10个月婴儿斯特奇-韦伯综合征的非典型影像学特征:1例报告

Biruk T. Mengistie , Chernet T. Mengistie , Michael A. Negussie , Solyana Bereded , Eden H. Hagos , Abebe M. Woldeyohannes
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引用次数: 0

摘要

斯特奇-韦伯综合征(SWS)是一种罕见的非遗传性神经皮肤疾病,以面部毛细血管畸形、脑膜血管瘤病和青光眼等眼部异常为特征。虽然其标志性的影像学发现是有据可查的,但非典型的表现,特别是在婴儿期早期,仍然被低估。本病例报告描述了一个10个月大的男婴罕见和严重的SWS表现。患者表现出标志性特征,包括葡萄酒色斑、青光眼和脑膜轻脑膜增强,以及非典型影像学表现,如弥漫性双侧脑萎缩、不对称颅底血管瘤病、双侧脉络膜丛扩大和髓周静脉弯曲。神经系统症状包括第一年开始的反复强直-阵挛性发作,以及持续的眼科并发症。先进的影像学在识别这些不寻常的特征方面发挥了关键作用,强调了SWS表现的可变性,以及对年轻患者进行全面神经影像学检查的必要性。本报告强调了早期诊断、多学科管理和警惕随访的重要性,以应对SWS带来的各种挑战,同时扩大其记录的表现范围。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Atypical imaging features of sturge-weber syndrome in a 10-month-old infant: A case report
Sturge-Weber Syndrome (SWS) is a rare, non-inherited neurocutaneous disorder characterized by facial capillary malformations, leptomeningeal angiomatosis, and ocular abnormalities such as glaucoma. While its hallmark imaging findings are well-documented, atypical presentations, especially in early infancy, remain underreported. This case report describes a 10-month-old male infant with a rare and severe presentation of SWS. The patient exhibited hallmark features, including a port-wine stain, glaucoma, and leptomeningeal enhancement, alongside atypical imaging findings such as diffuse bilateral cerebral atrophy, asymmetric pial angiomatosis, bilateral choroid plexus enlargement, and tortuous perimedullary veins. Neurological symptoms included recurrent tonic-clonic seizures starting within the first year of life, alongside persistent ophthalmologic complications. Advanced imaging played a pivotal role in identifying these unusual features, underscoring the variability in SWS presentations and the need for comprehensive neuroimaging in young patients. This report highlights the importance of early diagnosis, multidisciplinary management, and vigilant follow-up to address the diverse challenges posed by SWS, while expanding the documented spectrum of its manifestations.
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来源期刊
Global pediatrics
Global pediatrics Perinatology, Pediatrics and Child Health
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