Modern rheumatology case reports最新文献_第10页

Infliximab biosimilar-induced lupus nephritis: A case report. 英夫利昔单抗生物类似物诱导的狼疮性肾炎：一例报告。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad061

Kenta Shidahara, Takayuki Katsuyama, Kei Hirose, Kazuya Matsumoto, Shoichi Nawachi, Takato Nakadoi, Yosuke Asano, Yu Katayama, Yoshia Miyawaki, Eri Katsuyama, Mariko Takano-Narazaki, Yoshinori Matsumoto, Ken-Ei Sada, Jun Wada

引用次数: 0

The first case of SARS-CoV-2-induced eosinophilic fasciitis. 首例严重急性呼吸系统综合征冠状病毒2型引起的嗜酸性筋膜炎。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad063

Hiba Boussaa, Mariem Kamoun, Saoussen Miladi, Yasmine Makhlouf, Kawther Ben Abdelghani, Alia Fazaa, Ahmed Laatar

{"title":"The first case of SARS-CoV-2-induced eosinophilic fasciitis.","authors":"Hiba Boussaa, Mariem Kamoun, Saoussen Miladi, Yasmine Makhlouf, Kawther Ben Abdelghani, Alia Fazaa, Ahmed Laatar","doi":"10.1093/mrcr/rxad063","DOIUrl":"10.1093/mrcr/rxad063","url":null,"abstract":"Eosinophilic fasciitis (EF), also known as Shulman syndrome, is a rare auto-immune fibrosing disorder of the fascia. Etiopathogeny of EF is still unclear. Nowadays, it is widely known that severe acute respiratory syndrome coronavirus 2 (SARS-CoV-2) may induce hyper-stimulation of the immune system. Several cases with fasciitis and rhabdomyolysis induced by coronavirus disease 2019 vaccines have been reported in the literature. Herein, we report the first case of EF possibly triggered by SARS-CoV-2 infection. A 45-year-old Tunisian woman, with no medical history, presented to our department with severe widespread muscle pain noticed one month after a SARS-CoV-2 infection. Physical examination showed an induration of the skin and subcutaneous tissue of the arms, forearms and legs with a restricted joint mobility. The level of eosinophils was 430 E/mm3 (6.1%) [1-4%]. Electromyography and creatine kinase levels were normal. Myositis-related antibodies were negative. Magnetic resonance imaging of the left arm showed high-intensity signal and thickness of the fascia without evidence of muscle or bone involvement. A muscular biopsy from the right deltoid showed thickening and inflammation of the fascia. The patient received intraveinous injections of 1000 mg of methylprednisolone for 3 days with an oral relay of 1 mg/kg per day of prednisone equivalent during 4 weeks. At one-month follow-up, a significant improvement of the skin induration and myalgia was observed, with a disappearance of the biological inflammatory syndrome. This brief report suggests a potential link between SARS-CoV-2 infection and new-onset of auto-immune fasciitis.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"224-228"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"71416414","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Re-emphasising the importance of catheter-based angiography to differentiate polyarteritis nodosa from cutaneous arteritis: Two case reports. 再次强调导管血管造影术鉴别结节性多动脉炎和皮动脉炎的重要性：两例报告。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad064

Koji Suzuki, Mitsuhiro Akiyama, Yasushi Kondo, Shuntaro Saito, Jun Kikuchi, Hironari Hanaoka, Yuko Kaneko

引用次数: 0

Eosinophilic granulomatous with polyangiitis complicated by swelling of the oral cavity floor and cervical soft tissue as initial manifestation mimicking IgG4-related disease: A case report. 嗜酸性肉芽肿伴多血管炎，并伴有口腔底和颈部软组织肿胀，其最初表现类似IgG4相关疾病：一例报告。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad062

Tomoko Suzuki, Mayuko Moriyama, Ikuko Takano, Nobue Miyajima, Yuki Yoshioka, Manabu Honda, Masahiro Kondo, Sachiko Shokei, Asuka Araki, Kyuichi Kadota, Kunihiro Ichinose

