Muhammad Mukhlesur Rahman , Meskat Raihan , MD. Ziaur Rahman Chowdhury , Mohammad Abdul Quayum , Syed Nafi Mahdee , Mohammad Ashraful Amin , Mohammad Delwer Hossain Hawlader
{"title":"Congenital supernumerary nostril with frontal sinus involvement in a 6-month-old infant: First surgically managed case from Bangladesh","authors":"Muhammad Mukhlesur Rahman , Meskat Raihan , MD. Ziaur Rahman Chowdhury , Mohammad Abdul Quayum , Syed Nafi Mahdee , Mohammad Ashraful Amin , Mohammad Delwer Hossain Hawlader","doi":"10.1016/j.xocr.2025.100697","DOIUrl":"10.1016/j.xocr.2025.100697","url":null,"abstract":"<div><div>A supernumerary nostril is one of the rarest of the congenital nasal malformations, and less than 40 cases have been reported worldwide. It could be an isolated defect or associated with craniofacial or systemic abnormalities. We report the 1st case of congenital supernumerary nostril ever recorded and treated surgically in Bangladesh. A 6-month-old male infant was found to have a left accessory nostril draining into the frontal sinus. Thus, a well-planned surgery that included preoperative planning and a total surgical excision resulted in excellent cosmetic and functional outcomes. This case report discusses the diagnostic and surgical issues related to these unusual anomalies, including their embryological background, imaging appearances and surgical techniques.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100697"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145007672","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Combined open and endoscopic excision of a large congenital laryngeal cyst causing airway obstruction in an infant: a case report","authors":"Turki Sulaiman Althunayyan , Roqaih Aldueb , Lamya Alhuwaimel , Yousef Aljathlany","doi":"10.1016/j.xocr.2025.100693","DOIUrl":"10.1016/j.xocr.2025.100693","url":null,"abstract":"<div><div>Congenital laryngeal cysts are rare airway anomalies with an incidence of ∼1.82 per 100,000 live births. These lesions can present with a range of respiratory symptoms, including stridor and feeding difficulties, and may be life-threatening if not diagnosed and managed promptly.</div><div>We report a case of a 9-month-old male, born preterm at 36 weeks, who presented with failure to thrive, poor feeding, and intermittent stridor since birth. Clinical evaluation revealed a midline neck swelling, and flexible laryngoscopy identified a laryngeal cyst. Imaging studies (CT angiography and MRI) demonstrated a large, multicystic lesion causing significant airway compression. The patient underwent surgical excision via a combined endoscopic and open approach. Postoperatively, he was managed in the pediatric intensive care unit (PICU) and was successfully extubated after two weeks. At follow-up, he showed marked improvement in respiratory function, feeding, and growth.</div><div>This case highlights the importance of considering congenital laryngeal cysts in infants with persistent stridor and feeding difficulties. While endoscopic techniques are often preferred, large or complex cysts may necessitate an open surgical approach to ensure complete excision and prevent recurrence. Multidisciplinary evaluation and timely intervention are essential for optimizing outcomes and promoting normal growth and development.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100693"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145007673","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Bilal Hasan , Zulfiqar Hamdan , Ahmad Nezar Mohammad
{"title":"A rare presentation of Tuberculous otitis media in an immunocompetent adult: Case report and literature review","authors":"Bilal Hasan , Zulfiqar Hamdan , Ahmad Nezar Mohammad","doi":"10.1016/j.xocr.2025.100703","DOIUrl":"10.1016/j.xocr.2025.100703","url":null,"abstract":"<div><h3>Introduction</h3><div>Tuberculous otitis media (TOM) is a rare manifestation of extrapulmonary tuberculosis, representing less than 1 % of chronic middle ear infections in developed countries. Its nonspecific presentation often mimics other chronic otitis media forms, leading to underdiagnose it, especially in resource-limited settings.