FMRP核糖核蛋白复合物与RNA稳态。

4区 生物学 Q2 Biochemistry, Genetics and Molecular Biology
Advances in Genetics Pub Date : 2020-01-01 Epub Date: 2020-02-06 DOI:10.1016/bs.adgen.2020.01.001
Gabriela Aparecida Marcondes Suardi, Luciana Amaral Haddad
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引用次数: 9

摘要

脆性智力迟钝1基因(FMR1)位于Xq27.3,编码脆性智力迟钝蛋白(FMRP),并在其5'-非翻译区显示一系列可能发生动态突变的多态性CGG三联体重复序列。脆性X染色体综合征(FXS)是男性遗传性智力残疾的主要原因,最常见的原因是FMR1完全突变和随之而来的转录抑制。FMR1前突变可能与至少两种其他临床疾病相关,称为脆性x相关性原发性卵巢功能不全(FXPOI)和震颤和共济失调综合征(FXTAS)。虽然FXPOI和FXTAS似乎是由FMR1 mRNA积累、FMRP相对减少和三联体重复翻译介导的,但FXS是由于缺乏rna结合蛋白FMRP介导的。除了在神经元和干细胞/祖细胞中作为mRNA翻译抑制因子外,FMRP还具有RNA编辑作用。在这篇综述中,我们简要介绍了FMR1转录微卫星及其相关的临床疾病,并讨论了FMRP在核糖核蛋白复合物组装和运输中的分子作用,以及FXS细胞中受影响的RNA稳态方面。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
FMRP ribonucleoprotein complexes and RNA homeostasis.

The Fragile Mental Retardation 1 gene (FMR1), at Xq27.3, encodes the fragile mental retardation protein (FMRP), and displays in its 5'-untranslated region a series of polymorphic CGG triplet repeats that may undergo dynamic mutation. Fragile X syndrome (FXS) is the leading cause of inherited intellectual disability among men, and is most frequently due to FMR1 full mutation and consequent transcription repression. FMR1 premutations may associate with at least two other clinical conditions, named fragile X-associated primary ovarian insufficiency (FXPOI) and tremor and ataxia syndrome (FXTAS). While FXPOI and FXTAS appear to be mediated by FMR1 mRNA accumulation, relative reduction of FMRP, and triplet repeat translation, FXS is due to the lack of the RNA-binding protein FMRP. Besides its function as mRNA translation repressor in neuronal and stem/progenitor cells, RNA editing roles have been assigned to FMRP. In this review, we provide a brief description of FMR1 transcribed microsatellite and associated clinical disorders, and discuss FMRP molecular roles in ribonucleoprotein complex assembly and trafficking, as well as aspects of RNA homeostasis affected in FXS cells.

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来源期刊
Advances in Genetics
Advances in Genetics 生物-遗传学
CiteScore
5.70
自引率
0.00%
发文量
1
审稿时长
1 months
期刊介绍: Advances in Genetics presents an eclectic mix of articles of use to all human and molecular geneticists. They are written and edited by recognized leaders in the field and make this an essential series of books for anyone in the genetics field.
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