{"title":"Transoral Approach Used to Remove a Giant Sialolith","authors":"F. Butt","doi":"10.1177/27528464231158454","DOIUrl":"https://doi.org/10.1177/27528464231158454","url":null,"abstract":"Study Design: Case Report.Objective: Sialoliths are a cause of Sialolithiasis affecting an estimated 12 in 1000 adult population. The patient’s presentation vary from being asymptomatic to pain with swelling and purulent discharge if accompanied with a infection. Giant sialoliths greater than 15 mm are rare. The purpose of the article is to document and educate clinicians on the management of giant sialoliths with possible sparing of the salivary gland.Methods: This report documents a patient with a sialolith measuring 45 mm in the widest diameter removed using a trans-oral approach.Results: The patient presented with an intra-oral sialolith which was asymptomatic except for the hard swelling felt cervically. Clinical examination and radiographic imaging was adequate for a diagnosis and the fact that there was no tenderness over the glandular area a decision to spare the gland was made.Conclusion: There are few reports of giant sialoliths and majority present with sialadenitis. In this case it was rare for the stone to have reached this size with hardly any symptoms. In patients where the gland has not been affected clinicians may consider sparing it and remove only the sialolith to reduce the morbidity and risks associated with glandular excision.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"16 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"128704414","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Silent Sinus Syndrome: A Case of Orbital Reconstruction With Patient-specific Implant and Intraoperative Navigation System and Computed Tomography Scan","authors":"Adrián Cardín Pereda, A. Pereira","doi":"10.1177/27528464231163967","DOIUrl":"https://doi.org/10.1177/27528464231163967","url":null,"abstract":"By reporting a case of orbital restoration with a patient-specific implant (PSI), intraoperative navigation and computed tomography scan (CT) in a silent sinus syndrome patient, we aim to make reconstructive surgeons aware of the advantages these tools confer. We report a case of a 33-year-old woman affected by spontaneous enophthalmos and hypoglobus of her right eye. Anamnesis, physical exam and CT findings were compatible with a silent sinus syndrome. Caldwell-Luc technique and concurrent transconjunctival repair of the orbital floor using a PSI with intraoperative navigation and CT scan were performed successfully, achieving satisfactory repositioning of the globe and facial symmetry. The silent sinus syndrome is an acquired uncommon condition which may require correction of secondary orbital deformities. In this scenario, patient-specific implants, CAD/CAM and intraoperative navigation have emerged as safe and effective tools.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"49 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"132297711","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Andrew Okiriamu, F. Butt, F. Opondo, Fredrick Onyango
{"title":"Morphology and Variant Anatomy of the Mandibular Canal in a Kenyan Population: A Cone-Beam Computed Tomography Study","authors":"Andrew Okiriamu, F. Butt, F. Opondo, Fredrick Onyango","doi":"10.1177/27528464231182775","DOIUrl":"https://doi.org/10.1177/27528464231182775","url":null,"abstract":"Descriptive cross-sectional study. The mandibular canal (MC) exhibits surgically significant anatomical variations in its course and terminal segment among different ethnic groups. The aim of this study was to document a surgically relevant position of the MC, its variants, and related anatomical structures in dentate patients from a select Kenyan population. 351 hemi mandibular cone-beam computed tomography (CBCT) scans from 202 patients were used to evaluate the MC and mental foramen (MF) for normal morphology, anatomical variations, and their linear relationship to various reference points. The most frequently encountered course of the MC was the progressive descent type seen in 241 (68.7%) scans. Accessory MC were observed in 15 (4.3%) scans. Accessory MF were observed in 29 (8.3%) scans. The mean diameter of the MC was 3.36 ± .39 mm. The orientation of the MC was more lingual towards the angle of the mandible and more buccal towards the MF. The most frequent position of the main MF in relation to the second premolar was anterior (53.3%). The average distance from the MF to the inferior border of the mandible was 12.17 ± 1.91 mm. The anterior loop of the mental nerve was observed in 18 (5.1%) scans and its mean length was 4.83 ± .89 mm. Our study revealed significant variations in the position, size, and course of the MC and MF. This knowledge should assist oral surgeons to avoid inadvertent injury to the inferior alveolar neurovascular bundle in the local population.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"13 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"124772109","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Sylvio Luiz Costa De-Moraes, R. D. Fares, Alexandre Maurity de Paula Afonso, R. Mattos, Roberto Gomes dos Santos, Rayssa Lima Pereira, J. Ribeiro da Silva
