儿童努南综合征患者的心脏移植结果:一个机构病例系列。

IF 1.5 4区 医学 Q3 CARDIAC & CARDIOVASCULAR SYSTEMS
Joseph Andreola, Svetlana Shugh, Robert Winchester, Fredrick Fricker, Maryanne Chrisant, Laura D'Addese
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引用次数: 0

摘要

努南综合征是一种常染色体显性遗传病,与心脏表现相关,可能需要心脏移植。本病例系列描述了5例心脏移植后努南综合征患者的短期和中期预后。回顾性、单中心图表回顾诊断为努南综合征的心脏移植后患者电子病历。在我们医院接受心脏移植手术的88名患者中,有5人在基因上证实患有Noonan综合征,其中RAF1或PTPN11突变。所有患者均有肥厚性心肌病。严重的流出道梗阻,并伴有顽固性心律失常、复发性晕厥和生长不良等合并症,是心脏移植的主要适应症。心脏移植术后最常见的并发症包括复发性病毒感染、胸膜和心包积液。孤立的并发症包括淋巴管扩张、后部可逆性脑病综合征和曲霉菌性肺炎。进食困难很常见。在本文发表时,所有患者都还活着。努南综合征与肥厚性心肌病高度相关,严重者可能需要心脏移植。在我们的队列中看到的心脏移植后并发症并不是努南综合征人群所独有的。心脏移植后的存活率很高。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Heart Transplantation Outcomes in Pediatric Patients with Noonan Syndrome: An Institutional Case Series.

Noonan syndrome is an autosomal dominant genetic condition associated with cardiac manifestations that may necessitate heart transplantation. This case series describes the short- and medium-term outcomes in five patients with Noonan syndrome status-post heart transplant followed at our institution. Retrospective, single center chart review of the electronic medical record in post-heart transplant patients with a diagnosis of Noonan syndrome. Five out of 88 heart transplant patients at our institution had genetically confirmed Noonan syndrome with either RAF1 or PTPN11 mutations. All patients were noted to have hypertrophic cardiomyopathy. Severe outflow tract obstruction, in conjunction with comorbidities such as intractable arrhythmias, recurrent syncope, and failure to thrive were leading indications for heart transplant. The most common complications post-heart transplant included recurrent viral infections and pleural and pericardial effusions. Isolated complications included lymphangiectasias, posterior reversible encephalopathy syndrome, and aspergillus pneumonia. Feeding difficulties were common. All patients are alive at the time of this publication. Noonan syndrome is highly associated with hypertrophic cardiomyopathy, and severe cases may necessitate heart transplantation. The post-heart transplant complications seen in our cohort are not unique to the Noonan syndrome population. Survival post-heart transplant is high.

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来源期刊
Pediatric Cardiology
Pediatric Cardiology 医学-小儿科
CiteScore
3.30
自引率
6.20%
发文量
258
审稿时长
12 months
期刊介绍: The editor of Pediatric Cardiology welcomes original manuscripts concerning all aspects of heart disease in infants, children, and adolescents, including embryology and anatomy, physiology and pharmacology, biochemistry, pathology, genetics, radiology, clinical aspects, investigative cardiology, electrophysiology and echocardiography, and cardiac surgery. Articles which may include original articles, review articles, letters to the editor etc., must be written in English and must be submitted solely to Pediatric Cardiology.
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