{"title":"Eosinophilic granulomatous with polyangiitis complicated by swelling of the oral cavity floor and cervical soft tissue as initial manifestation mimicking IgG4-related disease: A case report.","authors":"Tomoko Suzuki, Mayuko Moriyama, Ikuko Takano, Nobue Miyajima, Yuki Yoshioka, Manabu Honda, Masahiro Kondo, Sachiko Shokei, Asuka Araki, Kyuichi Kadota, Kunihiro Ichinose","doi":"10.1093/mrcr/rxad062","DOIUrl":"10.1093/mrcr/rxad062","url":null,"abstract":"Eosinophilic granulomatous polyangiitis is a systemic vasculitis associated with bronchial asthma and eosinophilic sinusitis. Here, we describe an unusual presentation of eosinophilic granulomatous polyangiitis that initially manifested as swelling of the oral cavity floor and cervical soft tissue. A 58 year-old Japanese man was diagnosed with bronchial asthma during childhood but did not receive regular medication. Prior to this presentation, he had a persistent cough for over 1 month, and a local physician diagnosed him with bronchial asthma. However, 6 months later, his cough worsened, and a blood test revealed elevated eosinophil levels. Immediately afterward, swelling of the floor of the oral cavity and cervical soft tissue developed. Cellulitis was suspected and antimicrobial treatment was initiated; however, the symptoms persisted and abdominal pain developed. An endoscopic examination revealed duodenitis and a duodenal ulcer. The patient was diagnosed with eosinophilic granulomatous polyangiitis based on three items of the 2022 American College of Rheumatology/European College of Rheumatology classification criteria: obstructive airway disease, blood eosinophil count ≥1 × 109 cells/L, and extravascular eosinophilic infiltration with a score of 10. Oral prednisolone (70 mg/day), intravenous cyclophosphamide (500 mg/m2), and subcutaneous mepolizumab (300 mg every 4 weeks) were administered. The patient's symptoms improved after these treatments, and the eosinophil count and inflammatory marker levels declined. When swelling of the oral cavity floor and cervical soft tissue following an increase in eosinophilia and allergic symptoms occurs, it is crucial to consider the likelihood of eosinophilic granulomatous polyangiitis and collaborate with otolaryngologists and dentists to ensure its prompt identification.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"178-181"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"71416411","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Solitary recurrence of IgG4-related giant coronary aneurysm: Case report and review of the literature focusing on treatment strategies and complications. IgG4相关巨大冠状动脉瘤的孤立性复发：病例报告和文献综述，重点关注治疗策略和并发症。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad065

Hiroyuki Kawahara, Ichiro Mizushima, Yasushi Matsumoto, Kenji Sakata, Masayuki Takamura, Dai Inoue, Satomi Kasashima, Mitsuhiro Kawano

{"title":"Solitary recurrence of IgG4-related giant coronary aneurysm: Case report and review of the literature focusing on treatment strategies and complications.","authors":"Hiroyuki Kawahara, Ichiro Mizushima, Yasushi Matsumoto, Kenji Sakata, Masayuki Takamura, Dai Inoue, Satomi Kasashima, Mitsuhiro Kawano","doi":"10.1093/mrcr/rxad065","DOIUrl":"10.1093/mrcr/rxad065","url":null,"abstract":"Coronary periarteritis is a dangerous manifestation of IgG4-related disease, because it forms coronary artery aneurysms, which may cause sudden cardiac death. We report the case of a 78-year-old woman with IgG4-related coronary periarteritis and a coronary aneurysm, which showed progressive enlargement despite maintenance therapy for Type 1 autoimmune pancreatitis. This case was unique, in that coronary periarteritis was the only active lesion that recurred. Low-dose glucocorticoids suppressed the progression of periarterial lesions but led to rapid thinning of the aneurysmal wall and an increase in the size of mural thrombi, which pose a risk of myocardial infarction. Our systematic literature review including 98 cases of 86 articles was performed to examine its treatment strategies and complications. Among the cases in which the effect of immunosuppressive therapy could be followed radiologically, 33 of 37 (89.1%) cases showed improvement in wall thickening/periarterial soft tissue, while 6 of 13 (46.2%) showed worsening increase in the outer diameter of the coronary aneurysms. We propose a draft treatment algorithm and suggest that immunosuppressive therapy for IgG4-related coronary periarteritis with coronary aneurysms should be conducted only after the therapeutic benefit has been determined to outweigh the risks. Because coronary periarteritis can occur without other organ involvement, as in our case, all cases of IgG4-related disease require careful monitoring of coronary artery lesions.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"182-194"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"72016592","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Colchicine-resistant sacroiliitis in a Japanese patient with familial Mediterranean fever. 一名患有家族性地中海热的日本患者的秋水仙碱耐药性骶管炎。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad050

