International Journal of Surgery Case Reports最新文献

{"title":"A case of gastric duplication cyst in an 18-year-old female","authors":"Osama Hroub ,&nbsp;Kareem Ibraheem ,&nbsp;Mohammad Hroub ,&nbsp;Ne’ma Manasrah ,&nbsp;Abdalrahman N. Herbawi ,&nbsp;Badawi Eltamimi","doi":"10.1016/j.ijscr.2025.111099","DOIUrl":"10.1016/j.ijscr.2025.111099","url":null,"abstract":"<div><h3>Introduction</h3><div>Gastric duplication cysts (GDCs) are rare congenital anomalies, usually diagnosed in childhood, but can occasionally present in adults with non-specific symptoms such as abdominal pain, nausea, vomiting, and dysphagia. Advanced imaging, particularly endoscopic ultrasonography (EUS), plays a crucial role in diagnosis, while surgical or endoscopic resection is the definitive treatment.</div></div><div><h3>Presentation of case</h3><div>An 18-year-old female with no significant medical history presented with recurrent epigastric pain radiating to the back, abdominal fullness, heartburn, and difficulty swallowing solid foods for one month. Upper endoscopy revealed a gastric mass, and EUS identified a 30 — 28 mm cystic lesion adjacent to the stomach fundus. Fine-needle aspiration confirmed the diagnosis of a gastric duplication cyst. The patient underwent successful endoscopic unroofing, leading to symptom resolution.</div></div><div><h3>Clinical discussion</h3><div>GDCs in adults are uncommon and often present with vague gastrointestinal symptoms, making diagnosis challenging. Imaging modalities such as EUS and fine-needle aspiration are essential for differentiation from other gastric lesions, including gastrointestinal stromal tumors and pancreatic cysts. Traditional management involved surgical resection, but endoscopic approaches, such as unroofing, offer a less invasive alternative with favorable outcomes.</div></div><div><h3>Conclusion</h3><div>This case emphasizes the need for GDCs to be considered in the differential diagnosis of gastric masses. Early identification with EUS and minimally invasive intervention, such as endoscopic unroofing, can effectively resolve symptoms and prevent complications.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111099"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143526969","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Incarcerated femoral hernia containing the ipsilateral fallopian tube without ovarian involvement: A rare case report","authors":"Hiba Ben Hassine,&nbsp;Ferdaoues Ouertani,&nbsp;Faiez Boughanmi,&nbsp;Midani Touati,&nbsp;Ibtissem Korbi,&nbsp;Faouzi Noomen","doi":"10.1016/j.ijscr.2025.111079","DOIUrl":"10.1016/j.ijscr.2025.111079","url":null,"abstract":"<div><h3>Introduction</h3><div>Femoral hernias, though less common than inguinal hernias, have a higher propensity for incarceration and strangulation, often leading to significant morbidity and mortality. They are more prevalent in women, and their clinical diagnosis remains challenging.</div></div><div><h3>Presentation of case</h3><div>This case report describes a 35-year-old woman presenting with an incarcerated right femoral hernia containing the ipsilateral fallopian tube alone, without the ovary. Emergency surgery revealed the fallopian tube within the hernia sac without ischemic changes, and repair was successfully performed using the McVay operation.</div></div><div><h3>Discussion</h3><div>Femoral hernias are rare but prone to complications like incarceration and strangulation. Isolated fallopian tube incarceration without ovarian involvement is extremely uncommon and challenging to diagnose, often requiring imaging for confirmation. Early surgical intervention, such as the McVay operation, is essential to prevent morbidity and ensure favorable outcomes.</div></div><div><h3>Conclusion</h3><div>This case highlights the importance of early diagnosis and appropriate surgical intervention in managing rare presentations of femoral hernias to prevent complications.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111079"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143527080","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Small bowel T-cell lymphoma with perforation in the HIV/AIDS context, a rare case report","authors":"Musa Machibya ,&nbsp;Bhavish Damji ,&nbsp;Shabbir Adamjee ,&nbsp;Willbroad Kyejo ,&nbsp;Aidan Njau ,&nbsp;Caroline Ngimba","doi":"10.1016/j.ijscr.2025.111087","DOIUrl":"10.1016/j.ijscr.2025.111087","url":null,"abstract":"<div><div>Introduction and Importance.