Psychological adjustment of siblings of children with Prader-Willi syndrome

IF 16.4 1区化学 Q1 CHEMISTRY, MULTIDISCIPLINARY

Accounts of Chemical Research Pub Date : 2022-11-02 DOI:10.3109/13668250.2022.2132630

L. B. Bennett Murphy, Jane Thornton, E. Thornton

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引用次数: 0

Abstract

ABSTRACT Background Siblings of children with Prader-Willi syndrome (PWS) may be at elevated risk for poor psychological adjustment (Mazaheri, M. M., Rae-Seebach, R. D., Preston, H. E., Schmidt, M., Kountz-Edwards, S., Field, N., Cassidy, S., Packman, Wet al. (2013). The impact of Prader-Willi syndrome on the family’s quality of life and caregiving, and the unaffected siblings’ psychosocial adjustment. Journal of Intellectual Disability Research, 57(9), 861–873. ; O’Neill, L. P., & Murray, L. E. (2016). Anxiety and depression symptomatology in adult siblings of individuals with different developmental disability diagnoses. Research in Developmental Disabilities, 51, 116–125. ). The current study describes psychological distress and symptoms of post-traumatic stress disorder (PTSD) in non-disabled siblings. Method Fifty-eight siblings and 86 parents participated. Results Parents reported that almost 40% of siblings had psychological symptoms that exceeded clinical cut-off scores; 58.9% of siblings reported symptoms of PTSD that exceeded diagnostic cut-off scores. Symptoms were significantly related to family organisation and control per parent report and negative affect per sibling report. Conclusion Growing up with a sibling with PWS may challenge adaptive resources of non-disabled siblings, leaving them vulnerable to psychological distress. Those who care for children with PWS are in a unique position to educate families about the potential vulnerability of non-disabled siblings. We encourage routine screening and support for affected family members, especially siblings.

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普瑞德-威利综合征患儿兄弟姐妹的心理调整

背景:prad - willi综合征(PWS)患儿的兄弟姐妹可能存在较高的心理适应不良风险(Mazaheri, M. M.， Rae-Seebach, R. D.， Preston, H. E.， Schmidt, M.， Kountz-Edwards, S.， Field, N.， Cassidy, S.， Packman, Wet al.， 2013)。Prader-Willi综合征对家庭生活质量和照顾的影响，以及未受影响的兄弟姐妹的心理社会适应。智障研究，57(9)，861-873。;O 'Neill, L. P.和Murray, L. E.(2016)。不同发育障碍诊断个体的成年兄弟姐妹的焦虑和抑郁症状。发育障碍研究，51,116-125。)．目前的研究描述了非残疾兄弟姐妹的心理困扰和创伤后应激障碍(PTSD)的症状。方法对58名兄弟姐妹和86名家长进行调查。结果父母报告近40%的兄弟姐妹有超过临床分值的心理症状;58.9%的兄弟姐妹报告的PTSD症状超过了诊断临界值。症状与父母报告的家庭组织和控制显著相关，与兄弟姐妹报告的负面影响显著相关。结论与患有PWS的兄弟姐妹一起成长可能会挑战非残疾兄弟姐妹的适应资源，使他们容易受到心理困扰。那些照顾患有PWS儿童的人处于一个独特的地位，可以教育家庭了解非残疾兄弟姐妹的潜在脆弱性。我们鼓励对受影响的家庭成员，特别是兄弟姐妹进行常规筛查和支持。

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来源期刊

Accounts of Chemical Research 化学-化学综合

CiteScore

31.40

自引率

1.10%

发文量

312

审稿时长

2 months

期刊介绍： Accounts of Chemical Research presents short, concise and critical articles offering easy-to-read overviews of basic research and applications in all areas of chemistry and biochemistry. These short reviews focus on research from the author’s own laboratory and are designed to teach the reader about a research project. In addition, Accounts of Chemical Research publishes commentaries that give an informed opinion on a current research problem. Special Issues online are devoted to a single topic of unusual activity and significance. Accounts of Chemical Research replaces the traditional article abstract with an article "Conspectus." These entries synopsize the research affording the reader a closer look at the content and significance of an article. Through this provision of a more detailed description of the article contents, the Conspectus enhances the article's discoverability by search engines and the exposure for the research.