步态失调症伴上肢运动过度表现为AARS2相关白质脑病。

IF 2.5 Q2 CLINICAL NEUROLOGY
Tremor and Other Hyperkinetic Movements Pub Date : 2022-08-02 eCollection Date: 2022-01-01 DOI:10.5334/tohm.705
Arka Prava Chakraborty, Adreesh Mukherjee, Aishee Bhattacharyya, Dwaipayan Bhattacharyya, Biman Kanti Ray, Atanu Biswas
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引用次数: 0

摘要

55岁男性患者表现为步态失用症,上肢运动夸张,认知功能相对保留,肢体轻度痉挛。他的研究通过下一代测序发现了脑磁共振成像(MRI)的后显性白质营养不良和线粒体丙烯酰转移RNA合成酶2 (AARS2)的复合杂合突变。他无症状的兄弟也有MRI改变,有轻微的锥体征象。AARS2突变是线粒体脑病的罕见病因,可引起白质营养不良伴卵巢早衰、婴儿心肌病、肺发育不全和肌病。步态失用症是这种罕见线粒体脑肌病的主要表现特征,迄今尚未报道。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Gait Apraxia with Exaggerated Upper Limb Movements as Presentation of AARS2 Related Leukoencephalopathy.

A 55-year-old male presented with apraxia of gait with exaggerated upper limb movement with relative preservation of cognition and mild spasticity of limbs. His investigations reveal posterior-predominant leukodystrophy in brain magnetic resonance imaging (MRI) and compound heterozygous mutations in mitochondrial alanyl-transfer RNA synthetase 2 (AARS2) by next generation sequencing. His asymptomatic brother also has MRI changes with subtle mild pyramidal signs. AARS2 mutation is a rare cause of mitochondrial encephalopathy which may give rise to leukodystrophy with premature ovarian failure, infantile cardiomyopathy, lung hypoplasia and myopathy. Gait apraxia as primary presenting feature of this rare variant of mitochondrial encephalomyopathy is hitherto un-reported.

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来源期刊
CiteScore
4.00
自引率
4.50%
发文量
31
审稿时长
6 weeks
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