Modern Rheumatology Case Reports最新文献_第8页

Successful treatment of relapsing polychondritis with circumferential bronchial wall thickening including the tracheomembranous area with tumor necrosis factor-α inhibitor. 肿瘤坏死因子-α抑制剂治疗包括气管膜区在内的支气管周壁增厚的复发性多软骨炎。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac005

Makiko Maekawa, Motoki Yoshimura, Masako Kadowaki, Miki Nakano, Atsushi Moriwaki, Hitoshi Ueda, Shigeru Yoshizawa

引用次数: 1

Calcific tendinitis of the shoulder induced by an mRNA vaccine for COVID-19: A case report. 新冠病毒mRNA疫苗致肩关节钙化性肌腱炎1例

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac006

Koji Nakajima, Akira Miyata, So Kato, Yasushi Oshima, Sakae Tanaka

{"title":"Calcific tendinitis of the shoulder induced by an mRNA vaccine for COVID-19: A case report.","authors":"Koji Nakajima, Akira Miyata, So Kato, Yasushi Oshima, Sakae Tanaka","doi":"10.1093/mrcr/rxac006","DOIUrl":"https://doi.org/10.1093/mrcr/rxac006","url":null,"abstract":"Coronavirus disease 2019 (COVID-19) vaccines have been widely used and have been shown to be effective in combating the pandemic. However, various side effects have been reported following vaccination. For instance, a condition called 'shoulder injury related to vaccine administration' (SIRVA) is characterized by shoulder pain and limited range of motion after intramuscular injection of a vaccine into the deltoid muscle of the shoulder. Despite an increase in SIRVA cases, the exact incidence of the disease is unclear, and there are a few reports of SIRVA about the COVID-19 vaccine. Here, we report a rare case of an 83-year-old woman who was diagnosed with calcification in her left shoulder 1 year ago and developed calcific tendinitis after receiving an mRNA vaccine for COVID-19 (Pfizer-BioNTech). Radiographs showed calcification of the supraspinatus tendon, and magnetic resonance images showed continuous inflammatory findings from the subdeltoid bursa to the subacromial bursa. We treated the patient with celecoxib and acetaminophen, and she recovered after about 2 months. In order to prevent SIRVA, the presence of shoulder joint disease should be carefully asked during a pre-vaccination assessment. The puncture point should be chosen with the median point of the deltoid muscle or the anterior-posterior axillary line as landmarks because the more cephalad the puncture position, the greater the chance of causing SIRVA.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"211-214"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8903335/pdf/rxac006.pdf","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10484632","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 3

Difficulties of diagnosing idiopathic hypertrophic pachymeningitis in children: Case report and literature review. 诊断儿童特发性肥厚性厚性脑膜炎的困难:病例报告及文献复习。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac026

Naoki Nicho, Tomo Nozawa, Ayako Murase, Ren Hayashibe, Reo Tanoshima, Risa Okubo, Seira Hattori, Kenichi Nishimura, Takashi Ohya, Shuichi Ito

{"title":"Difficulties of diagnosing idiopathic hypertrophic pachymeningitis in children: Case report and literature review.","authors":"Naoki Nicho, Tomo Nozawa, Ayako Murase, Ren Hayashibe, Reo Tanoshima, Risa Okubo, Seira Hattori, Kenichi Nishimura, Takashi Ohya, Shuichi Ito","doi":"10.1093/mrcr/rxac026","DOIUrl":"https://doi.org/10.1093/mrcr/rxac026","url":null,"abstract":"Hypertrophic pachymeningitis (HP) is a rare inflammatory disorder characterised by local or diffuse thickening of the cranial and spinal dura mater. HP occurs owing to idiopathic or secondary causes, including autoimmune disease, infection, and trauma. HP has mainly been reported in adults, with few reported cases in children. We encountered an 11-year-old boy with idiopathic HP who presented with chronic inflammation and daily occipital headache. Gadolinium (Gd)-enhanced magnetic resonance imaging (MRI) helped us to diagnose him with HP. He was successfully treated with corticosteroids and azathioprine with no recurrence. We also conducted a literature review of childhood-onset HP and found only 16 cases, including our patient. Seven patients had idiopathic HP, and the remaining nine had secondary HP, including two with rheumatic disease. The most common clinical symptoms were headache (68.8%) and cranial nerve-related symptoms (68.8%). Inflammatory laboratory markers were elevated in 60% of patients with available data. Fifteen cases were diagnosed using Gd-enhanced MRI. The main initial treatment was steroids and/or immunosuppressants, to which 87.5% of patients responded. However, two patients with HP associated with trauma and neuroblastoma (12.5%) died, and seven patients (43.8%) had left cranial nerve-related sequelae. As the prognosis for childhood HP is poor, early diagnosis and treatment are essential. Children with headache, cranial nerve symptoms, and elevated inflammatory marker levels should be suspected of having HP and Gd-enhanced MRI should be considered.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"233-236"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10484970","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 2

