Journal of Pediatric Surgery Case Reports最新文献

{"title":"Omphalocele and patent omphalomesenteric duct: A case report","authors":"Wassie Almaw Yigzaw,&nbsp;Abebe Tsegaye Danole,&nbsp;Abay Gosaye Wondimu","doi":"10.1016/j.epsc.2025.102988","DOIUrl":"10.1016/j.epsc.2025.102988","url":null,"abstract":"<div><h3>Introduction</h3><div>The omphalomesenteric duct (OMD) is an embryonic structure that connects the yolk sac to the midgut. Under normal circumstances, it closes and self absorbes before birth. When the OMD does not obliterate, it remains patent after birth. Patent OMD are hardly ever associated with other congenital anomalies.</div></div><div><h3>Case presentation</h3><div>A 1-day-old term male neonate was referred to our hospital with a postnatal diagnosis of omphalocele minor. The omphalocele had not been seen on any of the prenatal ultrasounds. He was born by vaginal delivery with a weight of 2700 g. In addition to the omphalocele, the physical exam revealed a mucosal opening on the membrane of the omphalocele. A patent OMD was suspected, since meconium was draining through the mucosal opening. Abdominopelvic ultrasound showed bowel loops within the omphalocele sac. All other intra-abdominal organs appeared normal. Echocardiography revealed tricuspid atresia and a large ventricular septal defect. On the second day of life the patient was taken to the operating room for an exploratory laparotomy. The abdomen was accessed through an incision on the junction between the skin and the membrane of the omphalocele. The bowel was detached bluntly from the inner surface of the omphalocele membrane. While the bowel was exposed, a Meckel's diverticulum was found close to the ileo-cecal valve. The tip of the Meckel's diverticulum was open and fused wo the membrane of the omphalocele. We resected the segment of the small bowel that contained the Meckel's diverticulum and did an end-to-end anastomosis. After that, the omphalocele defect was closed. The patient died on the second postoperative day from his congenital heart disease.</div></div><div><h3>Conclusion</h3><div>Patent OMD should be suspected in patients with omphalocele who have a mucosal opening on the omphalocele membrane that drains meconium.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102988"},"PeriodicalIF":0.2,"publicationDate":"2025-03-18","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143684585","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Meckel's diverticulum causing massive lower intestinal bleeding in a teenager: A case report","authors":"Abate Bane Shewaye ,&nbsp;Mohan Ramchandani ,&nbsp;Kaleb Assefa Berhane ,&nbsp;Dawit Taye Endalew ,&nbsp;Asteraye Tsige Minyilshewa ,&nbsp;Tamrat Petros Elias","doi":"10.1016/j.epsc.2025.102986","DOIUrl":"10.1016/j.epsc.2025.102986","url":null,"abstract":"<div><h3>Introduction</h3><div>Meckel's diverticulum (MD), the most common congenital gastrointestinal (GI) abnormality, results from incomplete obliteration of the vitelline duct and is often asymptomatic. Its diagnosis can be challenging in older patients due to nonspecific symptoms and reduced sensitivity of Technetium-99m pertechnetate scans.</div></div><div><h3>Case presentation</h3><div>A 15-year-old male presented with a 4-day history of hematochezia, vomiting, and symptoms of anemia. Upon admission, he experienced a massive lower GI bleed (∼2 L), leading to hemodynamic instability, which improved after resuscitation. Laboratory tests revealed hemoglobin (Hb) of 7.7 g/dL, international normalized ratio (INR) of 1.5, and platelet (PLT) count of 131,000/μL. Initial imaging, including esophagogastroduodenoscopy (EGD), colonoscopy, and contrast-enhanced abdominal computed tomography (CT), failed to identify the bleeding source. A subsequent Meckel's scan was also negative. However, CT angiography revealed a diverticular structure with edematous, enhancing walls, consistent with MD. Laparoscopic resection of the diverticulum, located 50 cm from the ileocecal junction, was performed with a stapled side-to-side anastomosis. Histopathology confirmed MD with ectopic gastric mucosa. The patient recovered well, was discharged on postoperative day two, and remained asymptomatic at follow-up.</div></div><div><h3>Conclusions</h3><div>MD must be suspected as a source of lower gastrointestinal bleeding in teenagers, even in cases with a negative Meckel's scan.