{"title":"Surgical Treatment of the Cranial Basis Teratoma in a Newborn and Palatal Reconstruction With Tongue Flap a 17-Years Follow-Up: A Case Report","authors":"Sylvio Luiz Costa De-Moraes, R. D. Fares, Alexandre Maurity de Paula Afonso, R. Mattos, Roberto Gomes dos Santos, Rayssa Lima Pereira, J. Ribeiro da Silva","doi":"10.1177/27528464231170750","DOIUrl":"https://doi.org/10.1177/27528464231170750","url":null,"abstract":"Epignathus or Tessier fissure 0-14 is a rare teratoma composed of the three embryonic germ layers. Clinically, it appears as a mass covered with skin and mucosa, originating from pluripotential stem cells. According to the latest classification by the World Health Organization teratoma represents the main benign Germ cell tumors of the sinus region and presents similar histological aspects with its counterparts in the gonads and other extragonadal sites. The purpose of this study is to present a case of epignathus originating from the base of the skull in a Caucasian female patient with a cleft palate after the incisive foramen, not affecting the nasal floor. During physical examination, via intraoral route, in the region below the base of the skull, an extensive solid mass, covered by mucosa and with the presence of hair. Computed tomography confirmed the lesion, in the region corresponding to the base of the patient’s skull. The first surgical approach of resection occurred at the 40th day of the patient’s life, under general anesthesia and subsequent primary closure of the palatal defect. The second surgery was performed 10 months later, when tissue expanders were used on the palate to increase the mucosal surface. At the age of 5, the patient underwent surgery with a tongue flap, from the lingual dorsum, with an anterior pedicle. The patient was kept under sedation and relaxation for a period of 10 days for flap autonomy. After this period, the section of the flap and the reconstruction of the tongue dorsum were performed. The patient had a good evolution and was maintained under outpatient treatment. Pediatricians and pediatric dentists should be aware of the importance of prenatal exams and soon after birth, to identify possible deformities in neonatal patients, which favors the diagnosis. The 17-year postoperative follow-up of complete surgical removal of the teratoma and reconstruction of the cleft palate, combining the use of a tissue expander on the palate and a flap on the dorsum of the tongue, proved to be a viable resource for improving the patient’s quality of life.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"9 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"124441087","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
V. Modgill, Bogdan Balas, Minghan Chi, P. Honigmann, F. Thieringer, N. Sharma
{"title":"Knowledge Domain and Innovation Trends Concerning Medical 3D Printing for Craniomaxillofacial Surgery Applications: A 30-Year Bibliometric and Visualized Analysis","authors":"V. Modgill, Bogdan Balas, Minghan Chi, P. Honigmann, F. Thieringer, N. Sharma","doi":"10.1177/27528464231170964","DOIUrl":"https://doi.org/10.1177/27528464231170964","url":null,"abstract":"Study Design: Descriptive study (review containing bibliometric analyses). Objective: Since the inception of three-dimensional printing (3DP), various studies have been conducted worldwide to investigate the utilization of 3DP in craniomaxillofacial (CMF) surgery. Analyzing the current state of global research in medical 3DP in CMF surgery is a crucial first step in identifying knowledge gaps and focusing research resources on pressing problems that have not yet been addressed. Therefore, the current study was designed to present a comprehensive review of scientific research data to discover trends in the last 30 years of global research on 3DP in CMF surgery. Methods: All publications from 1994 until 14 February 2023 were retrieved from the core collection of Web of Science using a defined search. Detailed bibliographic data for all retrieved publications were collected. The bibliometric analysis was performed using VOS viewer, Histcite, and Microsoft Excel. Results: A total of 1367 evaluable articles were retrieved. Results showed that although there is an exponential increase in the number of publications related to 3DP in CMF surgery, there is a substantial regionalization of research, with the U.S.A. and China being the most significant contributors to the retrieved articles. It was also observed that there is a scarcity of published literature related to bioprinting in CMF surgery. Conclusion: This is the first study that specifically analyzed the published literature concerning 3DP in CMF surgery in a structured quantitative manner. The study found a concentration of research in specific geographies and indicated a need for more diversified research in this field. The study also identified a need for public sector involvement in such research to aid in the further dissemination of knowledge.