RUNX1的生殖系拷贝数变异:一份最新的病例报告和十年来的转移注意力。

Natalie T Deuitch, Amra Kajdic, Erica Bresciani, Marshall S Horwitz, Hamish S Scott, Katie Craft, Shawn Chong, David J Young, Lucy A Godley, Paul P Liu
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引用次数: 0

摘要

RUNX1的致病性/可能致病性(P/LP)种系变异导致家族性血小板疾病伴髓系恶性肿瘤(FPDMM),也称为RUNX1-家族性血小板疾病(RUNX1-FPD,或FPD),一种以定性和定量血小板缺陷和造血恶性肿瘤易感性为特征的疾病。在这里,我们提出了一个病例的随访女性急性髓性白血病和终身血小板减少症,这是以前归因于推定致病性(P) GATA2错义变异体。然而,利用更新的分子技术对拷贝数变异(CNVs)的检测进行重新评估,发现RUNX1外显子5-6的P缺失,这在第一次检测时是未被检测到的。这个案例强调了全面的分子评估和仔细的变异解释的重要性,特别是对于CNVs。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Germline copy number variants in RUNX1: An updated case report and a decade-old red herring.

Pathogenic/likely pathogenic (P/LP) germline variants in RUNX1 cause familial platelet disorder with associated myeloid malignancies (FPDMM), also known as RUNX1-Familial Platelet Disorder (RUNX1-FPD, or FPD), a condition characterized by qualitative and quantitative platelet defects and predisposition to hematopoietic malignancies. Here, we present follow up to a case of a woman with acute myeloid leukemia and lifelong thrombocytopenia which had previously been attributed to presumptive pathogenic (P) GATA2 missense variants. However, re-evaluation with updated molecular technology sensitive for detection of copy number variants (CNVs) led to the identification of a P deletion of exons 5-6 in RUNX1, which had been undetected when examined at first presentation. This case highlights the importance of comprehensive molecular evaluation and careful variant interpretation, especially regarding CNVs.

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