Ursula Biba, McKayla J Poppens, Erin K Collier, Kyle Cheng
{"title":"Radiation therapy for a case of poikilodermatous plaques in an otherwise healthy young man: A case report.","authors":"Ursula Biba, McKayla J Poppens, Erin K Collier, Kyle Cheng","doi":"10.1177/2050313X241274837","DOIUrl":"https://doi.org/10.1177/2050313X241274837","url":null,"abstract":"<p><p>Poikilodermatous mycosis fungoides is a rare variant of cutaneous T-cell lymphoma that is often misdiagnosed given its diverse clinical presentation. Often diagnosed as vitiligo or morphea, poikilodermatous mycosis fungoides can be asymptomatic or present as pruritic lesions. Discrepant signs and symptoms can lead to diagnostic delays. No consensus on its treatment currently exists, but treatment options include corticosteroids, phototherapy, and radiation. Here, we present a case of poikilodermatous mycosis fungoides in an otherwise healthy young man who showed limited improvement after years of treatment with topical antifungals, topical steroids, and phototherapy. Improvement was seen following a single session of radiation therapy, highlighting radiation's potential in cases resistant to traditional first-line treatments. We propose that radiation may be efficacious for the treatment of poikilodermatous mycosis fungoides in cases of delayed diagnosis or resistance, and further research is needed to investigate radiation monotherapy as a treatment option for poikilodermatous mycosis fungoides.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241274837"},"PeriodicalIF":0.6,"publicationDate":"2024-10-09","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11467975/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142473735","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Cerebral salt wasting syndrome in a child with central diabetes insipidus following surgery for recurrent craniopharyngioma: A case report.","authors":"Manuel André Virú-Loza","doi":"10.1177/2050313X241275445","DOIUrl":"10.1177/2050313X241275445","url":null,"abstract":"<p><p>Surgical treatment of craniopharyngiomas in children can produce disorders related to water and sodium such as central diabetes insipidus (CDI) and cerebral salt wasting syndrome (CSWS). The combination of both in children is unusually reported in the literature and is associated with high mortality. The management of CSWS is based on fluid therapy. Fludrocortisone is useful in children with CSWS who do not respond to fluid management. The objective of the paper is to describe the case of 6 years and 10 months old male child with hypopituitarism secondary to a craniopharyngioma surgery performed 7 months before, who presented to the emergency department due to recurrent craniopharyngioma. The child presented a combination of CDI and CSWS following surgery for this recurrent tumor. Therapy with fludrocortisone was effective. Pediatric patients as the one of this report can help build the foundation for subsequent systematic reviews or trials.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241275445"},"PeriodicalIF":0.6,"publicationDate":"2024-10-08","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11462566/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142392945","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Charlotte El Hajjar, Hawraa Mohamad, Mohammad Siblini, Khouloud Demachkie, Georges Yared, Mohamad Ramadan, Jihad El Hassan, Hassan Barakat, Kariman Ghazal
{"title":"Advanced abdominal pregnancy complicated by pelvic inflammatory disease: A compelling case report.","authors":"Charlotte El Hajjar, Hawraa Mohamad, Mohammad Siblini, Khouloud Demachkie, Georges Yared, Mohamad Ramadan, Jihad El Hassan, Hassan Barakat, Kariman Ghazal","doi":"10.1177/2050313X241288432","DOIUrl":"https://doi.org/10.1177/2050313X241288432","url":null,"abstract":"<p><p>This case report discusses the rare and complex occurrence of an advanced abdominal pregnancy in a 36-year-old multiparous woman at 26 weeks of gestation, compounded by chronic pelvic inflammatory disease and Fitz-Hugh-Curtis syndrome. The patient was presented with severe symptoms, including abdominal pain, fever, chills, constipation, and vaginal spotting, leading to her hospital admission. Diagnosis was challenging due to the advanced stage of the pregnancy and its abdominal location, particularly in the Douglas pouch, as detected through ultrasonography. According to anatomical standards, this is an intraperitoneal pregnancy rather than an intra-abdominal pregnancy because the fetus developed in the peritoneal cavity. This case is significant for illustrating the critical need for high clinical suspicion and skilled sonographic evaluation to identify such advanced abdominal pregnancies. The successful management of this case through laparotomy, despite the complexities of concurrent conditions, emphasizes the possibility of safe placental removal without increased hemorrhage risk. This report highlights the importance of awareness and expertise in handling rare presentations of ectopic pregnancies, underscoring the potential for positive outcomes with appropriate surgical intervention.