18岁男性支气管源性囊肿继发气管压迫1例报告

IF 0.2 Q4 PEDIATRICS
Shruthi Srinivas , Nicholas A. Zumberge , Ashley L. Miller , Jennifer MacDonald , Jennifer H. Aldrink , Sara A. Mansfield
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引用次数: 0

摘要

哮喘是儿科最常见的呼吸系统疾病;然而,误诊率正在稳步上升。识别具有相似症状的手术治疗条件对于确保及时治疗至关重要。病例介绍一名18岁健康男性,因咳嗽和呼吸短促到儿科医生和急诊科就诊后被诊断为哮喘。几周后,他被开抗生素、强的松、沙丁胺醇和氟替卡松,但没有好转。他急性恶化,并表现出呼吸窘迫归因于状态哮喘。他需要紧急插管,在推进气管内插管(ETT)时遇到阻力,这很困难。计算机断层成像显示纵隔上有一个巨大的囊性肿块,气管压迫远端气管。转到我们的设施后,他急性代偿失调,呼吸需求恶化,低血压需要血管加压药物。在多学科讨论后,他被带到手术室进行肿块吸出和刚性支气管镜检查。超声引导下经皮引流肿物后,他的潮气量立即改善,支气管镜检查显示阻塞减轻。术后他已脱离呼吸支持并拔管。引流造影剂研究显示与食管或气管没有连接,并显示气管受压,向腔内注入造影剂。最终,他接受了肿瘤的彻底切除,功能恢复良好。病理证实为先天性支气管囊肿。结论支气管源性囊肿可引起气道受压,表现为新的哮喘样症状。它们甚至会引起急性气道阻塞。对于出现新的哮喘样症状但对标准治疗无效的患者,应及时排除支气管源性囊肿。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Tracheal compression secondary to a bronchogenic cyst in an 18-year-old male: a case report

Introduction

Asthma is the most common pediatric respiratory disease; however, misdiagnosis is steadily increasing. Identification of surgically managed conditions with similar symptoms is essential to ensuring timely management.

Case presentation

An 18-year-old healthy male was diagnosed with asthma after visits to the pediatrician and Emergency Department for cough and shortness of breath. For several weeks, he was prescribed antibiotics, prednisone, albuterol, and fluticasone without improvement. He acutely worsened and presented with respiratory distress attributed to status asthmaticus. He required emergent intubation, which was difficult given resistance when advancing the endotracheal tube (ETT). Cross-sectional imaging with computed tomography demonstrated a large superior mediastinal cystic mass with tracheal compression distal to the ETT. After transfer to our facility, he acutely decompensated with worsening ventilatory needs and hypotension requiring vasopressors. After a multidisciplinary discussion, he was brought to the operating room for aspiration of the mass and rigid bronchoscopy. Ultrasound-guided percutaneous drainage of the mass was achieved with immediate improvement in his tidal volumes and evidence of alleviated obstruction on bronchoscopy. He was weaned from respiratory support and extubated postoperatively. A drain contrast study demonstrated no connection to the esophagus or trachea and showed tracheal compression with instillation of contrast into the cavity. Ultimately, he underwent definitive resection of the mass and has had excellent functional recovery. Pathology confirmed a congenital bronchogenic cyst.

Conclusion

Bronchogenic cysts can cause airway compression, which may present as new asthma-like symptoms. They can even cause acute airway obstruction. Bronchogenic cysts should be promptly ruled out in patients who develop new asthma-like symptoms but fail to respond to standard treatments.
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来源期刊
CiteScore
0.60
自引率
25.00%
发文量
348
审稿时长
15 days
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