单细胞转录组学揭示了galt基因编辑诱导小鼠肺损伤的机制

IF 2.5 3区 生物学 Q3 BIOCHEMISTRY & MOLECULAR BIOLOGY
Zhihao Li , Ning Wang , Haobo Wang , Lingling Yang , Yong Li , Lantao Gu , Can Fu , Pengpeng Yue , Honghao Yu
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引用次数: 0

摘要

半乳糖血症是由GALT基因突变引起的,可导致多器官损伤。本研究探讨了Galt c.847 + 1G >;利用单细胞转录组学研究肺组织中的T突变。我们利用CRISPR/Cas9技术生成Galt基因编辑的小鼠模型,其中Galt c. 847 + 1G >;T突变,并通过PCR和Western blotting检测Galt表达。组织病理学分析显示明显的肺结构改变,包括肺泡充血和炎症。单细胞RNA测序显示,GAL小鼠的免疫细胞(NK细胞、T细胞、巨噬细胞、B细胞)明显减少,肺泡II型细胞、血管内皮细胞和肌成纤维细胞增加。肺泡II型细胞丰度的增加表明分化和修复受损。代谢分析显示Galt c.847 + 1G >显著异常;T突变,TGF-β1、FGF和Mif通路中断,导致细胞功能障碍,加重肺损伤。该模型揭示了半乳糖血症肺损伤的分子机制,强调了肺细胞群和关键信号通路的显著改变。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Single-cell transcriptomics reveals the mechanisms of lung injury induced by galt gene editing in mouse
Galactosemia, caused by mutations in the GALT gene, leads to multi-organ damage. This study investigates the impact of Galt c.847 + 1G > T mutation on lung tissue using single-cell transcriptomics. We employed CRISPR/Cas9 to generate a Galt gene-edited mouse model with the Galt c. 847 + 1G > T mutation and assessed Galt expression through PCR and Western blotting. Histopathological analysis revealed significant structural lung changes, including alveolar congestion and inflammation. Single-cell RNA sequencing demonstrated a marked reduction in immune cells (NK, T, macrophages, B cells) and an increase in alveolar type II cells, vascular endothelial cells, and myofibroblasts in the GAL mouse. The increased abundance of alveolar type II cells indicated impaired differentiation and repair. Metabolic analysis revealed significant abnormalities linked to Galt c.847 + 1G > T mutation, with disruptions in TGF-β1, FGF, and Mif pathways contributing to cellular dysfunction and exacerbated lung injury. This model provides insights into the molecular mechanisms of lung injury in galactosemia, highlighting significant alterations in lung cell populations and key signaling pathways.
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来源期刊
Biochemical and biophysical research communications
Biochemical and biophysical research communications 生物-生化与分子生物学
CiteScore
6.10
自引率
0.00%
发文量
1400
审稿时长
14 days
期刊介绍: Biochemical and Biophysical Research Communications is the premier international journal devoted to the very rapid dissemination of timely and significant experimental results in diverse fields of biological research. The development of the "Breakthroughs and Views" section brings the minireview format to the journal, and issues often contain collections of special interest manuscripts. BBRC is published weekly (52 issues/year).Research Areas now include: Biochemistry; biophysics; cell biology; developmental biology; immunology ; molecular biology; neurobiology; plant biology and proteomics
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