Grégory Schürmann , Benedikta Kamdem , Michael Liu , Vincent Dunet , Mercy George
{"title":"\"The first case report of acute cochleovestibular deficit caused by labyrinthine hemorrhage in a patient with Ehlers-Danlos syndrome after temporomandibular joint arthrocentesis\"","authors":"Grégory Schürmann , Benedikta Kamdem , Michael Liu , Vincent Dunet , Mercy George","doi":"10.1016/j.xocr.2024.100643","DOIUrl":"10.1016/j.xocr.2024.100643","url":null,"abstract":"<div><h3>Objective</h3><div>This article aims to present a unique case of labyrinthine hemorrhage in a patient with Ehlers-Danlos syndrome following arthrocentesis of the temporomandibular joint (TMJ), and to review the labyrinthin hemrrohage as cause of cochleovestibular loss.</div></div><div><h3>Patient</h3><div>We report a unique case of intra-labyrinthine hemorrhage (ILH) in a 42-year-old patient with Ehlers-Danlos syndrome after bilateral arthrocentesis of the temporomandibular joint (TMJ). <u>Intervention</u>: Imagery with CT scan, MRI FLAIR sequence, vestibular and audiogram at beginning and 6 month. <u>Outcome</u>: Review of literature of labyrinth hemorrhage as cause of cochleovestibular deficit, the management and prognosis.</div></div><div><h3>Results</h3><div>labyrinth hemorrhage is a rare cause of cochleovestibular deficit, with profound hearing loss and poor recovery.</div></div><div><h3>Conclusion</h3><div>This is the first reported case of acute cochleovestibular deficit because of labyrinthine hemorrhage in an Ehlers-Danlos patient following TMJ arthrocentesis. Labyrinthine hemorrhage is a rare cause of inner ear deficit that has to be ruled out in patients with risk factors by an MRI. The prognosis is usually poor with the need for a hearing aid, and a hematological work-up should be done.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100643"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183340","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Jessica R. Weinberg , Alexander N. Goel , Krishna Gurram , Diana N. Kirke
{"title":"An interdisciplinary approach to the endoscopic removal of a metallic nail from the esophagus of an infant","authors":"Jessica R. Weinberg , Alexander N. Goel , Krishna Gurram , Diana N. Kirke","doi":"10.1016/j.xocr.2025.100655","DOIUrl":"10.1016/j.xocr.2025.100655","url":null,"abstract":"<div><h3>Objective</h3><div>Exemplifying the value of an interdisciplinary approach between Otolaryngology and Gastroenterology in achieving safe removal of sharp foreign bodies from the upper aerodigestive tract.</div></div><div><h3>Methods</h3><div>Case report with imaging.</div></div><div><h3>Results</h3><div>We report the case of a 13-month-old boy who presented to the ER one day after ingestion of a metallic nail which was impacted in his cervical esophagus. Rigid esophagoscopy identified a curved metallic nail with one end easily visualized, and the other embedded in the esophageal wall. Significant resistance was met when using standard rigid endoscopic instruments to extract the object. It was only after insufflation was utilized from a flexible endoscope that the object was safely extracted, thus highlighting the need for a two team approach.</div></div><div><h3>Conclusion</h3><div>In such cases where the shape and orientation of an object hinder removal, a multidisciplinary approach, in this case with our gastroenterology colleagues, can help to avoid injury to surrounding structures and/or mitigate the need for open surgical removal in the pediatric patient.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100655"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183344","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Shuyue Guo, Lue Zhang, Quanming Zhang, Nan Zeng, Shuo Li, Yaqin Zhao, Mingxing Tang, Qiong Yang
{"title":"Treatment of tympanic paraganglioma by underwater endoscopic transcanal coblation: A case report and literature review","authors":"Shuyue Guo, Lue Zhang, Quanming Zhang, Nan Zeng, Shuo Li, Yaqin Zhao, Mingxing Tang, Qiong Yang","doi":"10.1016/j.xocr.2024.100650","DOIUrl":"10.1016/j.xocr.2024.100650","url":null,"abstract":"<div><div>Tympanic paraganglioma (TP) is a type of rare and benign tumor that is mostly confined within the tympanic cavity. As it is rich in vascular vessels, it is a great challenge to control haemorrhage during the conventional microscopic surgery. Here we report the case of a 59-year-old female patient who was diagnosed with TP after several tests. The patient underwent a surgical treatment by underwater endoscopic transcanal coblation excision of TP. Follow-up examinations revealed that the hearing of the affected ear rapidly restored to normal level post the operation, and no residual TP inside the tympanic chamber. Compared to the conventional microscopic surgery program, the otoendoscopy provided surgeons with a wider and clearer field of view, and the plasma knife enabled more space for operation. This report thus proved that the underwater endoscopic transcanal coblation is a safe and effective surgical method for resection of TP, and it is worth advocating in the future clinical practice.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100650"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183333","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Tjerk W. Aukema , Wilma J. van Veen , Annemieke M. Boot , Ann-Louise McDermott , Myrthe K.S. Hol