</div><div>Small bowel lymphomas, which represent &lt;1 % of gastrointestinal cancers, are most found in the ileum due to its high concentration of gut-associated lymphoid tissue. T-cell lymphomas of the small bowel are particularly rare. While increased risk is noted in conditions like celiac disease and immunodeficiency, their occurrence in HIV/AIDS patients is uncommon and poorly understood. The rare complication of gastrointestinal perforation in these cases complicates diagnosis and management.</div></div><div><h3>Case presentation</h3><div>42-year-old woman with HIV/AIDS, on antiretroviral therapy for 4 years, presented with a 1-month history of progressively worsening abdominal pain, intermittent fevers, weight loss, and a productive cough. On physical examination, she was cachectic, febrile, and had generalized abdominal tenderness with signs of peritonism. Laboratory investigations revealed anemia, elevated CRP, and ESR, with a CD4 count of 441 cells/mcL. Imaging studies, including abdominal CT, showed free air and fluid suggestive of a perforated viscus. The patient underwent emergency laparotomy, which revealed multiple bowel perforations. Resection was performed, and histopathology confirmed small bowel T-cell lymphoma (anaplastic large cell lymphoma). Despite intensive postoperative care, the patient died on the fourth postoperative day.</div></div><div><h3>Clinical discussion</h3><div>Small bowel T-cell lymphoma is rare, especially in HIV/AIDS patients, and poses significant diagnostic challenges. Its presentation is often nonspecific, and perforation is a serious complication. While chemotherapy and surgery are key treatments, T-cell lymphomas are more resistant to therapy, leading to a poor prognosis, particularly when complicated by perforation.</div></div><div><h3>Conclusion</h3><div>This case highlights the rarity and complexity of small bowel T-cell lymphoma in HIV/AIDS, compounded by gastrointestinal perforation. Early diagnosis, advanced imaging, and multidisciplinary management are essential for improving outcomes. Further research is needed to optimize treatment strategies for this challenging case.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111087"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143520996","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Sigmoid volvulus revealing large bowel cancer: A case report with a literature review","authors":"Mohamed Ben Khalifa ,&nbsp;Wassim Romdhan ,&nbsp;Mossaab Ghannouchi ,&nbsp;Sabri Aouadi ,&nbsp;Mohamed Maatouk ,&nbsp;Moez Boudokhane","doi":"10.1016/j.ijscr.2025.111075","DOIUrl":"10.1016/j.ijscr.2025.111075","url":null,"abstract":"<div><h3>Introduction</h3><div>Sigmoid volvulus (SV) is the most common type of colonic volvulus. In Tunisia, it is the second leading cause of colonic obstruction. The primary predisposing factors include chronic constipation and a high, wide mesosigmoid with a narrow root. Endoscopic detorsion and surgery are the standard treatments. The association with underlying cancer is rare but significantly alters the therapeutic approach.</div></div><div><h3>Case presentation</h3><div>We present the case of a 68-year-old patient with a history of prostate hypertrophy and chronic constipation who presented with abdominal pain, biliary vomiting, and distension. Imaging revealed a sigmoid volvulus without necrosis. During laparotomy, manual counterclockwise detorsion was performed, followed by a carcinologic resection and Hartmann's procedure. The patient had an uneventful recovery and was discharged on the seventh postoperative day. Pathological findings confirmed the presence of a mucinous adenocarcinoma of the sigmoid colon.</div></div><div><h3>Discussion</h3><div>Sigmoid volvulus is the most common type of colon volvulus, accounting for 50–90 % of cases. While SV is frequently encountered, the association with underlying sigmoid cancer is rare. To our knowledge, only five cases of malignant tumors presenting with SV have been reported in the literature. Detecting this association necessitates a change in operative technique, specifically towards a carcinological resection.</div></div><div><h3>Conclusion</h3><div>Sigmoid volvulus is the most common type of colon volvulus. It is crucial for surgeons and radiologists to be aware of its potential association with underlying colon cancer. This awareness allows for adjustments in surgical technique, ultimately leading to improved postoperative outcomes.