Antimicrobial therapy for nontuberculous mycobacterial pulmonary disease improved hearing loss and normalized myeloperoxidase-anti-neutrophil cytoplasmic antibody level: A case report. 非结核性分枝杆菌肺病的抗菌治疗改善了听力损失和髓过氧化物酶-抗中性粒细胞胞浆抗体水平的正常化:1例报告

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac047

Yutaka Tomishima, Masei Suda, Hiromichi Tamaki

{"title":"Antimicrobial therapy for nontuberculous mycobacterial pulmonary disease improved hearing loss and normalized myeloperoxidase-anti-neutrophil cytoplasmic antibody level: A case report.","authors":"Yutaka Tomishima, Masei Suda, Hiromichi Tamaki","doi":"10.1093/mrcr/rxac047","DOIUrl":"https://doi.org/10.1093/mrcr/rxac047","url":null,"abstract":"Several case reports have indicated that nontuberculous mycobacterial pulmonary disease is associated with anti-neutrophil cytoplasmic antibody-associated vasculitides. However, the effect of the treatment for nontuberculous mycobacterial pulmonary disease on anti-neutrophil cytoplasmic antibody-associated vasculitides remains unclear. An asymptomatic 80-year-old woman presented with nodular bronchiectasis. After 1 year, she developed a productive cough. Mycobacterial culture of the respiratory specimen revealed Mycobacterium avium. She was diagnosed with nontuberculous mycobacterial pulmonary disease based on the criteria proposed by the American Thoracic Society. Concurrently, she had hearing loss, tinnitus, and weight loss. A blood test showed an elevated level of myeloperoxidase-anti-neutrophil cytoplasmic antibody (107 IU/mL, normal level: <3.5 IU/mL). Bilateral otitis media with anti-neutrophil cytoplasmic antibody-associated vasculitis was diagnosed based on the diagnostic criteria proposed by the Japan Otological Society. After starting antimicrobial agents for the nontuberculous mycobacterial pulmonary disease, her pulmonary symptoms and hearing loss improved, and the level of myeloperoxidase-anti-neutrophil cytoplasmic antibody normalized. No immunosuppressive treatment was administered. The present case suggests that nontuberculous mycobacterial pulmonary disease can cause otitis media with anti-neutrophil cytoplasmic antibody-associated vasculitides, and antimicrobial treatment for the nontuberculous mycobacterial pulmonary disease may resolve otitis media with anti-neutrophil cytoplasmic antibody-associated vasculitides.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"283-287"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10485148","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Efficacy of canakinumab in a patient with adult-onset glucocorticoid-resistant periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis syndrome. canakinumab在成人发病糖皮质激素抵抗性周期性发热、口腔炎、咽炎和宫颈腺炎综合征患者中的疗效

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac043

Bernardo Sopeña, Olga Araújo, Mayka Freire, Lucía Barrera-López, Hernández-Rodríguez José

