Ischiopagus连体双胞胎1例报告。

IF 0.7 Q3 MEDICINE, GENERAL & INTERNAL
International Medical Case Reports Journal Pub Date : 2025-08-07 eCollection Date: 2025-01-01 DOI:10.2147/IMCRJ.S525402
Abdihakim Elmi Abdi Shakur, Salad Ahmed Halane, Farah Yusuf Farah
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引用次数: 0

摘要

背景:连体双胞胎的出生是一种极其罕见的新生儿疾病,大约发生在100,000个活产婴儿中。Ischiopagus是一种连体双胞胎,双胞胎在骨盆处结合,占所有连体双胞胎的6-11%。Ischiopagus连体双胞胎是一种先天性异常。由于涉及复杂的解剖和生理,手术分离连体双胞胎是具有挑战性的。全面的术前评估,细致的计划和熟练的手术团队是确保手术成功的必要条件。这种情况明显需要分离手术,因为它提出了独特的解剖挑战。临床结果可能因医疗设施和可用资源而异。连体双胞胎的发展一直引起研究人员和临床医生的极大关注。除了这种情况的罕见性,这些双胞胎的发育方式仍然是一个持续争论的话题。本报告描述了一例坐骨连体双胞胎,其特征是两个头(双头),四个上肢(四臂),共用骨盆,单脐带。这对双胞胎的母亲在怀孕期间从一家初级医院索马里苏丹专科医院转到专科医院接受专门护理,在那里进行了剖宫产手术。病例总结:一对双胞胎,34岁,产妇9 para 7,既往无先天性异常,母亲患有糖尿病,正在服用降糖药。父母双方都没有出生缺陷的家族史,也没有接触过已知的致畸物。成像(MRI)显示,这对双胞胎有独立的心脏、肺、肾脏(其中一个肾积水严重)、胃、肝、脾和肛管,但有共同的肠袢,一个胎盘有一个脐静脉,两个脐动脉有一个脐带。此外,他们有子宫样的结构,没有外生殖器。尽管有多种相关的心血管异常,但没有颅面、肢体或脑外异常。这对双胞胎住进新生儿重症监护室,观察到胎便和尿从同一开口(泄殖腔)排出正常。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Ischiopagus Conjoint Twins: A Case Report.

Ischiopagus Conjoint Twins: A Case Report.

Ischiopagus Conjoint Twins: A Case Report.

Background: The birth of conjoined twins is an extremely rare neonatal condition, occurring in approximately 1 in 100,000 live births. Ischiopagus, a form of conjoined twinning where the twins are joined at the pelvis, accounts for 6-11% of all conjoined twins. Ischiopagus conjoined twinning is a congenital anomaly. The surgical separation of conjoined twins is challenging due to the intricate anatomy and physiology involved. Thorough preoperative evaluation, meticulous planning, and a skilled surgical team are essential for ensuring a successful outcome. This condition significantly requires separation surgeries due to the unique anatomical challenges it presents. Clinical outcomes can vary depending on the healthcare facility and resources available. The development of conjoined twins consistently draws significant attention from researchers and clinicians. Aside from the rarity of such cases, the manner in which these twins develop remains a topic of ongoing debate. This report describes a case of ischiopagus conjoined twins, characterized by two heads (dicephalus), four upper limbs (tetrabrachius), and a shared pelvis with single umbilical cord. The mother of the twins was referred from a primary hospital Somali Sudanese Specialized Hospital for specialized care during her twin pregnancy, where a cesarean section was performed.

Case summary: The twins delivered by 34 years old gravida 9 para 7, no previous congenital anomalies, the mother was diabetic and she was on anti-diabetic drugs. Both parents had no family history of birth defects or exposure to known teratogens. Imaging (MRI) revealed that that the twins had separate hearts, lungs, kidneys with severe hydronephrosis in one of them, stomach, liver, spleen, and anal canals but shared the bowel loops, a single placenta with one umbilical vein and two umbilical arteries with single umbilical cord. Additionally, they have uterus-like structure with the absence of external genitalia. Despite multiple associated cardiovascular anomalies, there were no external craniofacial, limb, or brain abnormalities. The twins admitted for the neonatal ICU and observed with normal meconium and urinary passage from same opening (cloaca).

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来源期刊
International Medical Case Reports Journal
International Medical Case Reports Journal MEDICINE, GENERAL & INTERNAL-
CiteScore
1.40
自引率
0.00%
发文量
135
审稿时长
16 weeks
期刊介绍: International Medical Case Reports Journal is an international, peer-reviewed, open access, online journal publishing original case reports from all medical specialties. Submissions should not normally exceed 3,000 words or 4 published pages including figures, diagrams and references. As of 1st April 2019, the International Medical Case Reports Journal will no longer consider meta-analyses for publication.
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