</div></div><div><h3>Case presentation</h3><div>A 50-year-old female presented with odorless, colorless otorrhea from the left ear for two weeks, without pain or systemic symptoms. She had a history of pulmonary tuberculosis diagnosed eight months earlier, but discontinued treatment after three months. On otoscopy, we observed purulent secretions and three tympanic membrane perforations. Polymerase chain reaction of the ear discharge confirmed <em>Mycobacterium tuberculosis</em>. Audiometry revealed a 25 dB air-bone gap, consistent with mild to moderate conductive hearing loss, while temporal bone CT showed no abnormalities. She received standard quadruple anti-tuberculous therapy for two months, followed by dual therapy for four months. After completing treatment, we performed tympanoplasty with a temporalis fascia graft.</div></div><div><h3>Clinical discussion</h3><div>Clinicians should suspect TOM in chronic otitis media unresponsive to conventional therapy, particularly in patients with an active TB history. The disease may spread hematogenously or through the Eustachian tube. Classic signs such as painless otorrhea, multiple perforations, and facial palsy are now less frequent. PCR offers rapid confirmation, and early therapy prevents irreversible complications.</div></div><div><h3>Conclusion</h3><div>This case emphasizes the need for clinician awareness, timely treatment, and adherence to therapy. Integrating TB screening into the evaluation of atypical chronic otitis media remains essential, especially in patients with a story of active TB.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100703"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145220612","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Miles J. Klimara , Eirene Alexandrou , Anand Kanagasabapathy , Matthew R. Hoffman
{"title":"An unusual laryngeal mass: primary tumoral calcinosis of the larynx in a child","authors":"Miles J. Klimara , Eirene Alexandrou , Anand Kanagasabapathy , Matthew R. Hoffman","doi":"10.1016/j.xocr.2025.100710","DOIUrl":"10.1016/j.xocr.2025.100710","url":null,"abstract":"<div><h3>Background</h3><div>Tumoral calcinosis (TC) is a rare, benign calcium hydroxyapatite deposition typically affecting periarticular tissue of large joints, which may occur sporadically or in association with hyperphosphatemia. Laryngeal TC has been reported in several patients, uniformly in the fifth and sixth decade of life. Presented is a case of sporadic combined intra-laryngeal and extra-laryngeal TC in a child.</div></div><div><h3>Case discussion</h3><div>A 10-year-old female presented with a right neck mass and stridor with activity. Flexible laryngoscopy revealed fullness of the right false vocal fold without intraluminal mass, and computed tomography showed a large, calcified, intra- and extra-laryngeal mass passing through the thyrohyoid space. Open resection was performed. Surgical pathology revealed TC. Laboratory and endocrine evaluation did not reveal any underlying metabolic etiology, supporting a diagnosis of primary laryngeal TC. Airway management, approach to resection, and published cases of laryngeal TC are reviewed.</div></div><div><h3>Conclusion</h3><div>TC of the larynx is an exceedingly rare entity. Given benign nature of this disease process, a conservative approach is favored when resection is pursued, with preservation of normal structures in order to minimize morbidity. Upon diagnosis, multidisciplinary evaluation should be pursued to rule out underlying endocrine, metabolic, and genetic disorders.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100710"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145519598","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Mika R. Gehrking , Chirag P. Parjiea , Martin Zeilinger , Sarina K. Mueller , Horia Sirbu , Matti Sievert
{"title":"Cervical abscess secondary to bilateral sternoclavicular joint septic arthritis","authors":"Mika R. Gehrking , Chirag P. Parjiea , Martin Zeilinger , Sarina K. Mueller , Horia Sirbu , Matti Sievert","doi":"10.1016/j.xocr.2025.100698","DOIUrl":"10.1016/j.xocr.2025.100698","url":null,"abstract":"<div><h3>Background</h3><div>Sternoclavicular joint septic arthritis is a rare infection of the sternoclavicular joint. This report describes a case presenting unusually as a cervical abscess.