Klinefelter综合征:一种突触的神经发育疾病。

IF 5.1 2区 医学 Q1 NEUROSCIENCES
Helen Zhao , Dan Zhou , Yolanda Feng , Gabriel G. Haddad
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引用次数: 0

摘要

Klinefelter综合征;47,XXY)是最常见的性染色体疾病,大约每500到650个新生儿中就有1个受到影响。患有KS的儿童表现出一系列的表型表现,包括异常的神经认知表型。然而,由于对中枢神经系统的研究有限,我们在细胞和分子水平上对KS的神经生物学的理解仍然很大程度上不清楚。在这项研究中,我们利用来自多能干细胞的皮质类器官和转录组学分析来探索KS患者早期大脑发育缺陷的机制。我们证明KS类器官显示改变神经发生,胶质发生和谷氨酸信号通路。我们认为这些早期的改变导致了KS患者大脑发育异常和后来的认知表型。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Klinefelter syndrome: A neurodevelopmental disease of the synapse
Klinefelter syndrome (KS; 47,XXY) is the most common sex chromosome disorder, affecting approximately 1 in every 500 to 650 newborn males. Children with KS display a spectrum of phenotypic manifestations, including abnormal neurocognitive phenotypes. However, due to the limited research focusing on the central nervous system, our understanding of the neurobiology of KS at the cellular and molecular levels remains largely unclear. In this study, we utilized cortical organoids derived from pluripotent stem cells and transcriptomic analysis to explore the mechanisms underlying early brain developmental defects in KS patients. We demonstrate that KS organoids display altered neurogenesis, gliogenesis, and glutamate signaling pathways. We believe these early alterations contribute to the abnormal brain development and later cognitive phenotypes in KS patients.
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来源期刊
Neurobiology of Disease
Neurobiology of Disease 医学-神经科学
CiteScore
11.20
自引率
3.30%
发文量
270
审稿时长
76 days
期刊介绍: Neurobiology of Disease is a major international journal at the interface between basic and clinical neuroscience. The journal provides a forum for the publication of top quality research papers on: molecular and cellular definitions of disease mechanisms, the neural systems and underpinning behavioral disorders, the genetics of inherited neurological and psychiatric diseases, nervous system aging, and findings relevant to the development of new therapies.
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