BCR::ABL1融合的混合表型急性白血病不同解剖部位的不同B/髓细胞和t淋巴母细胞群

IF 0.6 4区 医学 Q4 HEMATOLOGY
Gina L Sotolongo, Luis F Carrillo, Ken H Young, Jadee L Neff, Eric D Carlsen
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引用次数: 0

摘要

急性白血病恶性细胞的多能性是一个日益增长的科学和临床兴趣领域。混合表型急性白血病(MPALs)的定义是存在至少两个谱系分化的母细胞。奇怪的是,MPALs表现出一些与单系急性白血病相同的复发性细胞遗传学异常(例如,BCR::ABL1, KMT2A重排)。在单系和混合表型急性白血病中,导致细胞群体表型选择和分化的因素尚不完全清楚。MPAL的最佳治疗管理仍然是一个有争议的问题。在此,我们报告一例MPAL合并BCR::ABL1融合,在不同解剖部位(分别为扁桃体和骨髓)显示出不同的t淋巴母细胞和b淋巴母细胞/髓母细胞群。两个胚群都显示出与克隆相关的TRG重排,这是克隆进化的证据。患者最初对酪氨酸激酶抑制剂治疗有反应,但他很快复发并在诊断一年后死亡。据我们所知,这是首次在treatment-naïve患者中显示MPAL具有不同的爆炸谱系分离到不同的解剖部位。本病例强调了对急性白血病采取多方面诊断方法的重要性,并强调了对这些知之甚少的肿瘤的生物学和治疗还有待学习。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Distinct B/myeloid and T-lymphoblast populations at separate anatomic sites in mixed-phenotype acute leukemia with BCR::ABL1 fusion.

The pluripotency of malignant blasts in acute leukemias is a growing area of scientific and clinical interest. Mixed-phenotype acute leukemias (MPALs) are defined by the presence of blasts showing evidence of differentiation along at least two lineages. Curiously, MPALs exhibit some of the same recurrent cytogenetic abnormalities (e.g., BCR::ABL1, KMT2A rearrangements) that are seen in single-lineage acute leukemias. Factors that contribute to phenotypic selection and divergence of blast populations in single-lineage and mixed-phenotype acute leukemias are incompletely understood. Optimal therapeutic management of MPAL also remains a matter of debate. Herein, we present a case of MPAL with BCR::ABL1 fusion that showed distinct T-lymphoblastic and B-lymphoblastic/myeloblastic populations at different anatomic sites (tonsil and bone marrow, respectively). Both blast populations showed clonally related TRG rearrangements with evidence of clonal evolution. The patient initially responded to tyrosine kinase inhibitor therapy, but he quickly relapsed and expired a year after diagnosis. To our knowledge, this is the first time an MPAL has been shown to have different blast lineages segregated to distinct anatomic sites in a treatment-naïve patient. This case emphasizes the importance of a multifaceted diagnostic approach to acute leukemias and highlights what is left to learn about the biology and management of these poorly understood neoplasms.

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来源期刊
Journal of Hematopathology
Journal of Hematopathology HEMATOLOGYPATHOLOGY-PATHOLOGY
CiteScore
0.80
自引率
0.00%
发文量
45
期刊介绍: The Journal of Hematopathology aims at providing pathologists with a special interest in hematopathology with all the information needed to perform modern pathology in evaluating lymphoid tissues and bone marrow. To this end the journal publishes reviews, editorials, comments, original papers, guidelines and protocols, papers on ancillary techniques, and occasional case reports in the fields of the pathology, molecular biology, and clinical features of diseases of the hematopoietic system. The journal is the unique reference point for all pathologists with an interest in hematopathology. Molecular biologists involved in the expanding field of molecular diagnostics and research on lymphomas and leukemia benefit from the journal, too. Furthermore, the journal is of major interest for hematologists dealing with patients suffering from lymphomas, leukemias, and other diseases. The journal is unique in its true international character. Especially in the field of hematopathology it is clear that there are huge geographical variations in incidence of diseases. This is not only locally relevant, but due to globalization, relevant for all those involved in the management of patients.
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