T滤泡辅助细胞淋巴瘤的空间和克隆多发B /浆细胞增殖:1例报告。

IF 3.4 4区 医学 Q2 PATHOLOGY
Yuka Yokota, Naoki Oishi, Kazunari Kasai, Masataka Kawai, Ippei Tahara, Tomohiro Inoue, Yuma Sakamoto, Megumi Koshiish-Yamada, Keita Kirito, Tetsuo Kondo
{"title":"T滤泡辅助细胞淋巴瘤的空间和克隆多发B /浆细胞增殖:1例报告。","authors":"Yuka Yokota, Naoki Oishi, Kazunari Kasai, Masataka Kawai, Ippei Tahara, Tomohiro Inoue, Yuma Sakamoto, Megumi Koshiish-Yamada, Keita Kirito, Tetsuo Kondo","doi":"10.1111/pin.70043","DOIUrl":null,"url":null,"abstract":"<p><p>T follicular helper cell lymphoma (TFHL) is a systemic T-cell lymphoma with a phenotype reminiscent of TFH cells and frequent RHOA p.G17V mutation. Here, we report a case of TFHL with spatially multiple and clonally independent B-/plasma cell proliferations (B/PC-Ps), which posed diagnostic difficulties. An 87-year-old female presented with a skin rash, and a skin biopsy from the chest was initially diagnosed as low-grade B-cell lymphoma with plasmacytic differentiation. Three months after rituximab monotherapy, bilateral pleural effusions developed. Cytology of the pleural effusion revealed abnormal lymphocytes and plasma cells. The abnormal T-cells were positive for CD3, CD4, CD10, and PD1, while the neoplastic plasma cells showed kappa-predominant light-chain restriction. Additional cutaneous biopsies from the left forearm and upper arm revealed Epstein-Barr virus-positive and -negative B/PC-Ps, respectively. Polymerase chain reaction identified RHOA p.G17V and the same monoclonal rearrangement of T-cell receptor gamma gene (TRG) in all the four specimens. In addition, three cutaneous lesions showed distinct monoclonal immunoglobulin heavy chain gene (IGH) rearrangements. This case demonstrates phenotypic and clonal diversity of monoclonal B/PC-Ps in TFHL, which can obscure the neoplastic TFH proliferation. In such cases, careful clinicopathological correlation and the integration of immunophenotypic and genetic analyses may aid in the diagnosis.</p>","PeriodicalId":19806,"journal":{"name":"Pathology International","volume":" ","pages":""},"PeriodicalIF":3.4000,"publicationDate":"2025-08-12","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":"{\"title\":\"Spatially and Clonally Multiple B-/Plasma Cell Proliferations in T Follicular Helper Cell Lymphoma: A Case Report.\",\"authors\":\"Yuka Yokota, Naoki Oishi, Kazunari Kasai, Masataka Kawai, Ippei Tahara, Tomohiro Inoue, Yuma Sakamoto, Megumi Koshiish-Yamada, Keita Kirito, Tetsuo Kondo\",\"doi\":\"10.1111/pin.70043\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<p><p>T follicular helper cell lymphoma (TFHL) is a systemic T-cell lymphoma with a phenotype reminiscent of TFH cells and frequent RHOA p.G17V mutation. Here, we report a case of TFHL with spatially multiple and clonally independent B-/plasma cell proliferations (B/PC-Ps), which posed diagnostic difficulties. An 87-year-old female presented with a skin rash, and a skin biopsy from the chest was initially diagnosed as low-grade B-cell lymphoma with plasmacytic differentiation. Three months after rituximab monotherapy, bilateral pleural effusions developed. Cytology of the pleural effusion revealed abnormal lymphocytes and plasma cells. The abnormal T-cells were positive for CD3, CD4, CD10, and PD1, while the neoplastic plasma cells showed kappa-predominant light-chain restriction. Additional cutaneous biopsies from the left forearm and upper arm revealed Epstein-Barr virus-positive and -negative B/PC-Ps, respectively. Polymerase chain reaction identified RHOA p.G17V and the same monoclonal rearrangement of T-cell receptor gamma gene (TRG) in all the four specimens. In addition, three cutaneous lesions showed distinct monoclonal immunoglobulin heavy chain gene (IGH) rearrangements. This case demonstrates phenotypic and clonal diversity of monoclonal B/PC-Ps in TFHL, which can obscure the neoplastic TFH proliferation. In such cases, careful clinicopathological correlation and the integration of immunophenotypic and genetic analyses may aid in the diagnosis.</p>\",\"PeriodicalId\":19806,\"journal\":{\"name\":\"Pathology International\",\"volume\":\" \",\"pages\":\"\"},\"PeriodicalIF\":3.4000,\"publicationDate\":\"2025-08-12\",\"publicationTypes\":\"Journal Article\",\"fieldsOfStudy\":null,\"isOpenAccess\":false,\"openAccessPdf\":\"\",\"citationCount\":\"0\",\"resultStr\":null,\"platform\":\"Semanticscholar\",\"paperid\":null,\"PeriodicalName\":\"Pathology International\",\"FirstCategoryId\":\"3\",\"ListUrlMain\":\"https://doi.org/10.1111/pin.70043\",\"RegionNum\":4,\"RegionCategory\":\"医学\",\"ArticlePicture\":[],\"TitleCN\":null,\"AbstractTextCN\":null,\"PMCID\":null,\"EPubDate\":\"\",\"PubModel\":\"\",\"JCR\":\"Q2\",\"JCRName\":\"PATHOLOGY\",\"Score\":null,\"Total\":0}","platform":"Semanticscholar","paperid":null,"PeriodicalName":"Pathology International","FirstCategoryId":"3","ListUrlMain":"https://doi.org/10.1111/pin.70043","RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"","PubModel":"","JCR":"Q2","JCRName":"PATHOLOGY","Score":null,"Total":0}
引用次数: 0