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"47 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"116601706","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Multi-suture craniosynostosis in Sotos Syndrome: A case Report","authors":"Sultan Z. Al-Shaqsi, Christopher R. Forrest","doi":"10.1177/27528464231166828","DOIUrl":"https://doi.org/10.1177/27528464231166828","url":null,"abstract":"Case report. Sotos syndrome is a rare genetic disorder which is characterized by excessive physical growth during the first few years of life. The principal features of this condition include macrocephaly, learning disability and physical overgrowth. The current diagnosis of Sotos Syndrome is based on identification of genetic mutations and deletions in the NSD family (the Nuclear-receptor-binding SET-Domain containing protein). Single suture craniosynostosis has been reported in a few cases of Sotos syndrome. We report an atypical presentation of multi-suture craniosynostosis in a child with Sotos Syndrome. The initial phenotypical presentation was consistent with left coronal craniosynostosis. She underwent strip suturectomy and orthotic helmeting with failure to correct her anterior plagiocephaly and orbital dysmorphology. Additional post-operative investigations revealed a multi-suture craniosynostosis. She subsequently underwent an anterior cranial vault reconstruction and fronto-orbital advancement. Sotos Syndrome can be associated with single or multi-suture craniosynostosis. This is likely driven by the overgrowth status of this disease. In our case report, the patient presents with unicoronal craniosynostosis which progressed to multi-suture craniosynostosis. Therefore, a multidisciplinary approach and close monitoring by craniofacial surgeons, neurosurgeons, developmental paediatricians and other allied teams is required in the care of such patients.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"39 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"123291027","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Delayed Onset Facial Palsy After Temporal Bone Fracture: A Case Series","authors":"Patrick Barba, Isaac Solomon, J. Greene","doi":"10.1177/27528464231151654","DOIUrl":"https://doi.org/10.1177/27528464231151654","url":null,"abstract":"Retrospective Case Series This study’s objective is to identify gaps in facial trauma care by exploring 4 cases of delayed onset facial nerve palsy after temporal bone fracture. A retrospective chart review was performed on 4 patients who presented to the emergency department with facial palsy after a previous trauma. Relevant physical exam findings, radiological images and follow-up was documented. We present a case series of young, previously healthy patients who presented to the emergency department days or weeks after traumatic temporal bone fracture with delayed onset unilateral facial nerve paralysis. None of these patients were warned of this potential complication, connected to an outpatient physician and all received a costly workup. Patients presenting with temporal bone fracture and intact facial nerve function can develop delayed-onset facial paralysis several days after their injury. To offset costly and stressful return visits to the emergency department, patients with temporal bone fractures along the course of the facial nerve should receive education regarding the possible delayed development of facial palsy prior to discharge and otolaryngological or primary care follow-up within 2 weeks of the injury.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"31 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"121513145","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Unilateral Severe Condylar Resorption Following Internal Fixation in Bilateral Mandibular Condylar Fracture","authors":"R. Sasaki, Noriko Sangu Miyamoto, T. Okamoto","doi":"10.1177/27528464231167305","DOIUrl":"https://doi.org/10.1177/27528464231167305","url":null,"abstract":"Case Report A severe condylar resorption following internal fixation of the mandibular condylar fracture is rarely reported. A 35-year-old female caused bilateral condylar base fracture due to fall. She had no connective tissue autoimmune disease, no temporomandibular joint (TMJ) problems, and no history of the orthodontic treatment. Each fractures of condyles were fixed by 2 none-locking titanium miniplates on ideal lines of the osteosynthesis. 