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102986"},"PeriodicalIF":0.2,"publicationDate":"2025-03-17","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143654621","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Pneumatosis cystoides intestinalis as a pathologic lead point of an ileocolic intussusception: A case report","authors":"Teren W.A. Culbertson ,&nbsp;David P. Bliss Jr.","doi":"10.1016/j.epsc.2025.102984","DOIUrl":"10.1016/j.epsc.2025.102984","url":null,"abstract":"<div><h3>Introduction</h3><div>Ileocolic intussusception is an acute intestinal obstruction that requires prompt diagnosis and treatment. This case presents a rare pathologic lead point for ileocolic intussusception.</div></div><div><h3>Case presentation</h3><div>A nine-year-old female with a history of functional abdominal pain and constipation presented to the emergency department with acute abdominal pain, bilious emesis and one episode of non-bloody diarrhea. Abdominal x-rays were concerning for a bowel obstruction and an abdominal ultrasound showed an intussusception of unclear location. Subsequent abdominal/pelvic computerized tomography scan identified an ileocolic intussusception with pneumatosis cystoides intestinalis (PCI) acting as a pathologic lead point. The patient underwent two air enema reduction procedures that were deemed to be incomplete. As a result, a diagnostic laparoscopy was performed, which confirmed PCI and identified a previously reduced ileocolic intussusception. Post-operatively, she completed a seven-day course of oral metronidazole and had an unmarkable recovery. At a three-week follow-up visit, persistent PCI was present on abdominal radiographs, which resolved after an additional 14-day course of metronidazole. Further outpatient evaluation revealed no other potential lead points other than that of the known PCI.</div></div><div><h3>Conclusion</h3><div>This case highlights the rare occurrence of pneumatosis cystoides intestinalis acting as a pathologic lead point for ileocolic intussusception in a pediatric patient. Ileocolic intussusception should be considered a potential complication for young patients with PCI.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102984"},"PeriodicalIF":0.2,"publicationDate":"2025-03-15","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143684584","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Acquired intestinal atresia secondary to postoperative adhesions in a 7-month-infant: A case report","authors":"Jongmin Han ,&nbsp;Ayoung Kang ,&nbsp;Soo-Hong Kim ,&nbsp;Hae-Young Kim","doi":"10.1016/j.epsc.2025.102985","DOIUrl":"10.1016/j.epsc.2025.102985","url":null,"abstract":"<div><h3>Introduction</h3><div>Acquired intestinal atresia is a very rare condition defined as complete luminal occlusion and absence of a previously patent section of the bowel. Most reported cases are related to strictures after necrotizing enterocolitis, whereas cases related to other conditions are extremely rare.</div></div><div><h3>Case presentations</h3><div>A 7-month-old girl presented with bilious vomiting and abdominal distension for 1 day. She was born at 24 weeks of gestation with a weight of 640 g. At 18 days of life, she underwent a small bowel segmental resection and end ileostomy for spontaneous small bowel perforation. After 60 days, the ileostomy was closed. Abdominal radiography revealed small bowel dilatation and abdominal computed tomography revealed dilated proximal small bowel loops and collapsed distal small bowel loops. A small bowel obstruction secondary to adhesive bands was suspected. The obstruction did not improve after conservative management for 4 days, which included nil per os and decompression via nasogastric tube, so the patient was taken to the operating room for a surgical exploration. The site of the obstruction was completely atretic due to compression from an adhesive band. there was also a V-shaped mesenteric defect under the site of the atresia. We resected the atretic segment and did an end-to-end anastomosis. She was discharged 7 days after the operation without complications. One year later, she was seen in the outpatient clinic and was growing normally without any digestive issues.</div></div><div><h3>Conclusion</h3><div>Acquired intestinal atresia should be included in the differential diagnosis of infants who had previous abdominal operations and present with an intestinal obstruction.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102985"},"PeriodicalIF":0.2,"publicationDate":"2025-03-14","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143654622","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Intraoperative diagnosis of rare pediatric internal hernias: A case series","authors":"Spencer E. Kim ,&nbsp;William R. Johnston ,&nbsp;Rosa Hwang ,&nbsp;Gary W. Nace","doi":"10.1016/j.epsc.2025.102983","DOIUrl":"10.1016/j.epsc.2025.102983","url":null,"abstract":"<div><h3>Introduction</h3><div>Internal hernias are a rare but serious condition in pediatric patients. Even with a thorough preoperative imaging workup, distinguishing them from other causes of bowel obstruction is challenging. This case series presents three patients with internal hernias of varying etiologies and complexity that were not diagnosed until intraoperative exploration.