{"title":"Efficacy of canakinumab in a patient with adult-onset glucocorticoid-resistant periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis syndrome.","authors":"Bernardo Sopeña, Olga Araújo, Mayka Freire, Lucía Barrera-López, Hernández-Rodríguez José","doi":"10.1093/mrcr/rxac043","DOIUrl":"https://doi.org/10.1093/mrcr/rxac043","url":null,"abstract":"Periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis (PFAPA) syndrome, a polygenic or multifactorial condition, is the most frequent autoinflammatory disease in children. There is increasing evidence that some patients may have a disease onset during adulthood. With regard to PFAPA syndrome treatment, single medium-to-high doses of glucocorticoids during flares constitute the therapy of choice in children and adults, colchicine may be useful in some patients, and tonsillectomy has been reported of utility mainly in paediatric patients. Interleukin-1 (IL-1) blockers have been sporadically used with good response in glucocorticoid-resistant cases. We report a patient with an adult onset of glucocorticoid-resistant PFAPA syndrome and inconsistent response to colchicine and anakinra, who later achieved a complete and sustained response to canakinumab. Although canakinumab seems to be a good therapeutic option in paediatric and adult patients with refractory PFAPA syndrome, the best anti-IL-1 agent and the sequence of administration have to be still determined in well-designed clinical trials.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"276-279"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10485160","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Colchicine as rescue treatment in two pediatric patients with chronic recurrent multifocal osteomyelitis (CRMO). 秋水仙碱作为两名儿童慢性复发性多灶性骨髓炎（CRMO）患者的抢救性治疗。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac010

Cristian Quintana-Ortega, Ana Prieto-Moreno Pfeifer, Laura Palomino Lozano, Ángel Lancharro, Jesús Saavedra Lozano, Angel Jose Villa-García, Elena Seoane-Reula

引用次数: 1

Successful switching treatment of adalimumab for refractory pyoderma gangrenosum in a patient with rheumatoid arthritis with prior use of tumour necrosis factor inhibitors: A case report and review of the literature. 阿达木单抗成功转换治疗顽固性坏疽脓皮病的类风湿关节炎患者既往使用肿瘤坏死因子抑制剂:一个病例报告和文献回顾。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac023

Shin-Ichiro Ohmura, Yoichiro Homma, Shiho Hanai, Yoshiro Otsuki, Toshiaki Miyamoto

引用次数: 1

Five cases of seronegative persistent inflammatory monoarthritis improved with biological therapy. 5例血清阴性的持续性炎症性单关节炎通过生物治疗得到改善。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac063

Takuya Izumiyama, Yu Mori, Soshi Hamada, Hiroaki Kurishima, Naoko Mori, Toshimi Aizawa

{"title":"Five cases of seronegative persistent inflammatory monoarthritis improved with biological therapy.","authors":"Takuya Izumiyama, Yu Mori, Soshi Hamada, Hiroaki Kurishima, Naoko Mori, Toshimi Aizawa","doi":"10.1093/mrcr/rxac063","DOIUrl":"10.1093/mrcr/rxac063","url":null,"abstract":"Persistent inflammatory monoarthritis is defined as inflammation of one joint that continues for longer than 3 months. Most cases remain as nonspecific arthritis after several years. Persistent inflammatory monoarthritis is difficult to diagnose and treat in the early stage because there are no criteria for diagnosis and treatment. We report five seronegative persistent inflammatory monoarthritis cases that affected the left knee, right knee, left knee, left ankle, and right knee. All patients underwent joint punctures; two patients received steroid injections in the affected joint. The bacterial and mycobacterial culture were negative in all patients. Two patients received oral steroids, and two patients were administered nonsteroidal anti-inflammatory drugs; however, their symptoms did not improve, and one patient experienced progression of joint destruction. We investigated the usefulness of biological disease-modifying antirheumatic drugs for the treatment of seronegative persistent inflammatory monoarthritis. We obtained a remarkable improvement effect and prevented the advance of joint destruction.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"307-314"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10490225","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Familial Mediterranean fever with pseudo-septic arthritis: A case report and review of the literature. 家族性地中海热合并假脓毒性关节炎1例报告及文献复习。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac040

Laith Alamlih, Layth Al-Karaja, Mohammad Alayaseh, Fawzy Abunejma, Ziyad Al-Zeer, Bashar Sultan