{"title":"“Spinning” bone-anchored hearing implantation in a 5-year old child: A case report","authors":"Tjerk W. Aukema , Wilma J. van Veen , Annemieke M. Boot , Ann-Louise McDermott , Myrthe K.S. Hol","doi":"10.1016/j.xocr.2025.100656","DOIUrl":"10.1016/j.xocr.2025.100656","url":null,"abstract":"<div><div>This case report highlights the occurrence of “spinners” during the first stage percutaneous bone conduction device implantation in a 5-year-old boy with congenital bilateral microtia and atresia. Due to skull thinness (<2mm), both primary and sleeper fixtures spun during insertion, necessitating a prolonged osseointegration period. Despite underweight status, firm osseointegration was achieved, and the patient exhibited improved speech and language development post-implantation. This report emphasizes the importance of awareness among otologists regarding spinning fixtures, particularly in underweight children, recommending a two-stage surgery approach and lower insertion torque to ensure successful osseointegration and device functionality.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100656"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143331117","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"A case of refractory dizziness effectively treated with the addition of aripiprazole to antidepressant therapy","authors":"Fumiyuki Goto, Shouji Kaneda, Koichiro Wasano, Kenji Okami","doi":"10.1016/j.xocr.2025.100657","DOIUrl":"10.1016/j.xocr.2025.100657","url":null,"abstract":"<div><h3>Objective</h3><div>To report a case of refractory dizziness associated with persistent postural-perceptual dizziness (PPPD) effectively treated with adjunctive aripiprazole.</div></div><div><h3>Methods</h3><div>A 41-year-old male presented with three months of persistent dizziness and aural fullness unresponsive to standard treatments for Ménière's disease. Comprehensive evaluations, including audiometry, vestibular function tests, and stabilometry, were normal. Based on clinical criteria, PPPD with comorbid anxiety and depression was diagnosed. Initial treatment with vortioxetine and clonazepam showed no improvement. Subsequently, aripiprazole was introduced.</div></div><div><h3>Results</h3><div>Subjective dizziness improved significantly within two weeks of adding aripiprazole (1.5 mg/day). Upon increasing the dose to 3 mg/day, Dizziness Handicap Inventory scores improved from 58 to 18, and psychological symptoms showed marked relief. However, stabilometric parameters remained unchanged.</div></div><div><h3>Conclusion</h3><div>Aripiprazole demonstrated efficacy in managing refractory dizziness by addressing comorbid psychological factors, underscoring the importance of neuropsychiatric approaches in PPPD management.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100657"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183346","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Endoscopic management of stapes fixation due to stapedial tendon calcification","authors":"David C. Gribble , Michael S. Cohen","doi":"10.1016/j.xocr.2024.100651","DOIUrl":"10.1016/j.xocr.2024.100651","url":null,"abstract":"<div><div>We present a unique case of a patient with conductive hearing loss who was found to have stapes fixation due to calcification of the stapedial tendon in the setting of longstanding chronic otitis media, tympanosclerosis, and tympanic membrane perforation. Endoscopic tympanoplasty was performed with lysis of the calcified stapedial tendon resulting in mobilization of the stapes and significant improvement in conductive hearing loss. This case report describes the presentation, management, and surgical techniques utilized in this case.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100651"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183334","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"An unusual presentation of Madelung's disease in a Hispanic 49-year-old male with pruritus","authors":"Nicole Johnsen , Shannon Nesbit , Qiang Zhang , Pranati Pillutla , Travis Shiba","doi":"10.1016/j.xocr.2024.100649","DOIUrl":"10.1016/j.xocr.2024.100649","url":null,"abstract":"<div><div>A 49-year-old Hispanic male presented with a 3-month history of mildly pruritic, bilateral nodules on the suboccipital neck. Examination revealed bilateral suboccipital nodules measuring 3 × 5 cm, alongside additional bilateral nodules in the preauricular and submandibular regions, as well as in the central submental and substernal areas, each approximately 2 × 3 cm. Laboratory tests indicated hypercholesterolemia and elevated transaminases, suggestive of alcoholic