Haruki Matsumoto, Yuya Sumichika, Kenji Saito, Shuhei Yoshida, Jumpei Temmoku, Yuya Fujita, Naoki Matsuoka, Tomoyuki Asano, Shuzo Sato, Kiyoshi Migita

{"title":"Colchicine-resistant sacroiliitis in a Japanese patient with familial Mediterranean fever.","authors":"Haruki Matsumoto, Yuya Sumichika, Kenji Saito, Shuhei Yoshida, Jumpei Temmoku, Yuya Fujita, Naoki Matsuoka, Tomoyuki Asano, Shuzo Sato, Kiyoshi Migita","doi":"10.1093/mrcr/rxad050","DOIUrl":"10.1093/mrcr/rxad050","url":null,"abstract":"The articular involvement in patients with familial Mediterranean fever (FMF) represents a clinical characteristic of acute monoarthritis with pain and hydrarthrosis, which always resolves spontaneously. Colchicine prevents painful arthritis attacks in most FMF cases. Spondyloarthritis is rarely associated with Japanese patients with FMF. Here, we report a Japanese male patient with FMF-related axial joint involvement. A 43-year-old male Japanese patient who presented with recurrent febrile episodes with hip joint and back pain was referred to our hospital. He carried heterozygous variants in exon 2 (L110P/E148Q) of the MEFV gene. FMF was suspected, and oral administration of colchicine (1 mg/day) was initiated. Colchicine treatment improved his febrile attack with hip joint pain. He was diagnosed as having FMF based on the Tel-Hashomer diagnostic criteria for FMF since he fulfilled one major criterion (repeated febrile attack accompanied by hip joint pain) and one minor criterion (improvement with colchicine treatment). Although the human leucocyte antigen-B27 allele was not detected, sacroiliitis-related symptoms progressed despite the ongoing colchicine treatment. Salazosulphapyridine and methotrexate were administered in addition to colchicine; however, these treatments were not effective. Canakinumab treatment successfully resolved this unique aspect of sacroiliitis, and the patient was finally diagnosed with FMF-associated axial joint involvement.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"215-218"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"71416402","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Paediatric Cogan Syndrome masquerading as IgA vasculitis. 儿童Cogan综合征伪装成IgA血管炎。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad060

Praveen K Ramani, Florin Grigorian, Heidi Lightle, Saumya V Joshi

{"title":"Paediatric Cogan Syndrome masquerading as IgA vasculitis.","authors":"Praveen K Ramani, Florin Grigorian, Heidi Lightle, Saumya V Joshi","doi":"10.1093/mrcr/rxad060","DOIUrl":"10.1093/mrcr/rxad060","url":null,"abstract":"Paediatric Cogan Syndrome is a rare and underrecognised autoimmune vasculitis characterised by ocular inflammation and sensorineural hearing loss. Its etiopathogenesis, diagnosis, and management are not well defined. We report a 12-year-old girl who initially presented with symptoms of IgA vasculitis formerly called Henoch Schoenlein Purpura (HSP) and eventually developed anterior uveitis and bilateral sensorineural hearing loss leading to the diagnosis of atypical Cogan Syndrome. The workup for infectious etiologies and other systemic rheumatologic disorders was negative. The management was multidisciplinary involving Rheumatology, Ophthalmology, Otorhinolaryngology, and Audiology. The anterior uveitis responded well to systemic glucocorticoids and Methotrexate, but the hearing loss was grossly progressive warranting a cochlear implant. We are not aware of Paediatric Cogan Syndrome being reported as a mimicker of IgA vasculitis previously in the literature. It is an important finding as IgA vasculitis is prevalent in the paediatric age group and new-onset ocular or vestibular symptoms after IgA vasculitis should alert the clinician to the possibility of Cogan Syndrome. In the absence of well-defined diagnostic criteria, it is crucial to recognise the clinical symptoms of Paediatric Cogan Syndrome for early diagnosis and treatment since the delay in diagnosis can lead to permanent disability.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"229-236"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"71416413","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