6 months after surgery, although patient showed no malocclusion and no TMJ pain, panoramic X-ray showed left side condylar head resorption. Twelve months after surgery, bilateral plate removal was performed. Twenty-six months after internal fixation, panoramic X-ray showed bone formation at the left side of the condylar head. Magnetic resonance imaging of the TMJ showed left TMJ disc displacement without reduction and severe deformity of the left condylar head. The condylar resorption might be caused by increasing functional loading due to new position of the condyle following osteosynthesis. Possible contributors for condylar resorption following osteosynthesis were: (1) internal fixation in bilateral condylar fracture, (2) disc displacement without reduction, and (3) female patient (hormonally-mediated theory, eg estrogen). However, the mechanize of condylar resorption was unclear and the further studies were necessary.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"23 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"125153528","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
{"title":"Bilateral TMJ Ankylosis: Total Joint Reconstruction in a Patient With Zero Mouth Opening: A Case Report","authors":"I. Malakuti, A. Thor","doi":"10.1177/27528464231163667","DOIUrl":"https://doi.org/10.1177/27528464231163667","url":null,"abstract":"Present a case of a young patient with bilateral bony ankylosis of the TMJ with zero mouth opening treated with TMJ prosthesis. The ankylosis was studied in detail with computed tomography (CT) and we used virtual surgical planning in the pre-operative phase to provide splints and cutting guides. The patient was treated with bilateral custom-made alloplastic TMJ prosthesis. Optimal functional improvement at the 5.5 year follow up after total joint reconstruction without any adverse effects. Mouth opening was 35 mm and the patient was free from pain. CT-images showed no signs of pathology or increased remodeling and bone formation. Ankylosis of the TMJ in young and adult population presents unique challenges given the need to account for growth of the mandible and anatomical variations. This report supports the use of total joint reconstruction for end-stage TMJ disease.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"136 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"122133670","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
M. Aycart, A. Banwell, Sultan Z. Al-Shaqsi, V. Kratky, N. Wolter, A. Kulkarni, Christopher R. Forrest, J. Riesel
{"title":"Resection and Reconstruction of a Giant Paranasal Osteoma in a Pediatric Patient","authors":"M. Aycart, A. Banwell, Sultan Z. Al-Shaqsi, V. Kratky, N. Wolter, A. Kulkarni, Christopher R. Forrest, J. Riesel","doi":"10.1177/27528464231167306","DOIUrl":"https://doi.org/10.1177/27528464231167306","url":null,"abstract":"Case Report. Paranasal osteomas are rare, benign bony tumors of the craniofacial skeleton and most are treated endoscopically without the need for reconstruction. In rare cases, open traditional craniofacial approaches are required with a paucity of literature describing extirpative maneuvers in this setting. We present a unique case of a rapidly growing, paranasal bony tumor in a pediatric patient and describe our surgical technique for resection and reconstruction. A 13-year old male presented with eight months of progressive, painless right periorbital swelling and proptosis. Trans-nasal biopsy confirmed an osteoma of the right ethmoid sinus and endoscopic resection was recommended. Due to interval tumor growth, there was worsening visual acuity that precluded a minimally invasive approach. Pre-operative and post-operative 3D computed tomography (CT) scans were completed, and a 3D printed skull model was produced to aid in surgical planning. A multi-disciplinary team of Otolaryngology, Neurosurgery, and Plastic Surgery was employed. The majority of the extirpation was performed with a highspeed carbide burr. Post-operative course was unremarkable and CT scan demonstrated a complete resection. Pathology confirmed the diagnosis of an osteoma. Six-month follow-up demonstrated normal ophthalmologic function and visual acuity with excellent aesthetic results. This is a rare, complex presentation of a paranasal osteoma that was successfully managed with an open, multi-disciplinary approach. We highlight pearls gleaned from this extirpative and reconstructive technique. Due to the tumor density and location, a multidisciplinary team, Stealth navigation, an open, intra- and extra-cranial approach and use of a highspeed carbide burr were essential.","PeriodicalId":314444,"journal":{"name":"Craniomaxillofacial Research & Innovation","volume":"12 1","pages":"0"},"PeriodicalIF":0.0,"publicationDate":"2023-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"115253970","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}