</div></div><div><h3>Case series</h3><div>Case 1 is a previously healthy 11-year-old boy with new-onset abdominal pain and emesis who was found to have a strangulated segment of small bowel herniated through a small congenital mesenteric defect. Case 2 is a 3-year-old boy with constipation presenting with acute-on-chronic abdominal pain. He was found to have a hernia sac formed from an abnormal attachment of omentum to the retroperitoneum, which contained segments of small and large bowel. Case 3 is a 23-year-old female with ataxia-telangiectasia-like syndrome and dystonia with a gastrostomy tube who presented with emesis and reflux. Surgical exploration revealed a highly unusual internal hernia through the hepatoduodenal and transverse mesocolon, through which the entire small bowel and majority of the transverse colon were herniated. None of these internal hernias were diagnosed with preoperative imaging. All patients underwent successful internal hernia repair with resolution of abdominal symptoms and have not required additional surgical workup.</div></div><div><h3>Conclusion</h3><div>Frequently, the diagnosis of an internal hernia is difficult to define preoperatively and is only made at the time of surgical exploration. Although internal hernias are rare, they should remain on the differential in pediatric and young adult patients presenting with signs of acute and/or chronic bowel obstruction.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102983"},"PeriodicalIF":0.2,"publicationDate":"2025-03-13","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143684586","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Povidone-iodine pleurodesis for congenital chylothorax in an infant: A case report","authors":"Citra Cesilia ,&nbsp;Riky Candra ,&nbsp;Hariadi Hatta ,&nbsp;Nurhasanah ,&nbsp;Muhammad Afdhal ,&nbsp;Mutiara Arcan","doi":"10.1016/j.epsc.2025.102982","DOIUrl":"10.1016/j.epsc.2025.102982","url":null,"abstract":"<div><h3>Introduction</h3><div>Chylothorax in infants can be classified into five types: congenital, traumatic, postoperative, embolic, and spontaneous, the last one being the most common one. Its etiology is not fully understood, it has a relatively high mortality rate, and there are no standardized guidelines regarding its treatment.</div></div><div><h3>Case presentation</h3><div>A I-month-old infant presented with worsening shortness of breath, without fever or any signs of an airway infection. A chest X-ray revealed a large right pleural effusion causing mediastinal shift. The fluid was drained with a 7Fr central venous catheter placed in the right pleural cavity and left as a chest tube. The fluid that was drained had a milky appearance, suggestive of chylothorax. Fluid analysis confirmed elevated triglycerides. The patient was initially managed with total parenteral nutrition (TPN). The chest tube drained several hundred milliliters per day. On the fifth day of hospitalisation, we initiated a plan of chemical pleurodesis using a combination of 2 mL of povidone-iodine, 2 mL of lidocaine, and 8 mL of normal saline, administered through the chest drain. The chest tube was clamped and the patient rotated frequently. The chest tube was clamped for about an hour and undamped thereafter. The procedure was repeated every other day, the last one being on the twelfth day of hospitalisation. The output of the chest tube decreased rapidly, and the chest tube was removed on the fifteenth day of hospitalisation. The patient was discharged after seventeen days of hospitalisation with near complete resolution of the chylothorax.</div></div><div><h3>Conclusion</h3><div>Chemical pleurodesis with povidone-iodine seems to be an effective management option for infants with congenital chylothorax.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102982"},"PeriodicalIF":0.2,"publicationDate":"2025-03-12","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143619308","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Fibrous hamartoma of infancy associated to hyperhidrosis: A case report","authors":"Bianca Aceto,&nbsp;Daniele Di Meglio,&nbsp;Giuliana Di Martino,&nbsp;Maria Capasso,&nbsp;Maria Giovanna Grella,&nbsp;Pietro Pirisi","doi":"10.1016/j.epsc.2025.102981","DOIUrl":"10.1016/j.epsc.2025.102981","url":null,"abstract":"<div><h3>Introduction</h3><div>Fibrous hamartoma of infancy (FHI) is a rare benign soft tissue tumor, and its association with local hyperhidrosis has only been reported anecdotally.