伊朗西北部416例家族性地中海热患者中最常见MEFV变异的筛查

IF 1.4 Q3 Pharmacology, Toxicology and Pharmaceutics
Armin Gharibi, Esmaeil Babaei, Ali Vahabi
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引用次数: 0

摘要

家族性地中海热(FMF)是一种常染色体隐性遗传的遗传病。FMF在地中海地区的少数民族人群中最为普遍,由地中海热(MEFV)基因的致病性突变引起。本研究采用的材料和方法,对来自伊朗西北地区的416名患者进行了MEFV基因18种常见变异的筛查。筛选过程包括使用多重扩增-连接聚合酶链反应与荧光标记的DNA探针相结合。该技术能够检测单核苷酸多态性,即MEFV基因序列中单个核苷酸碱基的变异。63.46%的病例最初症状表现在1 - 20岁之间。患者最常见的4种临床表现为腹痛、发热、关节痛和呕吐。对416例FMF患者18种流行MEFV变异的分子分析揭示了242例患者的潜在遗传原因。242例病例中,单一致病变异杂合携带者129例(53.3%),单一致病变异纯合携带者19例(7.8%),两种不同致病变异复合杂合携带者48例(19.83%),多致病变异46例(19%),属于复杂病例。4个基因型组中,R202Q变异最为普遍,等位基因频率最高(39.94%),其次是E148Q(20.62%)、M694V(15.14%)和V726A(15.14%)。MEFV变异的遗传分析显示,R202Q占优势,E148Q、M694V和V726A的出现频率由高到低。除土耳其人外,R202Q变异的等位基因频率与其他种族相比具有统计学上的显著差异。有趣的是,虽然M694V变异在其他几个人群和种族群体中最为普遍,但在我们的研究队列中,它是第三个最常见的变异。这一发现表明,特定等位基因的频率在不同的国家、人群和种族群体中可能存在很大差异。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Screening of the most common MEFV variants in 416 patients of familial mediterranean fever living in Northwest of Iran.

Familial Mediterranean Fever (FMF) is an inherited disorder with an autosomal recessive pattern of inheritance. FMF is the most prevalent among ethnic populations originating from the Mediterranean region and results from pathogenic mutations in the Mediterranean fever (MEFV) gene. For the materials and methods employed in this study, a total of 416 patients from the northwestern region of Iran were screened for the presence of 18 commonly occurring variants in the MEFV gene. The screening process involved the use of multiplex amplification-ligation polymerase chain reaction coupled with fluorescently labeled DNA probes. This technique enabled the detection of single nucleotide polymorphisms, which are variations in a single nucleotide base within the MEFV gene sequence. The initial manifestation of symptoms occurred between the ages of 1 and 20 years in 63.46% of the cases studied. The four most commonly observed clinical manifestations among the patients were abdominal pain, fever, joint pain, and vomiting. Molecular analysis of 18 prevalent MEFV variants in 416 FMF patients revealed the underlying genetic causes in 242 individuals. Out of these 242 cases, 129 patients (53.3%) were heterozygous carriers of a single pathogenic variant, 19 patients (7.8%) were homozygous for a single variant, 48 patients (19.83%) were compound heterozygotes harboring two different pathogenic variants, and 46 patients (19%) exhibited multiple variants, which were classified as complex cases. The R202Q variation emerged as the most prevalent among the four genotypic groups and exhibited the highest allele frequency (39.94%), followed by E148Q (20.62%), M694V (15.14%), and V726A (15.14%). Genetic profiling of MEFV variations revealed a predominance of R202Q, with E148Q, M694V, and V726A occurring in descending order of frequency. The allele frequency of the R202Q variant exhibited a statistically significant difference when compared to other ethnic groups, with the exception of the Turkish population. Interestingly, while the M694V variant is reported as the most prevalent in several other populations and ethnic groups, in our study cohort, it emerged as the third most common variant. This finding suggests that the frequencies of specific alleles can vary substantially across different countries, populations, and ethnic groups.

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来源期刊
CiteScore
2.00
自引率
7.10%
发文量
44
审稿时长
20 weeks
期刊介绍: Journal of Advanced Pharmaceutical Technology & Research (JAPTR) is an Official Publication of Society of Pharmaceutical Education & Research™. It is an international journal published Quarterly. Journal of Advanced Pharmaceutical Technology & Research (JAPTR) is available in online and print version. It is a peer reviewed journal aiming to communicate high quality original research work, reviews, short communications, case report, Ethics Forum, Education Forum and Letter to editor that contribute significantly to further the scientific knowledge related to the field of Pharmacy i.e. Pharmaceutics, Pharmacology, Pharmacognosy, Pharmaceutical Chemistry. Articles with timely interest and newer research concepts will be given more preference.
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