皮肤及粘膜部位炎性肌成纤维细胞瘤:3例临床病理及分子分析,并着重于鉴别诊断。

IF 1.4 4区 医学 Q3 PATHOLOGY
Danting Xiong, Xiaona Yin, Yongli Gan, Wenjuan Gan, Xiao Cheng, Ming Zhao
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引用次数: 0

摘要

本研究报告了三例发生在浅表部位的alk重排炎性肌纤维母细胞瘤(IMTs)的分子确诊病例,显示了它们的罕见性、临床病理异质性和诊断复杂性。这一系列肿瘤包括口咽粘膜、前臂真皮/皮下组织和舌粘膜。组织病理学检查显示梭形到卵形细胞的特征性增生,呈束状排列在不同的胶原到黏液样基质中,并伴有慢性炎症浸润。显著的形态学变化包括:(1)横纹肌母细胞分化为横纹肌样形态和desmin,一例MyoD1和myogenin共表达,组织学上与炎性横纹肌母细胞瘤重叠;(2)组织细胞样形态,胞浆呈微泡状,类似于非神经颗粒细胞瘤。所有病例均表现出较强的弥漫细胞质ALK免疫反应性。分子分析在两例中发现DCTN1(外显子26)::ALK(外显子20)融合,在舌病变中发现TIMP3(外显子1)::ALK(外显子19)融合,后者证实了TIMP3::ALK融合与头颈部粘膜部位之间的关联。完全切除后随访4-30个月,所有患者均无疾病。这些发现扩大了皮肤和浅表粘膜alk重排IMTs的已知形态谱,同时强调了综合组织病理学和分子病理学评估在区分这些肿瘤与它们的组织模拟物(如炎性横纹肌母细胞瘤、非神经颗粒细胞瘤和上皮样纤维组织细胞瘤/浅表alk重排黏液样梭形细胞肿瘤)方面不可或缺的作用。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Inflammatory myofibroblastic tumors of the skin and mucosal sites: A clinicopathological and molecular analysis of 3 cases with emphasis on differential diagnosis.

This study presents three molecularly confirmed cases of ALK-rearranged inflammatory myofibroblastic tumors (IMTs) occurring in superficial locations, demonstrating their rarity, clinicopathologic heterogeneity and diagnostic complexity. The series comprised tumors involving oropharyngeal mucosa, dermal/subcutaneous tissue of the forearm, and tongue mucosa. Histopathological evaluation revealed characteristic proliferations of spindle-to-ovoid cells arranged in fascicular patterns within variably collagenous to myxoid stroma, accompanied by chronic inflammatory infiltrates. Notable morphologic variations included: (1) rhabdomyoblastic differentiation evidenced by rhabdoid morphology and desmin, MyoD1 and myogenin co-expression in one case, histologically overlapping with inflammatory rhabdomyoblastic tumor; and (2) histiocytoid morphology featuring microvesicular cytoplasm in another case, resembling non-neural granular cell tumor. All cases exhibited strong diffuse cytoplasmic ALK immunoreactivity. Molecular profiling identified DCTN1(exon26)::ALK(exon20) fusions in two cases and TIMP3(exon1)::ALK(exon19) fusion in the lingual lesion, the latter corroborating established associations between TIMP3::ALK fusions and head/neck mucosal sites. With follow-up periods of 4-30 months post complete resection, all patients remained disease-free. These findings expand the recognized morphologic spectrum of cutaneous and superficial mucosal ALK-rearranged IMTs while underscoring the indispensable role of integrated histopathologic and molecular pathologic evaluation in differentiating these neoplasms from their histologic mimics, such as inflammatory rhabdomyoblastic tumor, non-neural granular cell tumor, and epithelioid fibrous histiocytoma/superficial ALK-rearranged myxoid spindle cell neoplasm.

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来源期刊
CiteScore
3.90
自引率
5.00%
发文量
149
审稿时长
26 days
期刊介绍: A peer-reviewed journal devoted to the publication of articles dealing with traditional morphologic studies using standard diagnostic techniques and stressing clinicopathological correlations and scientific observation of relevance to the daily practice of pathology. Special features include pathologic-radiologic correlations and pathologic-cytologic correlations.
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