先天性高铁血红蛋白血症:卡塔尔阿拉伯人群中CYB5R基因新变体的首例确诊病例:病例报告。

IF 2.1 Q3 HEMATOLOGY
Abdulrahman Al-Abdulmalek, Reem Al-Sulaiman, Mohammad Abu-Tineh, Mohamed A Yassin
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引用次数: 0

摘要

高铁血红蛋白血症(MetHb)是一种罕见的血液学条件的特点是高铁血红蛋白水平在血液中。它发生在血红蛋白被氧化时,导致缺氧和紫绀,这可能发生在遗传或获得形式。遗传性或先天性高铁血红蛋白血症是一种罕见的常染色体隐性遗传病,从未在阿拉伯人群中报道过。在这里,我们报告一个22岁的阿拉伯男性阳性家族史,谁提出了蓝色的手指和嘴唇变色,被发现有高铁血红蛋白血症。对患者及其家族的遗传研究发现,CYB5R3外显子5 c.431G>A p.Gly144Asp可能致病变异和CYB5R3外显子9 c.871G>A p.Val291Met变异存在复合杂合变异,意义未知。我们认为新的c.871G>A p.Val291Met变异可能是高铁血红蛋白血症的病因。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Congenital Methemoglobinemia: First Confirmed Case in the Arab Population with a Novel Variant in the <i>CYB5R</i> Gene in the State of Qatar: A Case Report.

Congenital Methemoglobinemia: First Confirmed Case in the Arab Population with a Novel Variant in the <i>CYB5R</i> Gene in the State of Qatar: A Case Report.

Congenital Methemoglobinemia: First Confirmed Case in the Arab Population with a Novel Variant in the CYB5R Gene in the State of Qatar: A Case Report.

Methemoglobinemia (MetHb) is a rare hematological condition characterized by high methemoglobin levels in the blood. It happens when hemoglobin is oxidized, resulting in hypoxia and cyanosis, which may occur in inherited or acquired forms. Inherited or congenital methemoglobinemia is a rare autosomal recessive condition and has never been reported in the Arab population. Here we report a case of a 22-year-old Arab man with a positive family history who presented with bluish discoloration of the fingers and lips and was found to have methemoglobinemia. Genetic study on the patient and his family revealed compound heterozygous variants in the CYB5R3 Exon 5 c.431G>A p.Gly144Asp likely pathogenic variant and CYB5R3 Exon 9 c.871G>A p.Val291Met variant of unknown significance. We suggest that the novel c.871G>A p.Val291Met variant could be causative for methemoglobinemia.

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来源期刊
CiteScore
3.50
自引率
0.00%
发文量
94
审稿时长
16 weeks
期刊介绍: The Journal of Blood Medicine is an international, peer-reviewed, open access, online journal publishing laboratory, experimental and clinical aspects of all topics pertaining to blood based medicine including but not limited to: Transfusion Medicine (blood components, stem cell transplantation, apheresis, gene based therapeutics), Blood collection, Donor issues, Transmittable diseases, and Blood banking logistics, Immunohematology, Artificial and alternative blood based therapeutics, Hematology including disorders/pathology related to leukocytes/immunology, red cells, platelets and hemostasis, Biotechnology/nanotechnology of blood related medicine, Legal aspects of blood medicine, Historical perspectives. Original research, short reports, reviews, case reports and commentaries are invited.
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