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111075"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143510310","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Multiple bile duct adenomas mimicking hepatic metastases during laparoscopic cholecystectomy - A case report","authors":"Duminda Subasinghe ,&nbsp;Jesuthasan Mithushan ,&nbsp;Anjana Abeysinghe ,&nbsp;Rachini Withanage ,&nbsp;Gayani Ranaweera","doi":"10.1016/j.ijscr.2025.111082","DOIUrl":"10.1016/j.ijscr.2025.111082","url":null,"abstract":"<div><h3>Introduction and importance</h3><div>Bile duct adenoma (BDA) is a rare benign liver neoplasm, with relatively few cases reported in literature.</div></div><div><h3>Case presentation</h3><div>A 55-year-old man diagnosed with symptomatic gallstone disease who underwent elective laparoscopic cholecystectomy. During the procedure, there were multiple liver nodules mimicking hepatic metastases. Histological examination and contrast-enhanced computed tomography (CECT) of the liver confirmed the diagnosis of BDA.</div></div><div><h3>Discussion</h3><div>When incidental liver nodules are encountered intraoperatively, thorough evaluation is essential to confirm the diagnosis. Structured approach using histological examination and imaging (CECT of the liver/ MRI) confirmed the diagnosis of BDA.</div></div><div><h3>Conclusions</h3><div>BDA is a rare benign liver neoplasm that can be challenging to differentiate from hepatocellular carcinoma or liver metastases. Accurate identification of BDA can prevent overtreatment or mismanagement.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111082"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143526970","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Acute abdominopelvic pain and distension in a 21-year-old woman revealing a mixed germ cell tumor: A case report","authors":"Dhekra Toumi ,&nbsp;Chayma Cheikh Mohamed ,&nbsp;Imen Ghaddab ,&nbsp;Amina Ben Salem ,&nbsp;Ahlem Bellalah ,&nbsp;Ahmed Hajji","doi":"10.1016/j.ijscr.2025.111063","DOIUrl":"10.1016/j.ijscr.2025.111063","url":null,"abstract":"<div><h3>Introduction and importance</h3><div>Primary ovarian germ cell tumors (OGCTs) account for 5 % of malignant pelvic neoplasms, predominantly affecting young females and often presenting as medical emergencies. Among OGCTs, malignant mixed germ cell tumors constitute approximately 8 % of cases and are characterized by their aggressive nature. Early and appropriate management of these rare tumors is crucial for optimizing patient outcomes.</div></div><div><h3>Case presentation</h3><div>We present the case of a 21-year-old female who was admitted urgently due to a large abdominopelvic mass. Clinical evaluation and supplementary investigations confirmed the diagnosis of a mixed OGCT, featuring the most common combination of yolk sac tumor and dysgerminoma. A transvaginal surgical approach was employed to preserve the patient's hymenal integrity and facilitate oocyte preservation, in accordance with her cultural and personal beliefs. The treatment consisted of unilateral adnexectomy followed by platinum-based chemotherapy.</div></div><div><h3>Clinical discussion</h3><div>Mixed OGCTs are rare but highly aggressive tumors that primarily affect young women. Despite their aggressive nature, these tumors often have a favorable prognosis when promptly diagnosed and treated. This case highlights the importance of individualized, fertility-preserving approaches in young patients. The combination of yolk sac tumor and dysgerminoma necessitated a multimodal treatment strategy to achieve optimal outcomes while respecting the patient's reproductive aspirations.</div></div><div><h3>Conclusion</h3><div>Mixed OGCTs are uncommon neoplasms that require early diagnosis and tailored management. This case is noteworthy due to the rare presentation of a mixed germ cell tumor in a young woman and the multidisciplinary approach undertaken to balance oncological management with fertility preservation, utilizing a transvaginal surgical technique to respect the patient's cultural and personal beliefs.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111063"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143528915","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"EBV-associated leiomyosarcoma in an immunocompromised child: A unique intracranial case with genomic study","authors":"Wiem Ben Makhlouf ,&nbsp;Rim Kallel ,&nbsp;Roeya Kolsi ,&nbsp;Sana Kmiha ,&nbsp;Khalil Ayadi ,&nbsp;Tahya Boudawara","doi":"10.1016/j.ijscr.2025.111073","DOIUrl":"10.1016/j.ijscr.2025.111073","url":null,"abstract":"<div><h3>Introduction and importance</h3><div>Epstein-Barr virus (EBV) is a common virus infecting more than 90 % of the adult population, typically without symptoms. While most infections remain asymptomatic, EBV is associated with over 200,000 new cancer cases annually. It is linked to several malignancies, including leiomyosarcoma (LS) in immunocompromised patients, a rare occurrence with fewer than 100 new cases per year globally. This report highlights the case of an EBV-associated intracranial leiomyosarcoma in a 4-year-old immunodeficient child.