Emma C Tovey Crutchfield, Andrea L Vincent, Mitchell D Anjou, Hugh R Taylor, Shaun Tatipata, Krystal S Tsosie, Livia S Carvalho, Lauren N Ayton, Alexis Ceecee Britten-Jones
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We included articles reporting Indigenous Peoples with IRDs from all global regions published between 1974 and 2023; 73 studies (581 cases) of IRDs in Indigenous Peoples from 24 countries were included, mostly reporting participants indigenous to the Middle East (34 %), Oceania (27 %) and North America (23 %). Studies of specific IRD cases showed geographical or cultural group associations, such as rod-cone dystrophy among the Diné (Navajo Nation) or Bardet-Biedl syndrome in Bedouin populations of the Middle East. With dedicated programs, population-specific IRD gene variants in the Middle Eastern Bedouin populations, New Zealand Māori and other Pacific peoples are the most well-characterised, and this has enabled improved diagnostic approaches. There is limited knowledge of the relative prevalence and support needs for IRDs among most other global Indigenous groups. 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引用次数: 0
摘要
准确的诊断对于获得针对遗传性视网膜疾病(IRDs)的新兴基因靶向治疗至关重要,但是许多少数群体在诊断方面面临额外的障碍。这篇范围综述综合了世界各地土著居民中IRDs患病率和诊断的临床研究。Medline, Embase, Global Health, Informit和CINAHL的检索时间为2023年12月4日。我们收录了来自全球所有地区的报告有ird的土著居民的文章。1974年至2023年间发表的73项研究(581例)包括来自24个国家的土著居民的ird,主要报告了中东(34%),大洋洲(27%)和北美(23%)的土著参与者。对特定IRD病例的研究显示了地理或文化群体的关联,例如din人(纳瓦霍族)的杆状锥体营养不良症或中东贝都因人的Bardet-Biedl综合征。通过专门的项目,中东贝都因人、新西兰Māori和其他太平洋民族的特定人群的IRD基因变异特征最为明显,这使得改进的诊断方法成为可能。对大多数其他全球土著群体中ird的相对流行程度和支持需求的了解有限。参与、共同设计的方法和集体努力,包括提高认识,可以解决限制土著人民公平获得IRD诊断的挑战,促进获得新兴治疗方法。
Inherited retinal disease in global Indigenous populations: A scoping review.
Accurate diagnosis is essential for accessing emerging gene-targeted treatments for inherited retinal diseases (IRDs), but many minoritised communities face additional barriers to diagnosis. This scoping review synthesised clinical studies on the prevalence and diagnosis of IRDs among Indigenous Peoples worldwide. Medline, Embase, Global Health, Informit and CINAHL were searched on December 4, 2023. We included articles reporting Indigenous Peoples with IRDs from all global regions published between 1974 and 2023; 73 studies (581 cases) of IRDs in Indigenous Peoples from 24 countries were included, mostly reporting participants indigenous to the Middle East (34 %), Oceania (27 %) and North America (23 %). Studies of specific IRD cases showed geographical or cultural group associations, such as rod-cone dystrophy among the Diné (Navajo Nation) or Bardet-Biedl syndrome in Bedouin populations of the Middle East. With dedicated programs, population-specific IRD gene variants in the Middle Eastern Bedouin populations, New Zealand Māori and other Pacific peoples are the most well-characterised, and this has enabled improved diagnostic approaches. There is limited knowledge of the relative prevalence and support needs for IRDs among most other global Indigenous groups. Engagement, co-designed approaches and collective efforts, including raising awareness, may address challenges limiting equitable access to IRD diagnosis for Indigenous Peoples, facilitating access to emerging treatments.
期刊介绍:
Survey of Ophthalmology is a clinically oriented review journal designed to keep ophthalmologists up to date. Comprehensive major review articles, written by experts and stringently refereed, integrate the literature on subjects selected for their clinical importance. Survey also includes feature articles, section reviews, book reviews, and abstracts.