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241288432"},"PeriodicalIF":0.6,"publicationDate":"2024-10-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11459669/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142396975","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"A rare case of nodular plaque variant of cutaneous-only Rosai-Dorfman disease: A case report.","authors":"Emily Seale, Alison Spurr, Reetesh Bose","doi":"10.1177/2050313X241289588","DOIUrl":"https://doi.org/10.1177/2050313X241289588","url":null,"abstract":"<p><p>Rosai-Dorfman disease (RDD) is a rare benign histiocytic proliferative disorder that classically involves lymph nodes. It often requires histopathological and immunohistochemical confirmation as it can often mimic malignancy on clinical examination and imaging. Treatment recommendations for this disease are widespread, with no clear universal approach. We present a 59-year-old otherwise healthy female with a rapidly growing and therapeutically challenging red-brown nodular plaque on the left cheek, which was consistent with an uncommon plaque-type variant of cutaneous RDD on histopathological evaluation. This case emphasizes the clinical variability of RDD and underscores the importance of histopathological evaluation to help clarify diagnosis, investigations and guide management for patients presenting with unusual clinical variants.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241289588"},"PeriodicalIF":0.6,"publicationDate":"2024-10-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11459551/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142392943","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Brenda Moshi, Daudi Gidion, Muzdalifat Abeid, Munawar Kaguta, James Chapa, Peter Majinge
{"title":"Congenital ureterovaginal fistula and a duplicated left ectopic ureter: A rare case in Tanzania.","authors":"Brenda Moshi, Daudi Gidion, Muzdalifat Abeid, Munawar Kaguta, James Chapa, Peter Majinge","doi":"10.1177/2050313X241287078","DOIUrl":"10.1177/2050313X241287078","url":null,"abstract":"<p><p>This case report presents the clinical journey of a 28-year-old nulliparous woman from Dar es Salaam, Tanzania, who sought medical attention due to lifelong urinary leakage since birth, profoundly impacting her emotional well-being and sexual encounters. Clinical examination revealed urinary leakage from the vagina, with unremarkable abdominal and genital findings. Laboratory investigations were normal. Computed tomography intravenous urography revealed a left duplex collecting system with significant hydroureteronephrosis in the left upper moiety, suggestive of an ectopic ureter. Intraoperative exploration confirmed a duplicated left ureter, with the upper moiety implanted into the vaginal canal. Surgical re-implantation of both left ureters into the bladder was successfully performed, correcting the anatomical anomaly. Postoperative follow-up demonstrated marked improvement in urinary symptoms, restoring the patient's confidence and alleviating emotional distress. This case underscores the complexity and rarity of congenital urinary tract anomalies, particularly in resource-constrained settings, and highlights the importance of a stepwise diagnostic and management approach.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241287078"},"PeriodicalIF":0.6,"publicationDate":"2024-10-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11526262/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142558686","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Hodgkin's lymphoma presenting as thoracic telangiectasias: A case report.","authors":"Mandana Fadaei Kermani, Julie Desrochers","doi":"10.1177/2050313X241289592","DOIUrl":"https://doi.org/10.1177/2050313X241289592","url":null,"abstract":"<p><p>The rarity of cutaneous manifestations in Hodgkin's lymphoma (HL) complicates diagnosis in affected patients. We present the case of a 31-year-old male presenting with a patch of thoracic telangiectasia that led to a dx of HL.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241289592"},"PeriodicalIF":0.6,"publicationDate":"2024-10-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11467974/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142473730","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Abdominal foreign body migration causing cardiac tamponade: A case report.","authors":"Neirouz Kammoun, Mohamed Guelbi, Mohamed Mahdi Trabelsi, Ibtissem Bouasker, Hichem Jerraya, Ramzi Nouira","doi":"10.1177/2050313X241287380","DOIUrl":"https://doi.org/10.1177/2050313X241287380","url":null,"abstract":"<p><p>Chronic asymptomatic retention of an intragastric foreign body can pose a life-threatening scenario. In the event of migration, it may result in perforation, as shown in our unique case of pericardial perforation through the fundus. Beyond illustrating a rare condition, this case prompts us to engage in a debate about whether to retain or remove asymptomatic foreign bodies in the gastrointestinal tract. It is a 28-year-old male patient, a prisoner, with a history of recurrent foreign body ingestion leading to five previous interventions, presented a year ago to our emergency department after ingesting four metal rods. Despite recommendations, the patient refused the intervention. After 1 year, he presented to our emergency department for respiratory distress. On examination, he had tachycardia, cardiac auscultation revealed a high-pitched sound signing a pericardial knock and abdominal palpation revealed epigastric tenderness. An abdominal X-ray revealed the presence of metallic foreign bodies located in the gastric area. An electrocardiogram showed a low voltage. Given these findings, there was a strong suspicion of rod migration from the stomach to the thoracic cavity with a cardiac tamponade. An emergency CT scan revealed that the rod had pierced through the stomach and pericardium, causing pericardial effusion. The patient was promptly transported to the operating room to discover the tip of the rod out of the stomach and penetrating the left diaphragm and the pericardial layer. The foreign body was removed.