Maitry Ronakbhai Trivedi, Amogh Manoj Joshi, Jay Shah, Benjamin P Readhead, Melissa A Wilson, Yi Su, Eric M Reiman, Teresa Wu, Qi Wang
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Herein we developed a deep learning framework, which consisted of multi-layer perceptron (MLP) models to classify neuropathologically confirmed AD versus controls, using bulk tissue RNA-seq data from the RNAseq Harmonization Study of the Accelerating Medicines Project for Alzheimer's Disease (AMP-AD) consortium. The models were trained based on data from three distinct brain regions, including dorsolateral prefrontal cortex (DLPFC), posterior cingulate cortex (PCC), and head of the caudate nucleus (HCN), obtained from the Religious Orders Study/Memory and Aging Project (ROSMAP). Subsequently, we inferred a disease progression trajectory for each brain region by applying unsupervised dimensionality transformation to the distribution of the subjects' expression profiles. To interpret the MLP models, we employed an interpretable method for deep neural network models, obtaining SHapley Additive exPlanations (SHAP) values and identified the most significantly AD-implicated genes for gene co-expression network analysis. Our models demonstrated robust performance in classification and prediction across two other external datasets from the Mayo RNA-seq (MAYO) cohort and the Mount Sinai Brain Bank (MSBB) cohort of AMP-AD. By interpreting the models both mechanistically and biologically, our study elucidated subtle molecular alterations in various brain regions, uncovering shared transcriptomic signatures activated in microglia and sex-specific modules in neurons relevant to AD. Notably, we identified, for the first time, a sex-linked transcription factor pair (ZFX/ZFY) associated with more pronounced neuronal loss in AD females, shedding light on a novel mechanism for sex dimorphism in AD. 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引用次数: 0
摘要
利用人工智能研究阿尔茨海默病(AD)影响脑组织的基因表达失调仍未得到充分探索,特别是在描绘涉及AD相关细胞和分子过程的不同大脑区域的共同和特定转录组特征方面,这可能有助于阐明新的疾病生物学生物标志物和靶点的发现。在此,我们开发了一个深度学习框架,该框架由多层感知器(MLP)模型组成,使用来自阿尔茨海默病加速药物项目(AMP-AD)联盟的RNAseq协调研究的大量组织RNA-seq数据,将神经病理学证实的AD与对照组进行分类。这些模型是基于来自三个不同大脑区域的数据进行训练的,包括背外侧前额叶皮层(DLPFC)、后扣带皮层(PCC)和尾状核头部(HCN),这些数据来自宗教团体研究/记忆和衰老项目(ROSMAP)。随后,我们通过对受试者表达谱的分布进行无监督维数转换,推断出每个大脑区域的疾病进展轨迹。为了解释MLP模型,我们采用深度神经网络模型的可解释方法,获得SHapley加性解释(SHAP)值,并鉴定出最显著的ad相关基因进行基因共表达网络分析。我们的模型在Mayo RNA-seq (Mayo)队列和Mount Sinai Brain Bank (MSBB) AMP-AD队列的其他两个外部数据集上显示了稳健的分类和预测性能。通过从机制和生物学两方面解释这些模型,我们的研究阐明了大脑不同区域的细微分子改变,揭示了与阿尔茨海默病相关的神经元中激活的小胶质细胞和性别特异性模块的共享转录组特征。值得注意的是,我们首次发现了一个与性别相关的转录因子对(ZFX/ZFY)与阿尔茨海默症女性中更明显的神经元丢失有关,从而揭示了阿尔茨海默症性别二态性的新机制。该研究为利用人工智能方法在分子水平上研究AD奠定了基础,这是传统分析方法如差异基因表达(DGE)分析难以实现的。与性别差异相关的转录因子也为阿尔茨海默病女性神经退行性变提供了新的分子机制基础,值得进一步研究。
Interpretable deep learning framework for understanding molecular changes in human brains with Alzheimer's disease: implications for microglia activation and sex differences.
The utilization of artificial intelligence in studying the dysregulation of gene expression in Alzheimer's disease (AD) affected brain tissues remains underexplored, particularly in delineating common and specific transcriptomic signatures across different brain regions implicated in AD-related cellular and molecular processes, which could help illuminate novel disease biology for biomarker and target discovery. Herein we developed a deep learning framework, which consisted of multi-layer perceptron (MLP) models to classify neuropathologically confirmed AD versus controls, using bulk tissue RNA-seq data from the RNAseq Harmonization Study of the Accelerating Medicines Project for Alzheimer's Disease (AMP-AD) consortium. The models were trained based on data from three distinct brain regions, including dorsolateral prefrontal cortex (DLPFC), posterior cingulate cortex (PCC), and head of the caudate nucleus (HCN), obtained from the Religious Orders Study/Memory and Aging Project (ROSMAP). Subsequently, we inferred a disease progression trajectory for each brain region by applying unsupervised dimensionality transformation to the distribution of the subjects' expression profiles. To interpret the MLP models, we employed an interpretable method for deep neural network models, obtaining SHapley Additive exPlanations (SHAP) values and identified the most significantly AD-implicated genes for gene co-expression network analysis. Our models demonstrated robust performance in classification and prediction across two other external datasets from the Mayo RNA-seq (MAYO) cohort and the Mount Sinai Brain Bank (MSBB) cohort of AMP-AD. By interpreting the models both mechanistically and biologically, our study elucidated subtle molecular alterations in various brain regions, uncovering shared transcriptomic signatures activated in microglia and sex-specific modules in neurons relevant to AD. Notably, we identified, for the first time, a sex-linked transcription factor pair (ZFX/ZFY) associated with more pronounced neuronal loss in AD females, shedding light on a novel mechanism for sex dimorphism in AD. This study lays the groundwork for leveraging artificial intelligence methodologies to investigate AD at the molecular level, which is not readily achievable from conventional analysis approaches such as differential gene expression (DGE) analysis. The transcription factor implicated in sex difference also underpins a new molecular mechanistic basis of women's greater neurodegeneration in AD warranting further study.