冯希佩尔-林道综合征的叙事回顾:从发现到现代医学和外科治疗。

IF 1.9 Q3 ONCOLOGY
Journal of Kidney Cancer and VHL Pub Date : 2025-09-05 eCollection Date: 2025-01-01 DOI:10.15586/jkc.v12i3.396
Danilo Coco, Silvana Leanza
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引用次数: 0

摘要

von Hippel-Lindau (VHL)综合征是一种罕见的常染色体显性遗传病,由VHL肿瘤抑制基因突变引起,可导致多种器官发生良性和恶性肿瘤,包括肾脏、脑、脊柱、视网膜和胰腺。自20世纪初首次描述以来,在了解其发病机制、遗传基础和临床管理方面取得了重大进展。这篇叙述性综述提供了VHL综合征的全面概述,从它的发现到最新的医学和外科治疗。按照系统评价和荟萃分析的首选报告项目(PRISMA)指南进行了系统文献综述,并采用Egger检验来评估发表偏倚。这篇综述强调了诊断标准的演变,基因检测的作用,以及靶向治疗的发展,如缺氧诱导因子2- α (HIF-2α)抑制剂。手术干预,包括肾保留手术和微创技术,也进行了讨论。本综述强调了多学科方法治疗VHL综合征的重要性,并探讨了有望改善患者预后的新兴疗法。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Narrative Review of Von Hippel-Lindau Syndrome: From Discovery to Modern Medical and Surgical Therapies.

The von Hippel-Lindau (VHL) syndrome is a rare autosomal dominant disorder caused by mutations in the VHL tumor suppressor gene, leading to the development of benign and malignant tumors in multiple organs, including the kidneys, brain, spine, retina, and pancreas. Since its initial description in the early 20th century, significant progress has been made in understanding its pathogenesis, genetic basis, and clinical management. This narrative review provides a comprehensive overview of VHL syndrome, from its discovery to the latest medical and surgical therapies. A systematic literature review was conducted following the Preferred Reporting Items for Systematic Reviews and Meta-Analyses (PRISMA) guidelines, incorporating the Egger test to assess publication bias. The review highlights the evolution of diagnostic criteria, the role of genetic testing, and the development of targeted therapies such as hypoxia-inducible factor 2-alpha (HIF-2α) inhibitors. Surgical interventions, including nephron-sparing surgery and minimally invasive techniques, are also discussed. This review emphasizes the importance of a multidisciplinary approach to managing VHL syndrome and explores emerging therapies that hold promise for improving patient outcomes.

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来源期刊
自引率
6.20%
发文量
22
审稿时长
4 weeks
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