Yu Zhang, Rui Liang, Gabriel Christopher Purnell, Lei Yan, Alia Nazarullah, Sarah Hackman, Courtney Thomas, Aaron M Abarbanell, Aaron Sugalski, Jeffrey L Foster, Linda P Thomas, Phillip Ong, Daniel DeArmond, Marjorie Parker David, Faqian Li
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引用次数: 0
摘要
原发性肺肿瘤在儿科患者中是罕见的。黏液表皮样癌(MEC),典型的低级别和诊断简单,是仅次于类癌肿瘤的第二常见的支气管肿瘤。然而,罕见的MEC可能表现为分化分化,被误诊为低级别腺癌,未进行其他分类,并给临床带来挑战,特别是当荧光原位杂交(FISH)显示mastermind-like protein 2 (MAML2)基因排列为阴性时。在这里,我们报告了一例青少年患者的MAML2 fish阴性低级别支气管肿瘤,根据形态学和免疫表型显示出粘液表皮样和腺泡分化。新一代测序发现了一个CREB调控的转录共激活因子3 (CRTC3::MAML2)融合基因,位于传统易位点的上游,目前可用的FISH探针可能无法检测到。该肿瘤似乎是一种具有粘液表皮样和腺泡双重分化的支气管肿瘤的新表现,最初被描述为粘液腺泡癌,这是一种新提出的MEC亚型,最初被描述为主要唾液腺。
Bronchial mucoacinar carcinoma: a newly proposed subtype of mucoepidermoid carcinoma in the bronchus.
Primary lung tumours are rare in paediatric patients. Mucoepidermoid carcinoma (MEC), typically low-grade and diagnostically straightforward, is the second most common tumour of the bronchus after carcinoid tumours. However, rare MEC may show divergent differentiation, be misdiagnosed as low-grade adenocarcinoma, not otherwise classified, and pose clinical challenges, especially when mastermind-like protein 2 (MAML2) gene arrangement is negative by fluorescence in situ hybridisation (FISH). Here, we report an MAML2 FISH-negative low-grade bronchial tumour in a juvenile patient that demonstrates both mucoepidermoid and acinar differentiation based on morphology and immunophenotype. Next-generation sequencing identified a CREB regulated transcription coactivator 3 (CRTC3::MAML2) fusion gene, located upstream of traditional translocation points and potentially undetectable by currently available FISH probes. This tumour appears to be a novel presentation of a bronchial tumour with dual mucoepidermoid and acinar differentiation, first described as mucoacinar carcinoma-a newly proposed subtype of MEC, originally described in the major salivary gland.
期刊介绍:
Journal of Clinical Pathology is a leading international journal covering all aspects of pathology. Diagnostic and research areas covered include histopathology, virology, haematology, microbiology, cytopathology, chemical pathology, molecular pathology, forensic pathology, dermatopathology, neuropathology and immunopathology. Each issue contains Reviews, Original articles, Short reports, Correspondence and more.