摘要

T滤泡辅助细胞淋巴瘤(TFHL)是一种全身性T细胞淋巴瘤,其表型与TFH细胞相似,并且经常发生RHOA p.G17V突变。在这里,我们报告了一例具有空间多重和克隆独立的B-/浆细胞增殖(B/PC-Ps)的TFHL,这给诊断带来了困难。87岁女性患者表现为皮疹,胸部皮肤活检最初诊断为低级别b细胞淋巴瘤伴浆细胞分化。利妥昔单抗单药治疗3个月后出现双侧胸腔积液。胸膜积液细胞学检查显示淋巴细胞和浆细胞异常。异常t细胞CD3、CD4、CD10和PD1阳性,肿瘤浆细胞以kappa为主的轻链限制。左前臂和上臂的皮肤活检分别显示eb病毒阳性和B/PC-Ps阴性。聚合酶链反应在4个标本中鉴定出RHOA p.G17V和相同的t细胞受体γ基因(TRG)单克隆重排。此外,三个皮肤病变显示明显的单克隆免疫球蛋白重链基因(IGH)重排。本病例显示单克隆B/PC-Ps在TFHL中的表型和克隆多样性,这可以掩盖肿瘤性TFH的增殖。在这种情况下,仔细的临床病理相关性和免疫表型和遗传分析的整合可能有助于诊断。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Spatially and Clonally Multiple B-/Plasma Cell Proliferations in T Follicular Helper Cell Lymphoma: A Case Report.

T follicular helper cell lymphoma (TFHL) is a systemic T-cell lymphoma with a phenotype reminiscent of TFH cells and frequent RHOA p.G17V mutation. Here, we report a case of TFHL with spatially multiple and clonally independent B-/plasma cell proliferations (B/PC-Ps), which posed diagnostic difficulties. An 87-year-old female presented with a skin rash, and a skin biopsy from the chest was initially diagnosed as low-grade B-cell lymphoma with plasmacytic differentiation. Three months after rituximab monotherapy, bilateral pleural effusions developed. Cytology of the pleural effusion revealed abnormal lymphocytes and plasma cells. The abnormal T-cells were positive for CD3, CD4, CD10, and PD1, while the neoplastic plasma cells showed kappa-predominant light-chain restriction. Additional cutaneous biopsies from the left forearm and upper arm revealed Epstein-Barr virus-positive and -negative B/PC-Ps, respectively. Polymerase chain reaction identified RHOA p.G17V and the same monoclonal rearrangement of T-cell receptor gamma gene (TRG) in all the four specimens. In addition, three cutaneous lesions showed distinct monoclonal immunoglobulin heavy chain gene (IGH) rearrangements. This case demonstrates phenotypic and clonal diversity of monoclonal B/PC-Ps in TFHL, which can obscure the neoplastic TFH proliferation. In such cases, careful clinicopathological correlation and the integration of immunophenotypic and genetic analyses may aid in the diagnosis.

求助全文
通过发布文献求助,成功后即可免费获取论文全文。 去求助
来源期刊
Pathology International
Pathology International 医学-病理学
CiteScore
4.50
自引率
4.50%
发文量
102
审稿时长
12 months
期刊介绍: Pathology International is the official English journal of the Japanese Society of Pathology, publishing articles of excellence in human and experimental pathology. The Journal focuses on the morphological study of the disease process and/or mechanisms. For human pathology, morphological investigation receives priority but manuscripts describing the result of any ancillary methods (cellular, chemical, immunological and molecular biological) that complement the morphology are accepted. Manuscript on experimental pathology that approach pathologenesis or mechanisms of disease processes are expected to report on the data obtained from models using cellular, biochemical, molecular biological, animal, immunological or other methods in conjunction with morphology. Manuscripts that report data on laboratory medicine (clinical pathology) without significant morphological contribution are not accepted.
×
引用
GB/T 7714-2015
复制
MLA
复制
APA
复制
导出至
BibTeX EndNote RefMan NoteFirst NoteExpress
×
提示
您的信息不完整,为了账户安全,请先补充。
现在去补充
×
提示
您因"违规操作"
具体请查看互助需知
我知道了
×
提示
确定
请完成安全验证×
copy
已复制链接
快去分享给好友吧!
我知道了
右上角分享
点击右上角分享
0
联系我们:info@booksci.cn Book学术提供免费学术资源搜索服务,方便国内外学者检索中英文文献。致力于提供最便捷和优质的服务体验。 Copyright © 2023 布克学术 All rights reserved.
京ICP备2023020795号-1
ghs 京公网安备 11010802042870号
Book学术文献互助
Book学术文献互助群
群 号:604180095
Book学术官方微信