resection of the bony spurs, the ruptured FPL tendon was reconstructed with grafting of the palmaris longus tendon, and the optimal tension was determined during active thumb movement. The patient was able to actively flex the interphalangeal joint of the thumb 12 months postoperatively.</div></div><div><h3>Conclusion</h3><div>This case highlights that asymptomatic STT osteoarthritis can potentially cause FPL tendon rupture through bony spurs and that wide-awake surgery offers advantages for precise intraoperative evaluation and repair.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 2","pages":"Pages 55-58"},"PeriodicalIF":0.0,"publicationDate":"2026-06-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"148060344","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Long-term outcomes of bone marrow blood transfusion combined with low-intensity pulsed ultrasound and external fixation in early-stage Preiser’s disease: A 10-year follow-up case report 骨髓输血联合低强度脉冲超声和外固定治疗早期Preiser病的长期疗效:10年随访病例报告
JOS Case Reports Pub Date : 2026-03-01 Epub Date: 2025-06-14 DOI: 10.1016/j.joscr.2025.05.003
Akira Ikumi , Takeshi Ogawa , Yuki Hara , Yuichi Yoshii , Naoyuki Ochiai , Masashi Yamazaki
{"title":"Long-term outcomes of bone marrow blood transfusion combined with low-intensity pulsed ultrasound and external fixation in early-stage Preiser’s disease: A 10-year follow-up case report","authors":"Akira Ikumi ,&nbsp;Takeshi Ogawa ,&nbsp;Yuki Hara ,&nbsp;Yuichi Yoshii ,&nbsp;Naoyuki Ochiai ,&nbsp;Masashi Yamazaki","doi":"10.1016/j.joscr.2025.05.003","DOIUrl":"10.1016/j.joscr.2025.05.003","url":null,"abstract":"<div><h3>Background</h3><div>Preiser’s disease, or avascular necrosis of the scaphoid, is a relatively rare condition, and its optimal treatment remains uncertain, especially in the early stages.</div></div><div><h3>Case presentation</h3><div>We described a case of a 37-year-old woman with stage I Preiser’s disease, who underwent bone marrow blood transfusion combined with low-intensity pulsed ultrasound and external fixation. Over a 10-year follow-up period, her wrist function was preserved, and disease progression was prevented.</div></div><div><h3>Conclusion</h3><div>This case highlights the long-term outcomes of bone marrow blood transfusion and low-intensity pulsed ultrasound for early-stage Preiser’s disease. While the combination of these treatments appeared effective, further studies are needed to determine the individual contributions of each modality.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 7-11"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414391","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Successful treatment of pediatric scaphoid nonunion with a vascularized bone graft: A report of four cases 带血管骨移植成功治疗儿童舟状骨不连:附4例报告
JOS Case Reports Pub Date : 2026-03-01 Epub Date: 2025-10-21 DOI: 10.1016/j.joscr.2025.10.001
Ryosuke Koshio , Hirotaka Akezuma , Ichiro Okano , Keikichi Kawasaki , Yoshifumi Kudo
{"title":"Successful treatment of pediatric scaphoid nonunion with a vascularized bone graft: A report of four cases","authors":"Ryosuke Koshio ,&nbsp;Hirotaka Akezuma ,&nbsp;Ichiro Okano ,&nbsp;Keikichi Kawasaki ,&nbsp;Yoshifumi Kudo","doi":"10.1016/j.joscr.2025.10.001","DOIUrl":"10.1016/j.joscr.2025.10.001","url":null,"abstract":"<div><h3>Background</h3><div>Scaphoid fractures are rare in children, and the occurrence of nonunion is even more uncommon. While vascularized bone grafting (VBG) has been shown to be effective in adult scaphoid nonunion, the commonly used distal radius VBG carries a risk of growth plate injury in pediatric patients. This study reports the outcomes of VBG from the second metacarpal base for scaphoid nonunion in teenagers with open epiphysial line.</div></div><div><h3>Case presentation</h3><div>Since 2001, we treated four pediatric patients (≤14 years) with scaphoid nonunion using second metacarpal VBG. Grafts were harvested from the second metacarpal base, preserving the dorsal metacarpal artery, and fixed with headless screws and K-wires. Bone union was achieved in all cases. Although one case showed incomplete correction of DISI deformity, all patients had favorable outcomes in terms of range of motion and Mayo Wrist Scores.</div></div><div><h3>Conclusions</h3><div>Second metacarpal VBG achieved bone union and good function in pediatric scaphoid nonunion. Nonetheless, the potential limitations in correcting DISI deformity should be considered.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 21-24"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414348","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Symptomatic os vesalianum pedis triggered by gouty tophus: A case report 痛风性痛风引起的症状性足疱1例
