动力蛋白依赖的内溶酶体降解驱动路易体疾病伴Aβ病理。

IF 14.3 1区 材料科学 Q1 CHEMISTRY, MULTIDISCIPLINARY
Linlin Zhou, Yuwei Wang, Yu Liu, Feipeng Zhu, Ge Gao, Chengjie Li, Pu Ai, Jingying Xu, Junxin Wang, Long Guo, Yuting Guan, Virginia Man-Yee Lee, Jianjun Chen, Jialin Zheng, Qihui Wu
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引用次数: 0

摘要

路易体痴呆(DLB)是痴呆的一个重要原因。然而,准确复制早期DLB发病机制的动物和细胞模型的有限可用性阻碍了对Aβ斑块如何影响α-突触核蛋白(αSyn)病理的理解。本研究通过将原代神经元与来自野生型或阿尔茨海默病(AD)小鼠的成年海马脑切片共培养来解决这一空白,这些海马脑切片含有丰富的Aβ斑块和细胞因子。暴露于AD切片的神经元显示动力蛋白依赖的细胞器运输受损,减少内核溶酶体融合,导致淀粉样蛋白αSyn原纤维降解缺陷,从而增加αSyn内含物。值得注意的是,AD小鼠中动力蛋白的异常预积累表明,在暴露于致病性原纤维时,功能失调的动力蛋白可能是αSyn聚集的成核位点。此外,Rab7激活成功地恢复了具有路易体和Aβ病变的小鼠模型中αSyn原纤维的内溶酶体降解,并减少了包涵体的形成。这些结果突出了动力蛋白依赖的内溶酶体途径是减轻共存的a β负担中α突触相关病理的有希望的治疗靶点,这是许多DLB病例的特征。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Dynein-Dependent Endo-Lysosomal Degradation Drives Lewy Body Disorders Accompanied by Aβ Pathology.

Dementia with Lewy bodies (DLB) is a significant cause of dementia. However, the limited availability of animal and cellular models that accurately replicate early DLB pathogenesis hampers the understanding of how Aβ plaques influence α-synuclein (αSyn) pathologies. This study addresses this gap by co-culturing primary neurons with adult hippocampal brain slices from either wild-type or Alzheimer's disease (AD) mice containing abundant Aβ plaques and cytokines. Neurons exposed to AD slices showed impaired dynein-dependent organelle trafficking, reducing endosome-lysosome fusion and causing defective degradation of amyloidogenic αSyn fibrils, thus increasing αSyn inclusions. Notably, an abnormal pre-accumulation of dynein in AD mice suggests that dysfunctional dynein may serve as a nucleation site for αSyn aggregation upon exposure to pathogenic fibrils. Furthermore, Rab7 activation successfully restored endo-lysosomal degradation of αSyn fibrils and reduced inclusion formation in mouse models presenting with both Lewy body and Aβ pathologies. These results highlight the dynein-dependent endo-lysosomal pathway as a promising therapeutic target for mitigating αSyn-related pathologies in co-existing Aβ burden, characteristic of many DLB cases.

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来源期刊
Advanced Science
Advanced Science CHEMISTRY, MULTIDISCIPLINARYNANOSCIENCE &-NANOSCIENCE & NANOTECHNOLOGY
CiteScore
18.90
自引率
2.60%
发文量
1602
审稿时长
1.9 months
期刊介绍: Advanced Science is a prestigious open access journal that focuses on interdisciplinary research in materials science, physics, chemistry, medical and life sciences, and engineering. The journal aims to promote cutting-edge research by employing a rigorous and impartial review process. It is committed to presenting research articles with the highest quality production standards, ensuring maximum accessibility of top scientific findings. With its vibrant and innovative publication platform, Advanced Science seeks to revolutionize the dissemination and organization of scientific knowledge.
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