Marian D. Moreno-Urías , Javier E. Anaya-Ayala , Alejandro Celis-Jiménez
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Six months later, the patient was referred having developed aneurysms in the left axillary and right brachial arteries. Open and endovascular approaches were discussed with his parents; endovascular management was opted for. Covered stents (6 x 56 mm and 8 x 56 mm Fluency Plus Endovascular Stent Graft, Becton Dickinson & Co., New Jersey, USA) were successfully placed in the left axillary and right brachial arteries during a single procedure. The patient remained haemodynamically stable and was discharged 24 hours post-operation without complications. At the 24 month follow up, the patient was asymptomatic, and ultrasound confirmed the continued patency of the stents.</div></div><div><h3>Conclusion</h3><div>This case highlights the importance of individualised treatment strategies for paediatric patients with Kawasaki disease complicated by arterial aneurysms. The use of stent grafts in children presents unique challenges, including long-term durability, vessel growth, and thrombosis risk, necessitating careful patient selection and lifelong follow up. The successful outcome observed in this case highlights the potential of endovascular techniques as a viable alternative to open surgery, emphasising the need for further studies to establish standardised guidelines for paediatric vascular interventions.</div></div>","PeriodicalId":36502,"journal":{"name":"EJVES Vascular Forum","volume":"64 ","pages":"Pages 16-19"},"PeriodicalIF":1.4000,"publicationDate":"2025-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":"{\"title\":\"Endovascular Management of Upper Limb Arterial Aneurysms in a Child With Kawasaki Disease\",\"authors\":\"Marian D. Moreno-Urías , Javier E. Anaya-Ayala , Alejandro Celis-Jiménez\",\"doi\":\"10.1016/j.ejvsvf.2025.04.005\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<div><h3>Background</h3><div>Kawasaki disease is an acute, self limited vasculitis that predominantly affects children under five years of age. It is clinically diagnosed by persistent fever for at least five days along with four of the main clinical features. Bilateral upper limb aneurysms are rare in Kawasaki disease, with limited literature comprising case reports and small series, leaving management guidelines unclear.</div></div><div><h3>Report</h3><div>This study presents the case of a three year old male with a history of incomplete Kawasaki disease at eight months of age. Initial treatment included two doses of gammaglobulin after which he was diagnosed with aneurysms in both the left and right coronary arteries; he remained in a stable condition under bi-annual monitoring. Six months later, the patient was referred having developed aneurysms in the left axillary and right brachial arteries. Open and endovascular approaches were discussed with his parents; endovascular management was opted for. Covered stents (6 x 56 mm and 8 x 56 mm Fluency Plus Endovascular Stent Graft, Becton Dickinson & Co., New Jersey, USA) were successfully placed in the left axillary and right brachial arteries during a single procedure. The patient remained haemodynamically stable and was discharged 24 hours post-operation without complications. At the 24 month follow up, the patient was asymptomatic, and ultrasound confirmed the continued patency of the stents.</div></div><div><h3>Conclusion</h3><div>This case highlights the importance of individualised treatment strategies for paediatric patients with Kawasaki disease complicated by arterial aneurysms. The use of stent grafts in children presents unique challenges, including long-term durability, vessel growth, and thrombosis risk, necessitating careful patient selection and lifelong follow up. 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引用次数: 0
摘要
川崎病是一种急性、自限性血管炎,主要影响5岁以下儿童。临床诊断为持续发热至少5天,并伴有4个主要临床特征。双侧上肢动脉瘤在川崎病中是罕见的,文献包括病例报告和小系列,使得治疗指南不明确。本研究报告一例三岁男童,在8个月大时有不完全性川崎病病史。最初的治疗包括两剂丙种球蛋白,之后他被诊断出左右冠状动脉都有动脉瘤;在一年两次的监测下,他的情况稳定。6个月后,患者因左腋动脉和右臂动脉出现动脉瘤而转诊。与父母讨论了开放和血管内入路;选择血管内治疗。覆盖支架(6 × 56毫米和8 × 56毫米)流畅+血管内支架移植物,Becton Dickinson &;Co., New Jersey, USA)在一次手术中成功地放置在左腋窝和右肱动脉中。患者血流动力学稳定,术后24小时出院,无并发症。随访24个月,患者无症状,超声检查证实支架通畅。结论本病例强调儿科川崎病合并动脉瘤患者个体化治疗的重要性。在儿童中使用支架具有独特的挑战,包括长期耐用性、血管生长和血栓形成风险,需要仔细选择患者并终身随访。在本病例中观察到的成功结果突出了血管内技术作为开放手术的可行替代方案的潜力,强调需要进一步研究以建立儿科血管干预的标准化指南。
Endovascular Management of Upper Limb Arterial Aneurysms in a Child With Kawasaki Disease
Background
Kawasaki disease is an acute, self limited vasculitis that predominantly affects children under five years of age. It is clinically diagnosed by persistent fever for at least five days along with four of the main clinical features. Bilateral upper limb aneurysms are rare in Kawasaki disease, with limited literature comprising case reports and small series, leaving management guidelines unclear.
Report
This study presents the case of a three year old male with a history of incomplete Kawasaki disease at eight months of age. Initial treatment included two doses of gammaglobulin after which he was diagnosed with aneurysms in both the left and right coronary arteries; he remained in a stable condition under bi-annual monitoring. Six months later, the patient was referred having developed aneurysms in the left axillary and right brachial arteries. Open and endovascular approaches were discussed with his parents; endovascular management was opted for. Covered stents (6 x 56 mm and 8 x 56 mm Fluency Plus Endovascular Stent Graft, Becton Dickinson & Co., New Jersey, USA) were successfully placed in the left axillary and right brachial arteries during a single procedure. The patient remained haemodynamically stable and was discharged 24 hours post-operation without complications. At the 24 month follow up, the patient was asymptomatic, and ultrasound confirmed the continued patency of the stents.
Conclusion
This case highlights the importance of individualised treatment strategies for paediatric patients with Kawasaki disease complicated by arterial aneurysms. The use of stent grafts in children presents unique challenges, including long-term durability, vessel growth, and thrombosis risk, necessitating careful patient selection and lifelong follow up. The successful outcome observed in this case highlights the potential of endovascular techniques as a viable alternative to open surgery, emphasising the need for further studies to establish standardised guidelines for paediatric vascular interventions.