成人先天性咽网:一例罕见临床异常的联合治疗

Katrina Minutello, Steven Pinther, R. Stachler
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引用次数: 1

摘要

主题介绍以前的报道先天性咽网,虽然罕见,已经描述了儿童。临床表现各不相同,从误吸到间歇性气道阻塞,最常见的是吞咽困难。在这个病例报告中,作者描述了一个不寻常的发现下咽网在成人患者。该患者既往无放化疗史、恶性肿瘤史或全喉切除术史,所有这些病史均与获得性咽部狭窄相关,支持此发现为先天性起源。在回顾了可能的胚胎发育异常后,假设是在发育过程中肠道再通失败。我们报告一个40多岁的女性,有固体食物吞咽困难的病史,在三个月内体重减轻了20公斤。患者否认吞咽困难进展为液体,吞咽疼痛,有酒精或烟草使用史。经喉镜检查喉部,发现先天性下咽网。通过消融成功切除腹膜,恢复梨状窦正常引流至食道,并显著改善吞咽功能和体重增加。结论:咽蹼是罕见的发现,特别是在成人患者中。这些先天性畸形可以通过内窥镜消融安全有效地治疗。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Congenital Pharyngeal Web in an Adult: Treatment of a Rare Clinical Anomaly by Coblation
INTRODUCTION TO THE TOPIC Previous reports of congenital pharyngeal webs, although rare, have been described in children. Clinical presentation varies, ranging from aspiration to intermittent airway obstruction, and most commonly, dysphagia. In this case report, the authors describe an unusual finding of a hypopharyngeal web in an adult patient. This patient had no prior history of chemoradiotherapy, malignancy, or total laryngectomy, all of which have been associated with acquired pharyngeal stenosis, supporting that this finding was of congenital origin. After a review of the possible embryological developmental abnormalities, the hypothesis is that of gut recanalization failure during development. CASE PRESENTATION We present a case of a woman in her mid-40’s with a history of solid food dysphagia resulting in a 20 kg weight loss over three months. The patient denied dysphagia progressing to liquids, pain with swallowing, and a history of alcohol or tobacco use. Upon examination of the larynx via laryngoscope, a congenital hypopharyngeal web was identified. Successful excision of the web via coblation restored proper drainage of the pyriform sinus into the esophagus and resulted in markedly improved swallowing function and weight gain. CONCLUSIONS Pharyngeal webs are rare findings, particularly in adult patients. These congenital anomalies can be safely and effectively treated endoscopically via coblation.
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