恩替尼治疗NTRK融合阳性结肠癌期间肿瘤反应与PTTM进展的分离

IF 3.4 4区 医学 Q2 ONCOLOGY
Hideki Nagano, Shigekazu Ohyama, Atsushi Sato, Jun Igarashi, Tomoko Yamamoto, Mikiko Kobayashi
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引用次数: 0

摘要

我们报告一例罕见的肺肿瘤血栓性微血管病(PTTM)发生在转移性神经营养性原肌球蛋白受体激酶(NTRK)融合阳性的横贯结肠癌患者,该患者对恩替尼表现出明显的放射学和生化反应。尽管肿瘤明显缩小,但在治疗开始后大约四周出现进行性呼吸困难和低氧血症。胸部CT显示弥漫性间质浸润,最初解释为药物性肺炎或感染。恩替尼停用,但呼吸衰竭进展,患者此后不久死亡。尸检显示广泛的肺微血管病变伴纤维细胞内膜增生和小肺动脉肿瘤栓塞,符合PTTM。值得注意的是,没有发现血液转移;相反,肿瘤似乎是通过胸导管的非典型淋巴途径扩散的。肿瘤表现出微卫星稳定性和适度的突变负担,表明淋巴播散和微血管病理可能独立于这些基因组特征而发展。该病例强调了肿瘤反应和血管并发症之间的关键分离,表明原肌球蛋白受体激酶(TRK)抑制剂单药治疗可能不足以预防PTTM。综合治疗可能需要同时针对肺微血管的策略,包括抗血管生成治疗和细胞因子和生长因子信号的调节。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Dissociation Between Tumor Response and PTTM Progression During Entrectinib Therapy in NTRK Fusion-Positive Colon Cancer.

We report a rare case of pulmonary tumor thrombotic microangiopathy (PTTM) in a patient with metastatic neurotrophic tropomyosin receptor kinase (NTRK) fusion-positive transverse colon cancer who exhibited a marked radiologic and biochemical response to entrectinib. Despite significant tumor shrinkage, progressive dyspnea and hypoxemia developed approximately four weeks after therapy initiation. Chest CT revealed diffuse interstitial infiltrates, initially interpreted as drug-induced pneumonitis or infection. Entrectinib was discontinued, but respiratory failure progressed, and the patient died shortly thereafter. Autopsy revealed widespread pulmonary microangiopathy with fibrocellular intimal proliferation and tumor emboli in small pulmonary arteries, consistent with PTTM. Notably, no hematogenous metastases were identified; instead, tumor spread appeared to occur via an atypical lymphatic route through the thoracic duct. The tumor exhibited microsatellite stability and a modest mutation burden, suggesting that lymphatic dissemination and microvascular pathology may progress independently of these genomic features. This case underscores a critical dissociation between oncologic response and vascular complications, indicating that tropomyosin receptor kinase (TRK) inhibitor monotherapy may be insufficient to prevent PTTM. Comprehensive management may require concurrent strategies targeting the pulmonary microvasculature, including antiangiogenic therapy and modulation of cytokine and growth factor signaling.

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来源期刊
Current oncology
Current oncology ONCOLOGY-
CiteScore
3.30
自引率
7.70%
发文量
664
审稿时长
1 months
期刊介绍: Current Oncology is a peer-reviewed, Canadian-based and internationally respected journal. Current Oncology represents a multidisciplinary medium encompassing health care workers in the field of cancer therapy in Canada to report upon and to review progress in the management of this disease. We encourage submissions from all fields of cancer medicine, including radiation oncology, surgical oncology, medical oncology, pediatric oncology, pathology, and cancer rehabilitation and survivorship. Articles published in the journal typically contain information that is relevant directly to clinical oncology practice, and have clear potential for application to the current or future practice of cancer medicine.
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