高甘油三酯血症诱发的胰腺炎在弗朗什-蒙塔尼马中的LMF1移码缺失。

IF 3.9 2区 综合性期刊 Q1 MULTIDISCIPLINARY SCIENCES
Michaela Drögemüller, Nathalie Fouché, Michelle Wyler, Corinne Gurtner, Seraina L Meister, Markus Neuditschko, Vidhya Jagannathan, Vinzenz Gerber, Tosso Leeb
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引用次数: 0

摘要

高甘油三酯血症(HTG)可能是遗传的,由编码脂质代谢酶的基因变异引起。这项研究是由观察到的8只弗朗什-蒙塔涅(FM)马驹血浆甘油三酯水平升高和致命性急性胰腺炎发作引起的。我们将这种表型称为高甘油三酯血症诱发的胰腺炎(HIP)。受影响的小马驹与一匹著名的种马有远亲和近交关系,表明常染色体隐性遗传。对一匹患病马驹的全基因组测序发现了编码脂肪酶成熟因子1的LMF1纯合子功能缺失变异。变体XM_023616679.1:c。369_373delinsTCT,导致早期移码,预计会改变或截断78%的LMF1编码序列。我们在2122匹FM马的队列中对该变异进行了基因分型,并鉴定出11只纯合突变动物,包括最初根据其临床表现鉴定出的所有8匹马驹。另外三个纯合突变动物具有相似的表型,并与同一种马近亲繁殖。我们得出结论,所有11人都患了同一种疾病。因此,我们在测试队列中发现了完美的基因型-表型关联。2111匹未受影响的FM马的载波频率为15.0%。我们的发现使基因检测能够防止无意中繁殖出更多的患髋关节的马驹。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

LMF1 frameshift deletion in Franches-Montagnes horses with hypertriglyceridemia-induced pancreatitis.

Hypertriglyceridemia (HTG) may be inherited and caused by variants in genes encoding enzymes of lipid metabolism. This study was prompted by the observation of eight Franches-Montagnes (FM) foals showing elevated plasma triglyceride levels and episodes of fatal acute pancreatitis. We termed this phenotype hypertriglyceridemia-induced pancreatitis (HIP). The affected foals were distantly related and inbred to a prominent stallion suggesting autosomal recessive inheritance. Whole genome sequencing of an affected foal identified a homozygous loss of function variant in LMF1 encoding lipase maturation factor 1. The variant, XM_023616679.1:c.369_373delinsTCT, leads to an early frameshift and is predicted to alter or truncate 78% of the LMF1 coding sequence. We genotyped the variant in a cohort of 2122 FM horses and identified 11 homozygous mutant animals including all eight foals that had initially been identified based on their clinical presentation. The three additional homozygous mutant animals had a comparable phenotype and were inbred to the same stallion. We concluded that all 11 had been affected by the same disease. Thus, we found perfect genotype-phenotype association in the tested cohort. The carrier frequency in the 2111 unaffected FM horses was 15.0%. Our findings enable genetic testing to prevent the unintentional breeding of further HIP-affected foals.

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来源期刊
Scientific Reports
Scientific Reports Natural Science Disciplines-
CiteScore
7.50
自引率
4.30%
发文量
19567
审稿时长
3.9 months
期刊介绍: We publish original research from all areas of the natural sciences, psychology, medicine and engineering. You can learn more about what we publish by browsing our specific scientific subject areas below or explore Scientific Reports by browsing all articles and collections. Scientific Reports has a 2-year impact factor: 4.380 (2021), and is the 6th most-cited journal in the world, with more than 540,000 citations in 2020 (Clarivate Analytics, 2021). •Engineering Engineering covers all aspects of engineering, technology, and applied science. It plays a crucial role in the development of technologies to address some of the world''s biggest challenges, helping to save lives and improve the way we live. •Physical sciences Physical sciences are those academic disciplines that aim to uncover the underlying laws of nature — often written in the language of mathematics. It is a collective term for areas of study including astronomy, chemistry, materials science and physics. •Earth and environmental sciences Earth and environmental sciences cover all aspects of Earth and planetary science and broadly encompass solid Earth processes, surface and atmospheric dynamics, Earth system history, climate and climate change, marine and freshwater systems, and ecology. It also considers the interactions between humans and these systems. •Biological sciences Biological sciences encompass all the divisions of natural sciences examining various aspects of vital processes. The concept includes anatomy, physiology, cell biology, biochemistry and biophysics, and covers all organisms from microorganisms, animals to plants. •Health sciences The health sciences study health, disease and healthcare. This field of study aims to develop knowledge, interventions and technology for use in healthcare to improve the treatment of patients.
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