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241287380"},"PeriodicalIF":0.6,"publicationDate":"2024-10-07","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11459493/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142392944","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"A case report of nasal myiasis caused by <i>Musca domestica</i> in a patient with respiratory failure.","authors":"Hua Xu, Wen Fan, Wenhua Li, Hongfei Wang, Lin Dou","doi":"10.1177/2050313X241286680","DOIUrl":"https://doi.org/10.1177/2050313X241286680","url":null,"abstract":"<p><p>Nasal myiasis is a nasal infestation caused by myiasis, a parasitic disease affecting the nasal cavity. It is a rare condition. The nasal cavity is in close proximity to the sinuses, eyes, and cranial cavity. If the fly larvae migrate into this location, it may result in significant complications. The prompt and appropriate removal of maggots and the administration of an efficacious treatment can effectively prevent further deterioration of the disease. In this case study, we present the case of a 55-year-old woman who was admitted to the intensive care unit with severe respiratory failure. On the fourth day following admission, the patient remained unconscious, and several white larvae emerged from the nasal cavity. Through identification, the larvae were determined to be <i>Musca domestica</i> larvae. Subsequently, saline irrigation was performed under nasal endoscopy, and anti-inflammatory therapy was administered to the patient to prevent intracranial infection. Following treatment, the patient's symptoms were effectively managed, and the prognosis remained favorable until the 1-month follow-up. This case report presents a literature review of the reported cases of nasal myiasis caused by <i>M. domestica</i> and discusses the susceptibility factors and treatment modalities for nasal myiasis.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241286680"},"PeriodicalIF":0.6,"publicationDate":"2024-10-05","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11457279/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142392942","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Endovascular treatment of a large bone cement pulmonary embolism: Case report.","authors":"Xia Lu, Yang Shen, Wenjun Zhao, Xiang Wang","doi":"10.1177/2050313X241277136","DOIUrl":"10.1177/2050313X241277136","url":null,"abstract":"<p><p>We report a case of endovascular treatment of bone cement embolism after percutaneous vertebroplasty. The patient underwent percutaneous vertebroplasty for acute L1 compression fracture. Two weeks later, the patient developed symptoms of pulmonary embolism. Computed tomography pulmonary angiogram confirmed the presence of a bone cement foreign body in the pulmonary artery. Endovascular treatment was performed, and the cement embolism was caught, pulled to the level of the iliac vein, and fixed with stents. At the 1-year follow-up, the patient did not have any complaints, postoperative computed tomography pulmonary angiogram showed no obvious manifestations of pulmonary embolism, and angiography showed that the bone cement was fixed in place and that the iliac veins were normal.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241277136"},"PeriodicalIF":0.6,"publicationDate":"2024-10-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11445775/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142366425","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Kyungu M Kime, Lisa Bazzett-Matabele, Mercy N Nassali, G Justus Hofmeyr
{"title":"Posterior lower uterine segment caesarean hysterotomy, an innovative surgical technique to avoid classical hysterotomy: Case report and discussion.","authors":"Kyungu M Kime, Lisa Bazzett-Matabele, Mercy N Nassali, G Justus Hofmeyr","doi":"10.1177/2050313X241284037","DOIUrl":"10.1177/2050313X241284037","url":null,"abstract":"<p><p>A 40-year-old patient underwent laparotomy at term gestation for a 25-cm lower abdominal mass arising from the lateral wall of the uterus, with an extensive secondary blood supply from the lower uterus and bladder, preventing access to the anterior lower uterine segment. The gravid uterus was exteriorised over the patient's thighs. A transverse posterior lower uterine segment hysterotomy was performed and a healthy 2920 g baby was delivered. A copper T 380A intrauterine device was placed at the fundus and the insertion tube passed through the cervix for retrieval after the surgery. A Foley catheter uterine tourniquet was applied to allow bloodless excision of the tumour. Histological examination confirmed a leiomyoma with extensive hyalinisation. The few prior reports of posterior lower uterine segment caesarean hysterotomy were mainly for uterine torsion or placenta accreta spectrum. It is useful to be aware of this simple though counter-intuitive approach when faced with technical difficulties.</p>","PeriodicalId":21418,"journal":{"name":"SAGE Open Medical Case Reports","volume":"12 ","pages":"2050313X241284037"},"PeriodicalIF":0.6,"publicationDate":"2024-10-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11526298/pdf/","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142558689","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}