JOS Case Reports Pub Date : 2026-03-01 Epub Date: 2025-09-01 DOI: 10.1016/j.joscr.2025.08.001
Yoshimasa Taniguchi , Tomonobu Hagio , Tetsuro Ishimatsu , Yuki Sugino , Seiya Tomonaga , Ryo Fukagawa , Ichiro Yoshimura , Takuaki Yamamoto
{"title":"Symptomatic os vesalianum pedis triggered by gouty tophus: A case report","authors":"Yoshimasa Taniguchi ,&nbsp;Tomonobu Hagio ,&nbsp;Tetsuro Ishimatsu ,&nbsp;Yuki Sugino ,&nbsp;Seiya Tomonaga ,&nbsp;Ryo Fukagawa ,&nbsp;Ichiro Yoshimura ,&nbsp;Takuaki Yamamoto","doi":"10.1016/j.joscr.2025.08.001","DOIUrl":"10.1016/j.joscr.2025.08.001","url":null,"abstract":"<div><h3>Background</h3><div>Os Vesalianum Pedis (OVP) is an accessory bone at the base of the fifth metatarsal. While rare, symptomatic cases requiring surgery may arise following sports injuries or trauma. We present a unique case of symptomatic OVP induced by gouty tophi.</div></div><div><h3>Case report</h3><div>A 25-year-old male with recurrent gout attacks had discontinued medication without supervision. One month before presentation, he experienced worsening foot pain that persisted despite resuming medication, prompting a visit to our department. Physical examination revealed swelling and tenderness in both lateral feet. Blood tests showed elevated uric acid and C-reactive protein. Imaging studies demonstrated osteolysis, marginal sclerosis, and erosion at the fifth metatarsal base. Surgical resection of the OVP relieved the pain completely.</div></div><div><h3>Conclusion</h3><div>This is the first reported case of OVP induced by gouty tophi. Prolonged hyperuricemia likely promoted tophus formation, impairing mobility between the fifth metatarsal and OVP, resulting in pain.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 16-20"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414349","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Epithelioid angiosarcoma arising within a schwannoma of the back: A case report 发生于背部神经鞘瘤的上皮样血管肉瘤1例报告
JOS Case Reports Pub Date : 2026-03-01 Epub Date: 2025-05-31 DOI: 10.1016/j.joscr.2025.05.002
Yuta Watanabe , Naofumi Asano , Tsuyoshi Mizuma , Satoshi Kamio , Sayaka Yamaguchi , Tomoaki Mori , Hajime Okita , Robert Nakayama , Masaya Nakamura
{"title":"Epithelioid angiosarcoma arising within a schwannoma of the back: A case report","authors":"Yuta Watanabe ,&nbsp;Naofumi Asano ,&nbsp;Tsuyoshi Mizuma ,&nbsp;Satoshi Kamio ,&nbsp;Sayaka Yamaguchi ,&nbsp;Tomoaki Mori ,&nbsp;Hajime Okita ,&nbsp;Robert Nakayama ,&nbsp;Masaya Nakamura","doi":"10.1016/j.joscr.2025.05.002","DOIUrl":"10.1016/j.joscr.2025.05.002","url":null,"abstract":"<div><h3>Background</h3><div>Schwannomas are benign tumors that commonly occur in peripheral nerves, and their malignant transformation is extremely rare.</div></div><div><h3>Case presentation</h3><div>A 53-year-old man was aware of a mass in his right back for eight years. As the mass increased in size and became painful, he was referred to our hospital. Magnetic resonance imaging (MRI) revealed a 3 cm mass within the muscle layer. The tumor margins were regular, but it was heterogeneously contrasted. A needle biopsy suggested schwannoma, and we performed a resection. However, pathologically, the tumor was found to be composed of a benign schwannoma, an epithelioid angiosarcoma, and diagnosed an epithelioid angiosarcoma arising from a benign schwannoma. We performed an additional wide resection, and there has been no recurrence for four years after surgery.</div></div><div><h3>Conclusions</h3><div>We present a rare case of epithelioid angiosarcoma that developed within a schwannoma. If progressive symptoms are present, malignant transformation should be considered.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 1-6"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414390","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Bilateral tibial stress fracture and stress reaction: A report of 14 cases 双侧胫骨应力性骨折及应力反应:附14例报告
