年轻女性筛窦原发滑膜肉瘤:罕见合并结节性硬化症的病例。

IF 0.7
Elias Edward Lahham, Marwan Qubaja, Rahmeh Deek, Mohammad Abuzir, Mahmoud Ramahi, Ibrahem Eid
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引用次数: 0

摘要

滑膜肉瘤是一种罕见的侵袭性软组织恶性肿瘤,累及头颈部的病例占一小部分。筛窦定位是非常罕见的,只有少数病例记录在文献中。我们报告一例34岁的女性,她发展为进行性右侧鼻塞和鼻出血,影像学显示局部侵入性筛样肿块。组织病理学和免疫组织化学分析证实了低分化滑膜肉瘤的诊断。顺便提一下,肾脏和颅内的检查结果提示可能有结节性硬化症。患者接受多模式治疗,包括新辅助化疗(异环磷酰胺和阿霉素)、放疗和内镜手术切除。术后影像学显示肿瘤完全清除,组织学证实无残留恶性肿瘤。该病例强调了筛样滑膜肉瘤的诊断和治疗挑战,强调了个体化、多学科治疗的重要性,同时也提出了与结节性硬化症的关联,值得进一步探讨。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Primary Synovial Sarcoma of the Ethmoid Sinus in a Young Female: A Rare Case Associated With Tuberous Sclerosis Complex.

Synovial sarcoma is a rare and aggressive soft tissue malignancy, with head and neck involvement comprising a small fraction of cases. Ethmoid sinus localization is exceptionally rare, with only a few cases documented in the literature. We present the case of a 34-year-old female who developed progressive right-sided nasal obstruction and epistaxis, with imaging revealing a locally invasive ethmoidal mass. Histopathological and immunohistochemical analysis confirmed a diagnosis of poorly differentiated synovial sarcoma. Incidentally, renal and intracranial findings suggested a possible underlying tuberous sclerosis complex. The patient was managed with a multimodal approach, including neoadjuvant chemotherapy (ifosfamide and doxorubicin), radiotherapy, and endoscopic surgical resection. Postoperative imaging demonstrated complete tumor clearance, and histology confirmed no residual malignancy. This case highlights the diagnostic and therapeutic challenges posed by ethmoidal synovial sarcoma and underscores the importance of individualized, multidisciplinary care, while also presenting an association with tuberous sclerosis that warrants further exploration.

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