</div></div><div><h3>Case presentation</h3><div>A 1-year-old healthy girl presented with a mass localized in the sacrococcygeal region associated to hypertrichosis and skin discoloration, non-tender on palpation. Ultrasound (U/S) revealed a predominantly hypoechogenic 42 × 14 mm lesion with hyperechogenic tissue. A magnetic resonance imaging (MRI) revealed a 7.4× 4.4 cm superficial soft tissue lesion with heterogeneous contrast enhancement involving the subcutaneous and cutaneous layers, extending to the underlying muscular fascia. The patient first underwent an incisional biopsy. Microscopic examination revealed the characteristic triphasic lesion, consistent with the morphological and immunophenotypic features of FHI. We followed the lesion clinically and with interval U/S and MRI. The lesion gradually increased in size, being approximately 8.6 × 10 cm by MRI one year after the diagnosis. At that time, it was accompanied by profuse hyperhidrosis of the overlying skin, which caused distress on the parents and caretakers. A complete surgical excision was then performed. She recovered well from the operation and at 11 months of follow up has no signs of recurrence.</div></div><div><h3>Conclusion</h3><div>Although rare, FHI can be associated with localized profuse hyperhidrosis. Complete surgical excision, if possible, should be considered in cases of debilitating hyperhidrosis.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102981"},"PeriodicalIF":0.2,"publicationDate":"2025-03-11","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143628532","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Type IV sacrococcygeal teratoma with intraspinal extension treated surgically through an anterior-posterior-anterior approach: A case report","authors":"Mouna Zaghedane ,&nbsp;Vladimir Gomola ,&nbsp;Jean-louis Lemelle ,&nbsp;Anthony Joud","doi":"10.1016/j.epsc.2024.102888","DOIUrl":"10.1016/j.epsc.2024.102888","url":null,"abstract":"<div><h3>Introduction</h3><div>Sacrococcygeal teratomas with intraspinal involvement are rare. To our knowledge, there is only one reported case specifically of a type-IV sacrococcygeal teratoma with intraspinal extension.</div></div><div><h3>Case presentation</h3><div>A 1-day-old female prenatally diagnosed with a type-IV sacrococcygeal teratoma by ultrasound at 37 weeks of gestation was delivered vaginally without complications at 38 weeks and 1 day. Her weight was 3580 g. Physical examination revealed no visible or palpable tumors and no skin abnormalities. The neurological assessment was normal. The patient voided spontaneously and had a spontaneous bowel movement. Postnatal computed tomography (CT) showed a cystic mass in the pelvis with a maximum diameter of 9 cm, compressing the vagina and uterus, which resulted in hydrocolpos. The mass extended through a widened sacral canal up to the S-1 level. The nature of the connection between the mass and the thecal sac and intradural neural elements was not clear. The serum alpha-fetoprotein (AFP) level was 29,448 ng/ml, which is considered normal for the patient’s age. After a multidisciplinary discussion the decision was made to proceed with a combined surgical resection. In supine position and through a laparotomy, the pelvic component was completely freed from all surrounding structures. The patient was then placed in prone position, and through a sacral laminectomy up to L5 we removed the intra-sacral extension of the cystic mass. The thecal sac remained intact. The last segment of the sacrum and the coccyx were excised. The tumor was removed with en-bloc. Last, she was placed again in supine position for the closure of the abdominal incision. She recovered well from the operation. At 12-months of follow-up her development is appropriate for age, and she has no neurological deficits.</div></div><div><h3>Conclusion</h3><div>A combined anterior-posterior-anterior surgical approach is a suitable strategy for the complete resection of type-IV SCTs that have an intraspinal extension.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"114 ","pages":"Article 102888"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143510163","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"Strong procedure with added anchoring stitches from the jejunum to the abdominal wall for Superior Mesenteric Artery Syndrome in children: A case report","authors":"Abdulaziz Abdulrahman AlQahtani,&nbsp;Rula Sallout,&nbsp;Walid Tareef,&nbsp;Majid Alkhamis","doi":"10.1016/j.epsc.2025.102977","DOIUrl":"10.1016/j.epsc.2025.102977","url":null,"abstract":"<div><h3>Introduction</h3><div>Sanjad-Sakati Syndrome (SSS) is a rare autosomal recessive disorder primarily observed in the Middle East. Superior mesenteric artery syndrome (SMAS) is also a rare gastrointestinal condition that mainly occurs in individuals who experience rapid weight loss and/or have a very low body mass index (BMI). The occurrence of these conditions together is extremely rare.