通过眼睛测量 CRISPR 基因编辑在镰状细胞病患者中的疗效。

IF 0.7 Q4 HEMATOLOGY
Case Reports in Hematology Pub Date : 2022-08-22 eCollection Date: 2022-01-01 DOI:10.1155/2022/6079631
Alexander Pinhas, Davis B Zhou, Oscar Otero-Marquez, Maria V Castanos Toral, Justin V Migacz, Jeffrey Glassberg, Richard B Rosen, Toco Y P Chui
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引用次数: 0

摘要

镰状细胞病(SCD)存在于一个表型谱系中,其遗传表达性各不相同,因此很难评估患者在任何特定时间点出现并发症的风险。目前和新出现的 SCD 治疗方法(包括基于 CRISPR 的基因编辑)会导致不同比例的受影响红细胞(RBC)仍然容易发生镰状细胞病。临床血清学指标(如血红蛋白、间接胆红素和网织红细胞计数)和临床指标(包括一段时间内急诊就诊和住院次数)往往无法客观量化缺血性疾病的活动性和治疗效果。显然,我们需要更好的临床生物标志物。眼科组学领域发展迅速,它利用眼部组织的透明性直接研究视网膜微血管,以确定全身性疾病的状况。在本病例报告中,我们展示了光学相干断层血管成像(OCT-A)检测和测量视网膜毛细血管床在红细胞交换输血前后和基于 CRISPR 的基因编辑后的微闭塞事件的能力,以此作为全身性缺血性疾病活动的指标和治疗效果的衡量标准。本文讨论了这些发现的意义。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Efficacy of CRISPR-Based Gene Editing in a Sickle Cell Disease Patient as Measured through the Eye.

Efficacy of CRISPR-Based Gene Editing in a Sickle Cell Disease Patient as Measured through the Eye.

Sickle cell disease (SCD) exists on a phenotypic spectrum with variable genetic expressivity, making it difficult to assess an individual patient's risk of complications at any particular point in time. Current and emerging SCD treatments, including CRISPR-based gene editing, result in a variable proportion of affected red blood cells (RBCs) still vulnerable to sickling. Clinical serological indicators of disease such as hemoglobin, indirect bilirubin, and reticulocyte count and clinical metrics including number of emergency department visits and hospitalizations over time often fall short in their ability to objectively quantify ischemic disease activity and efficacy of treatments. Clearly, better clinical biomarkers are needed. The rapidly developing field of oculomics leverages the transparent nature of the ocular tissue to directly study the retinal microvasculature in order to characterize the status of systemic diseases. In this case report, we demonstrate the ability of optical coherence tomography angiography (OCT-A) to detect and measure micro-occlusive events within the retinal capillary bed before and after RBC exchange transfusion and following CRISPR-based gene editing, as an indicator of systemic ischemic disease activity and measure of treatment efficacy. The implications of these findings are discussed.

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