</div></div><div><h3>Case presentation</h3><div>A 4-year-old girl with a history of primary immune deficiency and multiple infections presented with febrile dyspnea. Imaging revealed a right temporo-parietal brain mass, which increased in size over 50 days. Surgical excision was performed, and histological examination showed a tumor with smooth muscle cell characteristics. Immunohistochemical analysis was positive for vimentin and CD99, while EBV genome presence was confirmed by in situ hybridization. The final diagnosis was EBV-associated malignant smooth muscle tumor. The postoperative course was favorable, and chemotherapy was not indicated.</div></div><div><h3>Clinical discussion</h3><div>Leiomyosarcoma is extremely rare in immunocompetent children but more common in immunocompromised individuals, where EBV infection plays a significant role in tumor development. Although EBV-related leiomyosarcomas occur more frequently in immunodeficient children, intracranial cases are exceptionally rare. These tumors are often challenging to diagnose due to their undifferentiated appearance. The detection of EBV DNA using in situ hybridization is crucial for confirming the diagnosis. While EBV-associated leiomyosarcomas generally respond well to therapy, the optimal treatment remains unclear, with surgery and radiotherapy being the primary approaches.</div></div><div><h3>Conclusion</h3><div>EBV-associated smooth muscle tumors are rare but increasing in incidence among immunocompromised patients. Early recognition of EBV infection in smooth muscle tumors, especially in children with immune deficiencies, is vital for diagnosis. Histological and molecular examination, including in situ hybridization, is essential to confirm the presence of EBV. Treatment typically involves complete surgical excision, with chemotherapy's role still uncertain.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111073"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143527081","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Primary CALVARIAL tuberculosis: A case report","authors":"Abdulsemed Mohammed Yasin,&nbsp;Eyob Zenebe,&nbsp;Kibruyisfaw Zewude,&nbsp;Dagnachew Tamrat Belete,&nbsp;Betelhem Gebreamlak","doi":"10.1016/j.ijscr.2025.111084","DOIUrl":"10.1016/j.ijscr.2025.111084","url":null,"abstract":"<div><h3>Introduction</h3><div>Calvarial tuberculosis is a rare manifestation of extra pulmonary tuberculosis. Primary calvarial tuberculosis, with no evidence of tuberculosis elsewhere in the body, is an even rarer entity. Most cases are often misdiagnosed as osteomyelitis, syphilis, or bony metastasis among others.</div></div><div><h3>Case Presentation</h3><div>We report a case of primary calvarial tuberculosis in a 17 years old female with complaints of progressively increasing swelling over the right frontoparietal region and headache with no history of previous tuberculosis. The patient was operated, and histopathological examination of excised tissue was suggestive of tubercular pathology. The patient is doing well after surgery and anti-tubercular therapy.</div></div><div><h3>Discussion</h3><div>Skeletal tuberculosis occurs in approximately 1 % of cases of mycobacterial infection, and calvarial tuberculosis accounts for 0.2 % to 1.3 % of all cases of skeletal tuberculosis. Early clinical signs are usually absent. The emergence of a painless, fluctuant swelling stands out as the most common presentation. Radiological findings, which are very valuable tools to reach a diagnosis, are known to be variable and nonspecific. The gold standard for diagnosis is the demonstration of Acid Fast Bacilli (AFB) on microscopy and growth on culture. Treatment includes surgery and antituberculous therapy.</div></div><div><h3>Conclusion</h3><div>Primary calvarial tuberculosis is a rare entity that can present with diverse symptoms and mimic other pathologies. A high index of suspicion should be maintained, especially in endemic areas, to ensure timely and accurate diagnosis. Surgery and antituberculous therapy remain the treatment of choice. Follow up is crucial to monitor for recurrence and other associated complications.