</div></div><div><h3>Case presentation</h3><div>An 8-year-old girl with SSS was admitted to the hospital with flu-like symptoms, shortness of breath, and reduced oral intake over the previous two days. Her medical history included a recent right lobar pneumonia and recurrent vomiting. She was admitted with a diagnosis of recurrent pneumonia and received intravenous antibiotics. We placed a nasogastric tube, which drained bilious fluid. She underwent a plain abdominal film, an upper gastrointestinal study, and a computerized tomography (CT) scan which revealed that she had SMAS. She was started on conservative management, which included parenteral nutrition, metoclopramide, and small volume of enteral feedings. After four weeks without any improvement, we decided to proceed with a modified Strong operation. The modification involved anchoring the first segment of the jejunum to the abdominal wall of the right upper quadrant using two stitches of absorbable material, with the goal of minimizing the chance of a recurrence by preventing the jejunum from slipping back to its normal anatomical position. She tolerated the operation well. After an uneventful recovery, oral feedings were gradually introduced and increased until she reached full volume by postoperative day 12, She was discharged home one day later. She was followed for nine months and to date she has shown adequate weight gain.</div></div><div><h3>Conclusion</h3><div>Even though the association is remarkably rare, patients with SSS who had failure to thrive should undergo testing to rule out SMAS. If SMAS is confirmed and conservative measures are not successful, the modified Strong procedure appears to be a safe and effective surgical option.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102977"},"PeriodicalIF":0.2,"publicationDate":"2025-02-24","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143592325","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

{"title":"High rectal atresia anastomosed using magnets: A case report","authors":"Athanasios Tyraskis ,&nbsp;Piero Alberti ,&nbsp;Anthony Lander ,&nbsp;Shailesh Patel ,&nbsp;Niyi Ade-Ajayi","doi":"10.1016/j.epsc.2025.102978","DOIUrl":"10.1016/j.epsc.2025.102978","url":null,"abstract":"<div><h3>Introduction</h3><div>Surgical access to anorectal malformations (ARM) can be difficult from abdominal, perineal and transanal approaches. We present a case in which magnetic compression anastomosis was successfully employed to achieve a minimally invasive repair of high rectal atresia in a neonate.</div></div><div><h3>Case presentation</h3><div>A female neonate born at 38 weeks and 5 days with no significant antenatal history and failure to pass meconium in the first 48 hours after birth developed abdominal distension and bilious vomiting on the third day of life. The patient was found on clinical examination and contrast enema to have rectal atresia just below the peritoneal reflection. A diverting colostomy was fashioned on day four of life. A distal colostogram at two months of age confirmed the diagnosis of high rectal atresia with minimal separation between the atretic ends. Magnetic compression anastomosis by insertion of a pair of magnets through the anus and mucous fistula was attempted to obviate the need for invasive surgery. Following a failed first attempt at the age of 11 months, a second attempt performed at the age of 15 months under endoscopic and fluoroscopic guidance successfully established luminal continuity. The colostomy was closed at the age of 16 months following a single topical application of mitomycin C. The patient recovered well and has excellent anorectal function three years postoperatively.</div></div><div><h3>Conclusion</h3><div>Selected cases of rectal atresia may be treated by magnamosis. Fluoroscopic and endoscopic guidance may be required to ensure appropriate positioning of the magnets.</div></div>","PeriodicalId":45641,"journal":{"name":"Journal of Pediatric Surgery Case Reports","volume":"116 ","pages":"Article 102978"},"PeriodicalIF":0.2,"publicationDate":"2025-02-24","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143507945","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}