28例一岁以内诊断的神经胶质及混合神经胶质肿瘤的临床病理研究。

IF 0.8 4区 医学 Q4 CLINICAL NEUROLOGY
Anna Maria Buccoliero, Chiara Caporalini, Selene Moscardi, Barbara Spacca, Mirko Scagnet, Francesca Castiglione, Iacopo Sardi, Laura Giunti, Lorenzo Genitori
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引用次数: 0

摘要

我们的目的是调查1岁以内受中枢神经系统肿瘤影响的儿童中胶质瘤和神经胶质肿瘤的发病率、结局以及H3.3K27M、BRAFV600E和IDH状况。我们收集了28个连续的胶质瘤和混合瘤。对福尔马林固定/石蜡包埋标本进行免疫组织化学和/或分子分析。24例(86%)肿瘤位于幕上。星形细胞瘤15例(54%)(胶质母细胞瘤5例,间变性星形细胞瘤1例,毛细胞星形细胞瘤1例,毛细胞样星形细胞瘤3例,室管膜下巨细胞星形细胞瘤2例,星形细胞瘤3例(NOS)),间变性室管膜瘤4例(14%),混合性肿瘤9例(32%)(神经节神经胶质瘤5例,神经节细胞瘤2例,结缔组织增生性婴儿神经节神经胶质瘤2例(DIGs))。存活患者中:高级别星形细胞瘤4例(67%)(平均随访64个月),低级别星形细胞瘤4例(67%)(平均随访83个月),星形细胞瘤NOS 2例(67%)(平均随访60个月),间变性室管膜瘤1例(25%)(随访12个月),混合性肿瘤9例(100%)(平均随访74个月)。H3.3K27M和IDH在所有肿瘤中均未发生突变(100%)。6例(21%)肿瘤(4例神经节胶质瘤、1例神经节细胞瘤和1例星形细胞瘤)中发现BRAFV600E突变,8年后发生间变性多形性黄色星形细胞瘤。1岁以内诊断的胶质瘤和混合性肿瘤在形态学上具有异质性。此外,与影响大龄儿童的基因类似,它们是IDH1-2和H3.3K27M(当位于中线外时)不突变,而BRAFV600E突变是神经节胶质瘤/神经节细胞瘤和多形性黄色细胞瘤的典型突变。高级别星形细胞瘤与发生在生命后期的相同病变相比,预后较好,而室管膜瘤的预后较差。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Clinical-pathological study of 28 glial and mixed neuronal-glial tumors diagnosed within the first year of life.

Our purpose was to investigate the incidence of gliomas and neuronal-glial tumors, their outcome, and H3.3K27M, BRAFV600E, and IDH status in children within 1 year of age affected by CNS tumor. We collected 28 consecutive gliomas and mixed tumors. Immunohistochemistry and/or molecular analyses were performed on formalin-fixed/paraffin-embedded specimens. 24 (86%) tumors were supratentorial. 15 (54%) tumors were astrocytomas (5 glioblastomas, 1 anaplastic astrocytoma, 1 pilocytic astrocytoma, 3 pilomixoid astrocytomas, 2 subependymal giant cell astrocytomas, 3 astrocytomas not otherwise specified (NOS)), 4 (14%) were anaplastic ependymomas, and 9 (32%) were mixed tumors (5 gangliogliomas, 2 gangliocytomas, 2 desmoplastic infantile gangliogliomas (DIGs)). Alive patients were: 4 (67%) affected by high-grade astrocytoma (mean follow-up 64 months), 4 (67%) affected by low-grade astrocytoma (mean follow-up 83 months), 2 (67%) affected by astrocytoma NOS (mean follow-up 60 months), 1 (25%) affected by anaplastic ependymoma (follow-up 12 months), and 9 (100%) affected by mixed tumors (mean follow-up 74 months). H3.3K27M and IDH were not-mutated in any tumor (100%). BRAFV600E mutation was documented in 6 (21%) tumors (4 gangliogliomas, 1 gangliocytoma, and 1 astrocytoma NOS resulted as anaplastic pleomorphic xanthoastrocytoma 8 years later). Gliomas and mixed tumors diagnosed within 1 year of age are morphologically heterogeneous. Moreover, analogously to those affecting older children, they are IDH1-2 and H3.3K27M (when located outside midline) not-mutated while BRAFV600E mutation is typical of gangliogliomas/gangliocytomas and pleomorphic xanthoastrocytomas. High-grade astrocytomas have a more favorable prognosis compared with the same lesions occurring later in life while ependymomas have a poorer outcome.

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来源期刊
Clinical Neuropathology
Clinical Neuropathology 医学-病理学
CiteScore
1.60
自引率
0.00%
发文量
70
审稿时长
>12 weeks
期刊介绍: Clinical Neuropathology appears bi-monthly and publishes reviews and editorials, original papers, short communications and reports on recent advances in the entire field of clinical neuropathology. Papers on experimental neuropathologic subjects are accepted if they bear a close relationship to human diseases. Correspondence (letters to the editors) and current information including book announcements will also be published.
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