Prader Willi综合征:遗传学进展。

4区 生物学 Q2 Biochemistry, Genetics and Molecular Biology
Advances in Genetics Pub Date : 2025-01-01 Epub Date: 2025-05-05 DOI:10.1016/bs.adgen.2025.03.001
Suhani Hingar, Marc Schneeberger Pané, María José Ortuño Romero
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引用次数: 0

摘要

普瑞德-威利综合征(PWS)是一种复杂的遗传疾病,由染色体15q11.2-q13异常引起,其特征是在整个生命周期中进化出独特的身体、认知和行为特征。早期表现包括婴儿期严重的张力不足、喂养困难和发育不良,后期发展为嗜食、肥胖、智力障碍和行为挑战。其他特征包括生长激素缺乏、身材矮小、青春期延迟和其他内分泌异常。遗传方面的进展已经阐明了印迹基因(如SNORD116)在驱动该综合征核心特征方面的作用,为了解其可变性和严重性提供了见解。包括催产素和胃饥饿素信号在内的靶向途径的新兴研究,为解决贪食和行为症状的创新治疗带来了希望。本章提供了PWS的临床特征、自然史和分子基础的全面概述,强调了早期诊断、多学科护理和精准医学在优化结果和提高PWS患者生活质量方面的重要性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Prader Willi syndrome: advances in genetics.

Prader-Willi syndrome (PWS) is a complex genetic disorder arising from abnormalities on chromosome 15q11.2-q13, characterized by distinct physical, cognitive, and behavioral features that evolve across the lifespan. Early manifestations include severe hypotonia, feeding difficulties, and failure to thrive in infancy, progressing to hyperphagia, obesity, intellectual disabilities, and behavioral challenges in later stages. Additional features include growth hormone deficiency, short stature, delayed puberty, and other endocrine abnormalities. Genetic advances have illuminated the role of imprinted genes, such as SNORD116, in driving the syndrome's core features, offering insights into its variability and severity. Emerging research on targeted pathways, including oxytocin and ghrelin signaling, holds promise for innovative treatments addressing hyperphagia and behavioral symptoms. This chapter provides a comprehensive overview of PWS's clinical features, natural history, and molecular underpinnings, underscoring the importance of early diagnosis, multidisciplinary care, and precision medicine in optimizing outcomes and enhancing the quality of life for individuals with PWS.

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来源期刊
Advances in Genetics
Advances in Genetics 生物-遗传学
CiteScore
5.70
自引率
0.00%
发文量
1
审稿时长
1 months
期刊介绍: Advances in Genetics presents an eclectic mix of articles of use to all human and molecular geneticists. They are written and edited by recognized leaders in the field and make this an essential series of books for anyone in the genetics field.
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