</div></div><div><h3>Case presentation</h3><div>A 72-year-old diabetic female presented to the tertiary care department of otorhinolaryngology, head and neck surgery at the university hospital with fever and painful swelling of the left side of her neck. MRI revealed a neck abscess involving the carotid sheath extending to the upper thoracic aperture. Surgical drainage was performed. After initial improvement of symptoms and infectious markers, the patient developed bilateral cellulitis of the hands from multiple cat scratches. Progressive wound deterioration in the lower neck prompted imaging, which revealed bilateral septic arthritis of the sternoclavicular joint. On both sides, resection of the joint and the medial part of the clavicle was necessary. The soft tissue defect was reconstructed with a pectoralis major muscle flap.</div></div><div><h3>Conclusion</h3><div>Sternoclavicular joint septic arthritis should be considered as a potential underlying cause of cervical abscess. Limited infection can be treated with intravenous antibiotics. Incision and drainage can help establish a microbiological diagnosis. More extensive surgical intervention may be needed in cases of osteomyelitis or mediastinitis. Clinicians should be suspicious if cervical abscesses do not resolve in the anticipated timeframe.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100698"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145096142","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Vestibular migraine and SSRI withdrawal: A case report","authors":"Grace Fairchild, Sarah Redding, Ashley G. Flagge","doi":"10.1016/j.xocr.2025.100706","DOIUrl":"10.1016/j.xocr.2025.100706","url":null,"abstract":"<div><div>Vestibular migraine (VM) has been described as a diagnosis of exclusion, with no one singular definitive assessment for diagnosis. It has been suggested that possible pharmaceutical intervention for VM can include antidepressant drugs, but this is potentially complicated by the fact that dizziness is a common side effect of both use and withdrawal for certain types of antidepressant medications. This article describes the case of a 56-year old with probable VM, who was previously diagnosed with depression and treated with the selective serotonin reuptake inhibitor (SSRI) Citalopram. Following discontinuation with no taper, the patient experienced a series of withdrawal side effects that prompted a vestibular audiology referral. This case study illustrates the potential effects of SSRI withdrawal on vestibular and balance symptoms, especially when co-occurring with VM.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100706"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145266101","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Chanan Shaul, Pierre Attal, Shahar Negari, Jean-Yves Sichel
{"title":"Retropharyngeal and mediastinal abscess following adenoidectomy: A case report","authors":"Chanan Shaul, Pierre Attal, Shahar Negari, Jean-Yves Sichel","doi":"10.1016/j.xocr.2025.100699","DOIUrl":"10.1016/j.xocr.2025.100699","url":null,"abstract":"<div><div>Adenoidectomy is one of the most common surgical procedures performed in children. While generally considered safe, rare but serious complications may occur. We present the case of a 3-year-old girl who developed a retropharyngeal abscess extending to the mediastinum following adenoidectomy. The patient presented with a high fever of up to 40 °C, severe torticollis, and significant dysphagia three days after the procedure performed at another hospital. Clinical examination revealed marked neck tenderness. Laboratory tests showed leukocytosis and elevated C-reactive protein. Initial treatment with amoxicillin-clavulanic acid did not improve her condition. A contrast-enhanced CT scan of the neck and upper chest demonstrated a retropharyngeal edema that progressed to a well-defined abscess with extension to the superior mediastinum on follow-up imaging. The patient underwent a surgical cervical approach with drainage of the abscess and placement of drains. Following one week of intravenous antibiotic therapy, she was discharged in good condition. A follow-up MRI performed one month later was normal. This case highlights a rare but potentially life-threatening complication of adenoidectomy. Early recognition, appropriate imaging, and prompt management are crucial for favorable outcomes. Otolaryngologists should be aware of this uncommon complication and maintain a high index of suspicion when evaluating post-adenoidectomy patients with persistent fever, neck pain and torticollis.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100699"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145118216","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Melania Bertolini , Marta De Vecchi , Monica Feltri , Luca Guastini , Diego Criminelli , Frank Rikki Mauritz Canevari