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111084"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143527079","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Aggressive vascularized odontogenic myxoma. Case report and literature review","authors":"Luis Pacheco-Ojeda ,&nbsp;Miriam Díaz-Yépez ,&nbsp;Germán Castillo-Aguirre ,&nbsp;Luis Mogrovejo-Freire ,&nbsp;Stalin Cañizares-Quisiguiña","doi":"10.1016/j.ijscr.2025.111060","DOIUrl":"10.1016/j.ijscr.2025.111060","url":null,"abstract":"<div><h3>Introduction and importance</h3><div>Odontogenic myxoma (OM) is an infrequent benign mesenchymal odontogenic tumor of the jaws composed of rounded and angular cells dispersed in an abundant mucoid stroma. An aggressive and vascularized presentation is unusual.</div></div><div><h3>Case presentation</h3><div>A 68-year-old woman was evaluated for a mass located under the palate and extended to the cheek. A large flattened mass covered the entire palate, except the left lateral dental arch, and extended to the cheek as a firmed 6 × 6 × 5 cm mass. An enhancement computed tomography and a magnetic resonance imaging revealed a large, heterogenous, expansive, 80 × 64 × 58 mm mass that destroyed the right maxilla and extended to the soft tissues of the cheek. Minimally invasive endovascular angiography and embolization was performed preoperatively. Through a modified Weber-Ferguson incision, a partial right lateral maxillectomy was performed, conserving the right nasal fossa and a left canine tooth, medially, and the floor of the orbit, upward. Pathology study reported an odontogenic myxoma with compromised margins but reexcision margins were negative. One year after surgery, there is no evidence of disease.</div></div><div><h3>Clinical discussion</h3><div>Pathological and radiological differential diagnosis that includes a large number of benign and malignant lesions are discussed. All authors agree that wide surgical excision is the treatment of choice.</div></div><div><h3>Conclusions</h3><div>Wide excision resulted in good functional and local control. Preoperative embolization is needed in case of a vascularized lesion. No immediate surgical reconstruction should be recommended to facilitate clinical surveillance and early recurrence detection.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111060"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143510311","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Inflammatory myofibroblastic tumor of the adrenal gland: A case report","authors":"Ghada Sahraoui ,&nbsp;Sirine Elfekih ,&nbsp;Imen Sassi ,&nbsp;Lamia Charfi ,&nbsp;Karima Mrad","doi":"10.1016/j.ijscr.2025.111054","DOIUrl":"10.1016/j.ijscr.2025.111054","url":null,"abstract":"<div><h3>Introduction and importance</h3><div>Inflammatory myofibroblastic tumor (IMT) is an extremely rare sarcoma mainly reported in the lung. The adrenal gland, however, is an extremely rare site of occurrence. Herein, we report a case of a large adrenal mass with no contributory imaging features presenting a challenging pathological diagnosis.</div></div><div><h3>Case presentation</h3><div>A healthy 32-year-old male patient, with no personal nor family history, presented with loss of body weight and condition developing for two months. Physical examination revealed no abnormalities with a soft and depressible abdomen and absence of palpable lump. Circulating Chromogranin A and catecholamine metabolites were within normal range. The preoperative imaging features were noncontributory. The pathological examination on biopsy specimen concluded to a spindle cell proliferation set in a chronically inflamed background suggesting the diagnosis of IMT. The patient, subsequently, underwent radical nephrectomy unveiling a 25 cm adrenal mass. Pathological findings on resection specimen confirmed the diagnosis of IMT of the left adrenal gland.</div></div><div><h3>Clinical discussion</h3><div>Due to their rarity in the adrenal gland and their noncontributory radiological features, IMTs are typically not considered as a potential diagnosis in this location. As a result, this condition is often underdiagnosed. In this setting, suspicion for IMT should be raised when spindle cell histology is observed.</div></div><div><h3>Conclusion</h3><div>It is fundamental for practicians to keep this entity in mind as the treatment consists of complete tumor extirpation. The latter being the only guarantee of recurrence free follow up.</div></div>","PeriodicalId":48113,"journal":{"name":"International Journal of Surgery Case Reports","volume":"128 ","pages":"Article 111054"},"PeriodicalIF":0.6,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143510307","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}