A case of dupilumab combination therapy for exacerbation of atopic dermatitis in a patient with eosinophilic granulomatosis with polyangiitis treated with mepolizumab. 一例特应性皮炎加重，患者为嗜酸性粒细胞增多症伴多血管炎，用Mepolizumab治疗，并用Dupilumab联合治疗成功。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad059

Yosuke Iwadate, Yoshiyuki Arinuma, Yu Matsueda, Tomoki Tanaka, Tatuhiko Wada, Sumiaki Tanaka, Kenji Oku, Kunihiro Yamaoka

引用次数: 0

A case of atypical IgG4-related disease presenting hypereosinophilia, polyneuropathy, and liver dysfunction. 一例非典型IgG4相关疾病，表现为嗜酸性粒细胞增多、多发性神经病和肝功能障碍。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad053

Hiroki Mukoyama, Kosaku Murakami, Hideo Onizawa, Mirei Shirakashi, Ryosuke Hiwa, Hideaki Tsuji, Koji Kitagori, Shuji Akizuki, Ran Nakashima, Akira Onishi, Hajime Yoshifuji, Masao Tanaka, Akio Morinobu

引用次数: 0

Total knee arthroplasty for neuropathic arthropathy in a patient with leprosy. 全膝关节置换术治疗麻风患者的神经性关节病。

Modern rheumatology case reports Pub Date : 2023-12-29 DOI: 10.1093/mrcr/rxad057

Sakumo Kii, Motoki Sonohata, Masaaki Mawatari

{"title":"Total knee arthroplasty for neuropathic arthropathy in a patient with leprosy.","authors":"Sakumo Kii, Motoki Sonohata, Masaaki Mawatari","doi":"10.1093/mrcr/rxad057","DOIUrl":"10.1093/mrcr/rxad057","url":null,"abstract":"Patients with leprosy are known to tend to develop neuropathic arthropathy, known as Charcot joint. There are no case reports of total knee arthroplasty (TKA) in patients with leprosy with polyarticular neuropathic arthropathy, and the results are unknown. In this study, we report a case of TKA in a patient with leprosy with polyarticular neuropathic arthropathy and discuss its outcomes and indications. Right TKA using the NexGen Legacy Constrained Condylar Knee implant was performed in a 62-year-old man with neuropathic arthropathy in multiple joints with clinical symptoms, particularly in the right knee. Seven years post-operation, the American Knee Society Score-knee and -function, which represent knee function and activities of daily living on a scale of 100 points, were significantly improved compared with preoperative values, from 30 to 99 points and 0 to 60 points, respectively. Indications for arthroplasty for neuropathic arthropathy should be carefully considered in each individual case. In this case, the patient had neuropathic arthropathy in multiple joints; however, TKA was performed because recovery of function in the right knee was expected to significantly improve the patient's activities of daily living, and a good mid-term clinical outcome was achieved. Therefore, indications for arthroplasty should be considered in patients with systemic neuropathic arthropathy such as leprosy, and with accurate assessment and appropriate implant selection, good long-term outcomes may be expected.","PeriodicalId":94146,"journal":{"name":"Modern rheumatology case reports","volume":" ","pages":"219-223"},"PeriodicalIF":0.0,"publicationDate":"2023-12-29","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"49686817","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0