{"title":"Lipoblastoma of the infratemporal pterygoid region: An unusual case report","authors":"Melania Bertolini , Marta De Vecchi , Monica Feltri , Luca Guastini , Diego Criminelli , Frank Rikki Mauritz Canevari","doi":"10.1016/j.xocr.2025.100704","DOIUrl":"10.1016/j.xocr.2025.100704","url":null,"abstract":"<div><h3>Objectives</h3><div>Lipoblastoma is a rare, benign tumor that arises from embryonic adipose tissue. It is more commonly found in males and is typically diagnosed in children under the age of 5. The tumor can occur in the head and neck region, including the cheek, jaw, and neck. Treatment involves complete surgical removal of the tumor. We present the clinical case of a lipoblastoma located in the pterygoid region, which has never been described before in the literature. The tumor was surgically treated using a transnasal transpterygoid endoscopic approach.</div></div><div><h3>Methods</h3><div>An 11-year-old female patient presented to our hospital with a history of persistent, diffuse headaches lasting for 3 years, accompanied by nausea, vomiting, and intolerance to lights and sounds. A brain MRI revealed a lesion in the right pterygoid fat. A CT scan was performed to assess the bony structures. Nasal endoscopy was normal.</div></div><div><h3>Results</h3><div>The patient underwent radical surgery under general anesthesia, with a transnasal transpterygoid endoscopic approach and reconstruction using a rescue flap. Pathological analysis confirmed the diagnosis of lipoblastoma. The postoperative course was uneventful and 3 months after surgery the patient reported no further headache. The patient was followed up for 5 years post-surgery, with no evidence of recurrence.</div></div><div><h3>Conclusions</h3><div>The transnasal transpterygoid endoscopic approach is a safe and effective technique, even in pediatric patients, but it should only be performed by a qualified and experienced surgeon. Although lipoblastoma is an extremely rare tumor, it should be considered in the differential diagnosis of headache in children.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100704"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145158331","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"A unique presentation of Bell's palsy in a pediatric cochlear implant patient","authors":"Rachel N. Grimes , Harry C. Owen , Sarah E. Hodge","doi":"10.1016/j.xocr.2025.100709","DOIUrl":"10.1016/j.xocr.2025.100709","url":null,"abstract":"<div><h3>Objective</h3><div>To describe a rare case of idiopathic delayed facial nerve palsy following cochlear implantation (CI) in a pediatric patient with a history of device extrusion, facial nerve stimulation, and cholesteatoma.</div></div><div><h3>Methods</h3><div>Retrospective chart review of a case of a 14-year-old female with bilateral severe-to-profound sensorineural hearing loss who underwent initial cochlear implantation at ages 3 and 4. Ten years later, she experienced bilateral CI failure and had left-sided electrode extrusion through the external auditory canal (EAC). She underwent multiple CI-related surgeries, including right explantation/reimplantation and left-sided explantation with EAC reconstruction and cholesteatoma removal, followed by interval reimplantation 6 months later.</div></div><div><h3>Results</h3><div>After left-sided reimplantation, the patient developed facial nerve stimulation necessitating deactivation of eight electrodes. Subsequently, she experienced delayed-onset complete facial nerve palsy, which was managed with high-dose corticosteroids, antivirals, and revision exploratory surgery to ensure proper electrode placement and absence of cholesteatoma. Her facial function gradually improved following medical management.</div></div><div><h3>Conclusion</h3><div>Delayed-onset facial paralysis in this case was ultimately diagnosed as Bell's Palsy, an extremely rare complication following pediatric cochlear implantation. This case highlights the importance of a comprehensive approach to evaluation and management of facial nerve dysfunction in post-CI patients.</div></div>","PeriodicalId":37154,"journal":{"name":"Otolaryngology Case Reports","volume":"37 ","pages":"Article 100709"},"PeriodicalIF":0.3,"publicationDate":"2025-11-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"145519599","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}