[突触成熟和自闭症:从神经素模型小鼠的学习]。

Katsuhiko Tabuchi, WenHsin Chang, WenHsin Hang, Nur Farehan Asgar, Nur Farehan Mohamed Asgar, Gopal Pramanik
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引用次数: 0

摘要

自闭症是一种神经发育障碍,其特征是社交互动、沟通障碍以及限制和重复行为。突触缺陷与自闭症有关;尽管如此,原因仍然很大程度上是未知的。在特发性自闭症患者中发现的首个单基因突变是神经素-3 (R451C)残基451处的半胱氨酸取代精氨酸。为了研究这种突变和自闭症之间的关系,我们制造了具有这种突变的敲入小鼠。敲入小鼠出生和成长正常,没有表现出任何主要的身体表型,但在社会交往方面表现出缺陷。我们研究了体感皮层第II/III层锥体神经元的突触功能,发现敲入小鼠的抑制性突触传递增强。GABA阻滞剂的施用挽救了社会互动,这表明这导致了这些小鼠的自闭症行为。我们还发现,通过Morris水迷宫测试,敲入小鼠的空间学习和记忆能力显著增强。海马CA1区电生理显示LTP、NMDA/AMPA比值、NR2B功能增强,提示敲入小鼠突触成熟受损。这可能会导致自闭症患者偶尔出现的社会行为缺陷和非凡的记忆能力。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
[Synapse maturation and autism: learning from neuroligin model mice].

Autism is a neurodevelopmental disorder characterized by impairments in social interaction, communication, and restricted and repetitive behavior. Synaptic defects have been implicated in autism; nevertheless, the cause is still largely unknown. A mutation that substitutes cysteine for arginine at residue 451 of Neuroligin-3 (R451C) is the first monogenic mutation identified in idiopathic autism patients. To study the relationship between this mutation and autism, we generated knock-in mice that recapitulated this mutation. The knock-in mice were born and grew up normally without showing any major physical phenotypes, but showed a deficit in social interaction. We studied synaptic function in the layer II/III pyramidal neurons in the somatosensory cortex and found inhibitory synaptic transmission was enhanced in the knock-in mice. The administration of GABA blocker rescued social interaction, suggesting that this caused autistic behavior in these mice. We also found, by Morris water maze test, that spatial learning and memory were significantly enhanced in the knock-in mice. Electrophysiology in the CA1 region of the hippocampus revealed that LTP, the NMDA/AMPA ratio, and NR2B function were enhanced, indicating that synaptic maturation was impaired in the knock-in mice. This may cause the deficit in social behavior and extraordinary memory ability occasionally seen in autistic patients.

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