{"title":"Familial Mediterranean fever with pseudo-septic arthritis: A case report and review of the literature.","authors":"Laith Alamlih, Layth Al-Karaja, Mohammad Alayaseh, Fawzy Abunejma, Ziyad Al-Zeer, Bashar Sultan","doi":"10.1093/mrcr/rxac040","DOIUrl":"https://doi.org/10.1093/mrcr/rxac040","url":null,"abstract":"INTRODUCTION Familial Mediterranean fever (FMF) is a hereditary autoinflammatory disease resulting from mutations of the MEFV gene. The disease is characterized by recurrent attacks of abdominal pain and fever. Most FMF patients develop arthritis at some point in their life usually manifesting as self-limiting mono-arthritis. On very rare occasions, arthritis in FMF can mimic septic arthritis (pseudo-septic arthritis) with very similar clinical and laboratory findings. CASE PRESENTATION We report a case of a young male patient who presented with recurrent attacks of prolonged mono-arthritis. For two years, he had undergone multiple admissions and operations for drainage of suspected septic joints. The synovial aspiration showed culture negative pus with very high synovial white blood cell counts highly suggestive of septic arthritis. The patient was later found to have FMF based on homozygous M694V mutation of the MEFV gene. He was treated with colchicine monotherapy with a quick improvement of the arthritis and later good control of his disease. Literature review showed very few case reports with similar presentation most of which responded well to colchicine. CONCLUSIONS FMF can mimic septic arthritis resulting in unnecessary expensive and invasive interventions and prolonged courses of antibiotics. Pseudo-septic arthritis is usually associated with M694V homozygous mutation and can complicate FMF at any time throughout the disease course. It is important to consider FMF in the differential diagnosis of septic arthritis particularly with a family history of FMF and in patients from communities with high prevalence of MEFV gene mutation.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"252-256"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10541654","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 0

Intravenous tocilizumab for Takayasu arteritis with aortic aneurysms, bilateral renal artery stenosis, and atypical aortic coarctation in a 2-year-old girl. 静脉注射tocilizumab治疗2岁女童高松动脉炎伴主动脉瘤、双侧肾动脉狭窄和非典型主动脉缩窄。

Modern Rheumatology Case Reports Pub Date : 2023-01-03 DOI: 10.1093/mrcr/rxac068

Yuji Fujita, Minako Tomiita, Sayumi Saida, Shohei Omura, Megumi Sato, Yuto Otsubo, Yuhi Takagi, Yuji Kano, Kaori Sekine, Keitaro Fukushima, Shigeko Kuwashima, Shigemi Yoshihara

{"title":"Intravenous tocilizumab for Takayasu arteritis with aortic aneurysms, bilateral renal artery stenosis, and atypical aortic coarctation in a 2-year-old girl.","authors":"Yuji Fujita, Minako Tomiita, Sayumi Saida, Shohei Omura, Megumi Sato, Yuto Otsubo, Yuhi Takagi, Yuji Kano, Kaori Sekine, Keitaro Fukushima, Shigeko Kuwashima, Shigemi Yoshihara","doi":"10.1093/mrcr/rxac068","DOIUrl":"https://doi.org/10.1093/mrcr/rxac068","url":null,"abstract":"Takayasu arteritis (TAK) is classified as large vessel vasculitis, and continuous inflammation of the vessel results in aneurysm or stenosis, which leads to various serious complications. Recently, a TAKT [TAK treated with tocilizumab (TCZ)] study showed that subcutaneous TCZ, a humanised anti-interleukin-6 receptor monoclonal antibody, is an effective treatment in patients with TAK above 12 years of age; however, the effectiveness of TCZ for juvenile TAK under 12 years old remains unclear. Here, we described the case of a 2-year-old girl with TAK, which was successfully treated with intravenous TCZ. She was diagnosed with TAK type V (Numano's angiographic classification system) with aortic aneurysms, bilateral renal arteries stenosis, and atypical descending aortic coarctation based on contrast-enhanced computed tomography findings. Treatment was started with 2 mg/kg/day prednisolone (PSL) and methotrexate instead of methylprednisolone pulse due to renovascular hypertension. She was immediately afebrile and her C-reactive protein level decreased, although it was elevated 4 weeks after starting PSL. Intravenous TCZ of 8 mg/kg/2 weeks was added because the progression of aneurysms or stenosis might lead to a poor prognosis. PSL was steadily reduced under intravenous TCZ. Magnetic resonance imaging showed that aortic aneurysms, renal arteries stenosis, and aortic coarctation ameliorated 4 months after starting TCZ, with the amelioration maintained at 1 year after starting TCZ. Aneurysms and stenosis improved; therefore, TCZ may be effective for the treatment of inflammation of vessels, aneurysms, and stenosis. It is desirable to examine the effect of TCZ on TAK patients under 12 years of age.","PeriodicalId":18677,"journal":{"name":"Modern Rheumatology Case Reports","volume":"7 1","pages":"160-165"},"PeriodicalIF":0.0,"publicationDate":"2023-01-03","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"10669018","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}

引用次数: 1