hepatitis. Fine-needle aspiration (FNA) cytology of the substernal and suboccipital masses revealed fibrous adipose tissue and spindle cell proliferation, and magnetic resonance imaging confirmed adipose-like density tumors. The diagnosis of Madelung's disease (also known as multiple symmetric lipomatosis, MSL) was established based on nodular distribution, laboratory findings, cytology, and imaging results. This rare disorder is characterized by non-encapsulated symmetric lipomas and is commonly associated with alcohol use disorder and metabolic abnormalities. This case is notable for its atypical presentation in a Hispanic male, as MSL typically affects Mediterranean or European populations, and the presence of pruritus, which has not been previously reported. Topical hydrocortisone was prescribed, resulting in pruritis improvement. The patient was counseled on alcohol cessation and offered surgical removal of the masses; however, he declined surgery. Providers should remain vigilant for MSL in patients with bilateral lipomas and a history of alcohol use disorder or metabolic abnormalities. A comprehensive workup should include FNA to exclude malignancy and imaging to assess for compression of underlying structures. Treatment should involve counseling on alcohol cessation, consideration of surgery, and topical hydrocortisone may be considered to manage pruritus.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100649"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183335","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Allergic fungal sinusitis mimicking mycetoma: A diagnostic challenge","authors":"Eric M. Smith , Steven D. Hart , Ashley E. Kita","doi":"10.1016/j.xocr.2024.100639","DOIUrl":"10.1016/j.xocr.2024.100639","url":null,"abstract":"<div><div>Allergic Fungal Rhinosinusitis (AFRS) is a subtype of chronic rhinosinusitis with nasal polyposis (CRSwNP) and is associated with sinus infections. We describe the case of a 42 year-old woman with a history of recurrent sinus infections and atopy who presented with worsening right-sided facial pressure, earaches, and nasal obstruction. A diagnosis of mycetoma was suspected due to a lobulated hyperdense lesion seen in the maxillary sinus on computed tomography (CT). As AFRS and mycetoma can have similar appearances on CT, histopathologic analysis of tissue remains the diagnostic gold standard. The patient was treated with endoscopic surgical debridement. Biopsies were positive for allergic mucin but negative for fungi, satisfying 4 of 5 AFRS diagnostic criteria. Given the initial suspicion for mycetoma, we discuss challenges in AFRS diagnosis.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100639"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183332","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Vocal range stunting, a notable effect of isotretinoin on a singer","authors":"James Aston, Alex Hall","doi":"10.1016/j.xocr.2025.100659","DOIUrl":"10.1016/j.xocr.2025.100659","url":null,"abstract":"<div><div>A patient presents to the Performing Arts Medicine Clinic with complaints of hoarseness coupled with a drop in vocal range by half an octave. The patient was found to have started Accutane (isotretinoin) a month and a half prior. After cessation of Accutane, the patient's vocal range and quality rapidly returned to normal. This case report reviews the impact of vitamin A analogs on the voice and proposes mechanisms by which they may affect it.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100659"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143529592","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Patrick Kiessling , Grace Kim , Kara Meister , Karthik Balakrishnan , Taseer Feroze Din
{"title":"Pediatric tracheal mucoepidermoid carcinoma treated with cricotracheal resection: A rare case and review of literature","authors":"Patrick Kiessling , Grace Kim , Kara Meister , Karthik Balakrishnan , Taseer Feroze Din","doi":"10.1016/j.xocr.2025.100654","DOIUrl":"10.1016/j.xocr.2025.100654","url":null,"abstract":"<div><div>Mucoepidermoid carcinoma (MEC) is a rare pathology in children, and even less commonly seen in the pediatric trachea. Here we describe an adolescent patient who presented with exercise intolerance following COVID-19 infection and was found to have a near-totally obstructive subglottic mass. This mass was debulked and biopsied, demonstrating MEC. Cricotracheal resection with cervical tracheoplasty was performed. A comprehensive review of the published cases of pediatric tracheal MEC was then conducted. This review of 19 patients comprises the largest collection of pediatric tracheal MEC cases analyzed to date, revealing important collective trends and insights for this rare diagnosis.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"34 ","pages":"Article 100654"},"PeriodicalIF":0.2,"publicationDate":"2025-03-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"143183343","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}