JOS Case Reports Pub Date : 2026-03-01 Epub Date: 2025-07-24 DOI: 10.1016/j.joscr.2025.06.001
Hiroaki Nishimoto , Junji Ohnishi , Lars Engebretsen , Tetsuo Yamaguchi
{"title":"Bilateral tibial stress fracture and stress reaction: A report of 14 cases","authors":"Hiroaki Nishimoto ,&nbsp;Junji Ohnishi ,&nbsp;Lars Engebretsen ,&nbsp;Tetsuo Yamaguchi","doi":"10.1016/j.joscr.2025.06.001","DOIUrl":"10.1016/j.joscr.2025.06.001","url":null,"abstract":"<div><h3>Background</h3><div>Several studies have reported that stress fractures (SFs) and stress reactions (SRs) rarely occur simultaneously in both tibiae.</div></div><div><h3>Case presentation</h3><div>This study of 14 athletes (11 males and 3 females) diagnosed with bilateral tibial SFs or SRs demonstrated that SFs and SRs occurred most frequently in July and September (21 % each). The mean age was 17.0 ± 4.0 and 15.6 ± 2.1 years in the SF and SR groups, respectively. SFs and SRs showed a high incidence in the mid-tibia, with minimal side-to-side difference.</div></div><div><h3>Conclusions</h3><div>Bilateral tibial SFs and SRs were more common in young male athletes, especially in summer. These injuries commonly occurred in the mid-tibia, with minimal side-to-side differences in fracture height. Anterior SFs were treated surgically, whereas posteromedial SFs and SRs were treated conservatively, allowing a return to competition.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"5 1","pages":"Pages 12-15"},"PeriodicalIF":0.0,"publicationDate":"2026-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"147414347","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Kaposiform hemangioendothelioma diagnosed following elbow painful contracture in an adolescent patient: A case report 卡波西样血管内皮瘤诊断后肘部疼痛挛缩的青少年患者:1例报告
JOS Case Reports Pub Date : 2025-12-01 Epub Date: 2025-03-17 DOI: 10.1016/j.joscr.2025.03.001
Yoko Tanabe , Robert Nakayama , Kayoko Uno , Yutaka Kurebayashi , Yosuke Yamamoto , Satoshi Kamio , Sayaka Yamaguchi , Tomoaki Mori , Naofumi Asano , Yohei Masugi , Taiki Nozaki , Noriko Aramaki , Masaya Nakamura
{"title":"Kaposiform hemangioendothelioma diagnosed following elbow painful contracture in an adolescent patient: A case report","authors":"Yoko Tanabe ,&nbsp;Robert Nakayama ,&nbsp;Kayoko Uno ,&nbsp;Yutaka Kurebayashi ,&nbsp;Yosuke Yamamoto ,&nbsp;Satoshi Kamio ,&nbsp;Sayaka Yamaguchi ,&nbsp;Tomoaki Mori ,&nbsp;Naofumi Asano ,&nbsp;Yohei Masugi ,&nbsp;Taiki Nozaki ,&nbsp;Noriko Aramaki ,&nbsp;Masaya Nakamura","doi":"10.1016/j.joscr.2025.03.001","DOIUrl":"10.1016/j.joscr.2025.03.001","url":null,"abstract":"<div><h3>Background</h3><div>Kaposiform hemangioendothelioma is a rare, locally invasive vascular tumor of intermediate malignancy that most frequently involves the extremities. Most cases manifest in infancy and are associated with life-threatening consumptive coagulopathy, known as the Kasabach–Merritt phenomenon, acute pain, and functional limitations.</div></div><div><h3>Case presentation</h3><div>We present an extremely rare case of kaposiform hemangioendothelioma in a 15-year-old girl who had had no remarkable symptoms other than skin erythema until she developed severe pain and elbow contracture during adolescence. Although marginal tumor resection necessitated concurrent triceps tendon resection, her symptoms resolved without recurrence over a 2-year follow-up.</div></div><div><h3>Conclusions</h3><div>This case highlights that probably congenital kaposiform hemangioendothelioma may not cause significant symptoms until adolescence and the importance of resection for symptomatic resectable lesions.</div></div>","PeriodicalId":100743,"journal":{"name":"JOS Case Reports","volume":"4 4","pages":"Pages 97-101"},"PeriodicalIF":0.0,"publicationDate":"2025-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145610538","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
0
×
引用
GB/T 7714-2015
复制
MLA
复制
APA
复制
导出至
BibTeX EndNote RefMan NoteFirst NoteExpress
×
提示
您的信息不完整,为了账户安全,请先补充。
现在去补充
×
提示
您因"违规操作"
具体请查看互助需知
我知道了
×
提示
确定
请完成安全验证×
相关产品
×
本文献相关产品
联系我们:info@booksci.cn Book学术提供免费学术资源搜索服务,方便国内外学者检索中英文文献。致力于提供最便捷和优质的服务体验。 Copyright © 2023 布克学术 All rights reserved.
京ICP备2023020795号-1
ghs 京公网安备 11010802042870号
Book学术文献互助
Book学术文献互助群
群 号:604180095
Book学术官方微信
小红书