特纳综合征。

IF 1.6 4区 医学 Q2 PEDIATRICS
Ken L Wan, Emma L Brown, Raj Krishnaswamy, Peter A Kaub
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引用次数: 0

摘要

特纳综合征(TS)是一种性染色体疾病,影响表型女性,她们有一条完整的X染色体和完全或部分缺失的第二性染色体。大约一个世纪前,谢列谢夫斯基、乌尔里希和特纳首次描述了它。然而,TS的细胞遗传学基础仅在1959年由Ford在Tjio和Levan对染色体可视化进行优化后报道。TS核型包括经典的X单体(40%-50%);单体X镶嵌(3%-25%);X同染色体(10%-18%);环X (10%-16%);X单体与正常或结构异常的Y染色体嵌合体(6%-12%);删除Xp (
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Turner Syndrome.

Turner syndrome (TS) is a sex chromosome disorder affecting phenotypic females who have one intact X chromosome and a completely or partially missing second sex chromosome. It was first described approximately a century ago by Seresevskij, Ullrich and Turner. However, the cytogenetic basis of TS was only reported by Ford in 1959 following Tjio and Levan's optimisation of chromosome visualisation. TS karyotypes include classic monosomy X (40%-50%); monosomy X mosaicism (3%-25%); isochromosome X (10%-18%); ring X (10%-16%); mosaicism for monosomy X and a normal or structurally abnormal Y chromosome (6%-12%); deletion Xp (< 5%) and unbalanced X-autosome translocation (< 2%). While parental age does not affect the complete loss of one X chromosome, the paternal X chromosome is absent in three-quarters of patients with TS. Clinically, detecting the parental origin of the remaining X chromosome is not currently useful in routine TS care. Recurrence risk is low for phenotypically normal parents with a child diagnosed with TS. Pregnancy loss is the outcome for the majority (~99%) of TS cases; however, prenatal ultrasound findings for foetuses with TS may include abnormalities like cystic hygroma and hydrops. Postnatal phenotype for patients with TS includes short stature, delayed puberty, ovarian dysgenesis, hypergonadotropic hypogonadism, infertility, cardiac defects, endocrine, metabolic and autoimmune disorders. This review aims to outline clinical indications for testing, describe test methodologies, provide genetic test result examples that highlight complex TS karyotype diagnoses, summarise clinical management options and discuss the phenomenon of 'normal' sex chromosome loss with advancing age.

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来源期刊
CiteScore
2.90
自引率
5.90%
发文量
487
审稿时长
3-6 weeks
期刊介绍: The Journal of Paediatrics and Child Health publishes original research articles of scientific excellence in paediatrics and child health. Research Articles, Case Reports and Letters to the Editor are published, together with invited Reviews, Annotations, Editorial Comments and manuscripts of educational interest.
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