Ameer Awashra , Zaid Sawaftah , Salsabeel Bishawi , Aseel Eid , Aya Milhem , Dawoud Hamdan , Ali Bani Odah , Ahmad Sawafta , Jehad Khamaysa , Yazan Ghannam , Hadi Rabee
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Imaging and further diagnostic evaluation confirmed BCS as the initial manifestation of BD, a rare but severe complication. Genetic testing revealed a heterozygous mutation for Factor V Leiden and the presence of the HLA-B51 allele, highlighting a thrombogenic synergy between BD and inherited thrombophilia. Aggressive anticoagulation therapy was initiated, resulting in partial recanalization of the hepatic veins and stabilization of the patient's condition. This case emphasizes the need for early consideration of BCS in BD patients, especially in those with concurrent prothrombotic disorders, as timely intervention is crucial for improving clinical outcomes. The interplay of autoimmune and genetic factors in this case provides valuable insights into the complex pathophysiology and management of BCS associated with BD.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":"20 2","pages":"Pages 1257-1262"},"PeriodicalIF":0.0000,"publicationDate":"2025-02-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC11665683/pdf/","citationCount":"0","resultStr":"{\"title\":\"Behçet's disease and factor V Leiden: A thrombogenic synergy causing budd-chiari syndrome\",\"authors\":\"Ameer Awashra , Zaid Sawaftah , Salsabeel Bishawi , Aseel Eid , Aya Milhem , Dawoud Hamdan , Ali Bani Odah , Ahmad Sawafta , Jehad Khamaysa , Yazan Ghannam , Hadi Rabee\",\"doi\":\"10.1016/j.radcr.2024.11.041\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<div><div>Behçet's Disease (BD) is a multisystem inflammatory disorder that can lead to severe vascular complications, including Budd-Chiari Syndrome (BCS), a rare but life-threatening condition characterized by hepatic vein obstruction. 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引用次数: 0
摘要
behet病(BD)是一种多系统炎症性疾病,可导致严重的血管并发症,包括Budd-Chiari综合征(BCS),这是一种罕见但危及生命的疾病,其特征是肝静脉阻塞。双相障碍与遗传性血栓性疾病(如Factor V Leiden突变)的共同发生,显著增加了血栓形成的风险,使患者的临床管理复杂化。在这个病例中,一名16岁的女性最初表现为全身疲劳和骨痛等非特异性症状,后来发展为腹胀和明显的肝脾肿大。影像学和进一步的诊断评估证实BCS为双相障碍的初始表现,是一种罕见但严重的并发症。基因检测显示了因子V Leiden的杂合突变和HLA-B51等位基因的存在,突出了BD和遗传性血栓形成之间的血栓形成协同作用。开始积极的抗凝治疗,导致肝静脉部分再通,患者病情稳定。该病例强调了早期考虑BD患者BCS的必要性,特别是合并血栓形成前疾病的患者,因为及时干预对改善临床结果至关重要。本病例中自身免疫和遗传因素的相互作用为BCS合并BD的复杂病理生理和治疗提供了有价值的见解。
Behçet's disease and factor V Leiden: A thrombogenic synergy causing budd-chiari syndrome
Behçet's Disease (BD) is a multisystem inflammatory disorder that can lead to severe vascular complications, including Budd-Chiari Syndrome (BCS), a rare but life-threatening condition characterized by hepatic vein obstruction. The co-occurrence of BD and inherited thrombophilia, such as Factor V Leiden mutation, significantly increases the risk of thrombosis, complicating the clinical management of affected individuals. In this case, a 16-year-old female initially presented with nonspecific symptoms of generalized fatigue and bone pain, which later progressed to abdominal distension and significant hepatosplenomegaly. Imaging and further diagnostic evaluation confirmed BCS as the initial manifestation of BD, a rare but severe complication. Genetic testing revealed a heterozygous mutation for Factor V Leiden and the presence of the HLA-B51 allele, highlighting a thrombogenic synergy between BD and inherited thrombophilia. Aggressive anticoagulation therapy was initiated, resulting in partial recanalization of the hepatic veins and stabilization of the patient's condition. This case emphasizes the need for early consideration of BCS in BD patients, especially in those with concurrent prothrombotic disorders, as timely intervention is crucial for improving clinical outcomes. The interplay of autoimmune and genetic factors in this case provides valuable insights into the complex pathophysiology and management of BCS associated with BD.
期刊介绍:
The content of this journal is exclusively case reports that feature diagnostic imaging. Categories in which case reports can be placed include the musculoskeletal system, spine, central nervous system, head and neck, cardiovascular, chest, gastrointestinal, genitourinary, multisystem, pediatric, emergency, women''s imaging, oncologic, normal variants, medical devices, foreign bodies, interventional radiology, nuclear medicine, molecular imaging, ultrasonography, imaging artifacts, forensic, anthropological, and medical-legal. Articles must be well-documented and include a review of the appropriate literature.