SAPHO综合征:目前的临床、诊断和治疗方法。

IF 3.2 3区 医学 Q2 RHEUMATOLOGY
Rheumatology International Pub Date : 2024-11-01 Epub Date: 2023-10-27 DOI:10.1007/s00296-023-05491-3
Tuba Demirci Yildirim, İsmail Sari
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引用次数: 0

摘要

这篇综述概述了SAPHO(滑膜炎、痤疮、脓疱病、骨质增生症和Osteitis),这是一种罕见的自身炎症性疾病,主要影响骨骼、皮肤和关节。我们在Medline/PubMed上使用关键词进行了搜索,如SAPHO综合征、慢性复发性多灶性骨炎/骨髓炎和相关术语。SAPHO综合征是罕见的,据报道在高加索人群中发生率为万分之一。然而,SAPHO综合征的实际发病率尚不清楚,而且该疾病的发病率可能更高。SAPHO综合征的发病机制尚不完全清楚。目前的证据表明,SAPHO是由免疫失调、遗传易感性和环境因素之间的复杂相互作用引起的。目前尚不清楚SAPHO综合征是一种自身免疫性疾病还是一种自身炎症性疾病,但目前的证据表明,它更有可能是一种自体炎症性疾病。原因包括中性粒细胞过度活跃、自然杀伤细胞减少、白细胞介素-1水平高,以及对阻断IL-1的治疗反应良好。骨关节(OA)受累是SAPHO的一个重要临床特征。它影响胸前壁、轴骨、周围关节、下颌骨、四肢长骨和骨盆。皮肤科受累是SAPHO的常见目标,60-90%的病例出现病变。常见的皮肤病变包括银屑病和痤疮,化脓性汗疹和中性粒细胞性皮肤病不太常见。其他临床发现包括全身炎症引起的体质症状,如发烧、体重减轻和疲劳。SAPHO综合征没有具体的实验室发现。然而,在活动性疾病期间,阳性急性期标志物可能会增加,如血沉(ESR)、C反应蛋白(CRP)、补体水平、轻度白细胞增多和血小板增多。SAPHO综合征缺乏特定的诊断发现,且经常被低估,诊断对其至关重要。对患者的病史和身体检查进行全面评估至关重要。治疗方案包括非甾体抗炎药(NSAIDs)、皮质类固醇、常规和合成疾病调节剂(cDMARDs和sDMARDs)、生物疗法、双磷酸盐和抗生素。对于对传统治疗没有反应的SAPHO患者,生物治疗已成为一种可行的替代方案。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

SAPHO syndrome: current clinical, diagnostic and treatment approaches.

SAPHO syndrome: current clinical, diagnostic and treatment approaches.

This review provides an overview of SAPHO (Synovitis, Acne, Pustulosis, Hyperostosis, and Osteitis), a rare autoinflammatory disease that primarily affects bones, skin, and joints. We conducted a search on Medline/PubMed using keywords such as SAPHO syndrome, chronic recurrent multifocal osteitis/osteomyelitis, and related terms. SAPHO syndrome is rare, with a reported frequency of 1 in 10,000 in the Caucasian population. However, the actual incidence of SAPHO syndrome is unknown, and the incidence of the disease is likely higher. The pathogenesis of SAPHO syndrome remains incompletely understood. Current evidence suggests that SAPHO results from a complex interplay between immune dysregulation, genetic susceptibility, and environmental factors. It's not clear if SAPHO syndrome is an autoimmune disease or an autoinflammatory disease, but current evidence suggests that it's more likely an autoinflammatory disease because of things like neutrophil hyperactivity, fewer natural killer (NK) cells, high levels of interleukin (IL)-1, and a good response to treatments that block IL-1. Osteo-articular (OA) involvement is a key clinical feature of SAPHO. It affects the anterior chest wall, axial skeleton, peripheral joints, mandible, long bones of the extremities, and pelvis. Dermatological involvement is a common target in SAPHO, with lesions observed in 60-90% of cases. Common skin lesions include psoriasis and acne, with hidradenitis suppurativa and neutrophilic dermatoses being less commonly seen. Other clinical findings include constitutional symptoms caused by systemic inflammation, such as fever, weight loss, and fatigue. There is no specific laboratory finding for SAPHO syndrome. However, during active disease, there may be an increase in positive acute phase markers, such as erythrocyte sedimentation rate (ESR), C-reactive protein (CRP), complement levels, mild leukocytosis, and thrombocytosis. Diagnosis is crucial for SAPHO syndrome, which lacks a specific diagnostic finding and is often underrecognized. A comprehensive evaluation of a patient's medical history and physical examination is crucial. Treatment options include non-steroidal anti-inflammatory drugs (NSAIDs), corticosteroids, conventional and synthetic disease-modifying agents (cDMARDs and sDMARDs), biological therapies, bisphosphonates, and antibiotics. Biological treatments have emerged as a viable alternative for SAPHO patients who do not respond to conventional treatments.

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来源期刊
Rheumatology International
Rheumatology International 医学-风湿病学
CiteScore
7.30
自引率
5.00%
发文量
191
审稿时长
16. months
期刊介绍: RHEUMATOLOGY INTERNATIONAL is an independent journal reflecting world-wide progress in the research, diagnosis and treatment of the various rheumatic diseases. It is designed to serve researchers and clinicians in the field of rheumatology. RHEUMATOLOGY INTERNATIONAL will cover all modern trends in clinical research as well as in the management of rheumatic diseases. Special emphasis will be given to public health issues related to rheumatic diseases, applying rheumatology research to clinical practice, epidemiology of rheumatic diseases, diagnostic tests for rheumatic diseases, patient reported outcomes (PROs) in rheumatology and evidence on education of rheumatology. Contributions to these topics will appear in the form of original publications, short communications, editorials, and reviews. "Letters to the editor" will be welcome as an enhancement to discussion. Basic science research, including in vitro or animal studies, is discouraged to submit, as we will only review studies on humans with an epidemological or clinical perspective. Case reports without a proper review of the literatura (Case-based Reviews) will not be published. Every effort will be made to ensure speed of publication while maintaining a high standard of contents and production. Manuscripts submitted for publication must contain a statement to the effect that all human studies have been reviewed by the appropriate ethics committee and have therefore been performed in accordance with the ethical standards laid down in an appropriate version of the 1964 Declaration of Helsinki. It should also be stated clearly in the text that all persons gave their informed consent prior to their inclusion in the study. Details that might disclose the identity of the subjects under study should be omitted.
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