早发散发性与早老素-1突变相关的阿尔茨海默病痴呆的合并症:阿尔茨海默病神经病理改变依赖性的证据

IF 3.2 3区 医学 Q2 CLINICAL NEUROLOGY
Diego Sepulveda-Falla, Carlos Andrés Villegas Lanau, Charles White Iii, Geidy E Serrano, Juliana Acosta-Uribe, Barbara Mejía-Cupajita, Nelson David Villalba-Moreno, Pinzhang Lu, Markus Glatzel, Julia K Kofler, Bernardino Ghetti, Matthew P Frosch, Francisco Lopera Restrepo, Kenneth S Kosik, Thomas G Beach
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引用次数: 0

摘要

研究早发性阿尔茨海默病(AD)的合并症可能为其发病机制提供有利的视角,因为衰老因素可能在很大程度上对这些受试者不起作用。我们比较了早发散发性病例与PSEN1突变的美国和哥伦比亚病例的AD合并症。AD神经病理改变(ADNC)在所有组中都非常严重,但PSEN1组更严重。路易体病和脑白质稀薄是AD合并症中最常见的(高达60%),其次是小动脉硬化(高达37%)和大血管动脉粥样硬化(高达20%)。三组之间的差异包括美国PSEN1病例发病年龄较早,散发病例病程较短,哥伦比亚PSEN1病例大血管动脉粥样硬化和脑淀粉样血管病更常见。经年龄和性别调整后的Logistic回归模型发现,PSEN1突变、载脂蛋白ε4等位基因和TDP-43病理的存在预示着发病年龄的提前;西班牙裔和多种族受试者可预测严重CAA。合并症在早发性AD中很常见,在计划此类受试者的临床试验时应予以考虑。然而,它们可能至少部分依赖于ADNC,因此可能通过抗淀粉样蛋白或和/或抗tau治疗来解决。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Comorbidities in early-onset sporadic versus presenilin-1 mutation-associated Alzheimer disease dementia: Evidence for dependency on Alzheimer disease neuropathological changes.

Studying comorbidities in early onset Alzheimer disease (AD) may provide an advantageous perspective on their pathogenesis because aging factors may be largely inoperative for these subjects. We compared AD comorbidities between early-onset sporadic cases and American and Colombian cases with PSEN1 mutations. AD neuropathological changes (ADNC) were very severe in all groups but more severe in the PSEN1 groups. Lewy body disease and cerebral white matter rarefaction were the most common (up to 60%) of AD comorbidities, followed by arteriolosclerosis (up to 37%), and large-vessel atherosclerosis (up to 20%). Differences between the 3 groups included earlier age of onset in the American PSEN1 cases, shorter disease duration in sporadic cases, and more frequent large-vessel atherosclerosis and cerebral amyloid angiopathy in the Colombian PSEN1 cases. Logistic regression models adjusted for age and sex found the presence of a PSEN1 mutation, an apolipoprotein ε4 allele and TDP-43 pathology to predict an earlier age of onset; Hispanic ethnicity and multiracial subjects were predictive of severe CAA. Comorbidities are common in early onset AD and should be considered when planning clinical trials with such subjects. However, they may be at least partially dependent on ADNC and thus potentially addressable by anti-amyloid or and/anti-tau therapies.

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来源期刊
CiteScore
5.40
自引率
6.20%
发文量
118
审稿时长
6-12 weeks
期刊介绍: Journal of Neuropathology & Experimental Neurology is the official journal of the American Association of Neuropathologists, Inc. (AANP). The journal publishes peer-reviewed studies on neuropathology and experimental neuroscience, book reviews, letters, and Association news, covering a broad spectrum of fields in basic neuroscience with an emphasis on human neurological diseases. It is written by and for neuropathologists, neurologists, neurosurgeons, pathologists, psychiatrists, and basic neuroscientists from around the world. Publication has been continuous since 1942.
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