从携带NFIA基因基因内缺失的患者身上衍生的人类诱导多能干细胞系。

IF 3.4 3区 生物学 Q3 CELL BIOLOGY
Ning Zhou, Shengnan Zhang, Chunli Wang, Bixia Zheng, Aihua Zhang, Wei Zhou
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引用次数: 0

摘要

脑畸形伴或不伴尿路缺陷(BRMUTD)是由NFIA基因的杂合变异引起的。BRMUTD是一种以胼胝体发育不全或缺失、脑积水或脑室肿大、发育迟缓为特征的神经发育障碍,可能伴有尿路缺陷,也可能不伴有。在这里,我们报告了利用基于仙台病毒的非整合重编程技术,从一名3岁男性BRMUTD患者成功生成诱导多能干细胞(hiPSCs)。该患者来源的细胞系含有NFIA基因的基因内缺失(NC_000001.10: g.61650967_61842967del [GRCh37]),这与NFIA表达的显著降低有关。该细胞系保持正常核型,表达多能性标记,并可分化为三个胚层。建立的hipsc细胞系将为研究nfia相关神经发育障碍的病理机制和潜在治疗方法提供体外模型。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Generation of human induced pluripotent stem cell lines derived from a patient carrying an intragenic deletion in the NFIA gene.

Brain malformations with or without urinary tract defects (BRMUTD) are caused by heterozygous variants in the NFIA gene. BRMUTD is a neurodevelopmental disorder characterized by hypoplasia or absence of the corpus callosum, hydrocephalus or ventriculomegaly, and developmental delay, which may or may not be accompanied by urinary tract defects. Here, we report the successful generation of induced pluripotent stem cells (hiPSCs) from a 3-year-old male BRMUTD patient using Sendai virus-based non-integrating reprogramming technology. This patient-derived cell line harbors an intragenic deletion within the NFIA gene (NC_000001.10: g.61650967_61842967del [GRCh37]), which is associated with a significant reduction in NFIA expression. This cell line maintains a normal karyotype, expresses pluripotency markers, and can differentiate into three germ layers. The established hiPSCs line will provide an in vitro model for studying pathological mechanisms and potential therapies of NFIA-related neurodevelopmental disorder.

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来源期刊
Human Cell
Human Cell CELL BIOLOGY-
CiteScore
5.90
自引率
2.30%
发文量
176
审稿时长
4.5 months
期刊介绍: Human Cell is the official English-language journal of the Japan Human Cell Society. The journal serves as a forum for international research on all aspects of the human cell, encompassing not only cell biology but also pathology, cytology, and oncology, including clinical oncology. Embryonic stem cells derived from animals, regenerative medicine using animal cells, and experimental animal models with implications for human diseases are covered as well. Submissions in any of the following categories will be considered: Research Articles, Cell Lines, Rapid Communications, Reviews, and Letters to the Editor. A brief clinical case report focusing on cellular responses to pathological insults in human studies may also be submitted as a Letter to the Editor in a concise and short format. Not only basic scientists but also gynecologists, oncologists, and other clinical scientists are welcome to submit work expressing new ideas or research using human cells.
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