妊娠中期以胎儿巨囊炎为表现的ACTG2内脏肌病的产前诊断。

IF 2.7 2区 医学 Q2 GENETICS & HEREDITY
Prenatal Diagnosis Pub Date : 2025-01-01 Epub Date: 2024-12-09 DOI:10.1002/pd.6726
Qiu-Xia Yu, Na Liu, Li Zhen, Yun-Jing Wen, Dong-Zhi Li
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引用次数: 0

摘要

ACTG2基因的变异导致常染色体显性ACTG2内脏肌病,这是一种膀胱和胃肠道系统平滑肌功能障碍的疾病。膀胱受累可表现为胎儿巨囊炎(FM)。我们报告四例产前ACTG2内脏肌病。所有4例均在妊娠中期超声诊断为FM。所有人在怀孕期间都进行了侵入性遗传调查,三人外显子组测序显示胎儿中可能存在致病性或致病性ACTG2变异。四种变异中有三种是从头开始的,一种是从母亲那里遗传的,母亲从小就有平滑肌功能障碍的症状。ACTG2内脏肌病是孤立性孕中期巨囊炎胎儿最关注的问题。与FM相关的单基因疾病的遗传诊断在父母咨询、妊娠管理和未来妊娠复发风险评估中是有用的。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Prenatal Diagnosis of ACTG2 Visceral Myopathy Presented With Fetal Megacystis Identified in the Second Trimester.

Variants of the ACTG2 gene cause autosomal dominant ACTG2 visceral myopathy, a disorder of smooth muscle dysfunction of the bladder and gastrointestinal system. Bladder involvement can behave as fetal megacystis (FM). We report four prenatal cases of ACTG2 visceral myopathy. All four cases presented with FM identified by ultrasound in the second trimester. All had invasive genetic investigations during pregnancy, and trio exome sequencing revealed likely pathogenic or pathogenic ACTG2 variants in the fetuses. Three of the four variants were de novo, and one was inherited form mother who had symptoms of smooth muscle dysfunction since childhood. ACTG2 visceral myopathy is the most concern in fetuses with isolated second-trimester megacystis. Genetic diagnosis of single gene disorders associated with FM is useful in parental counseling, pregnancy management and risk assessment of recurrence in future pregnancy.

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来源期刊
Prenatal Diagnosis
Prenatal Diagnosis 医学-妇产科学
CiteScore
5.80
自引率
13.30%
发文量
204
审稿时长
2 months
期刊介绍: Prenatal Diagnosis welcomes submissions in all aspects of prenatal diagnosis with a particular focus on areas in which molecular biology and genetics interface with prenatal care and therapy, encompassing: all aspects of fetal imaging, including sonography and magnetic resonance imaging; prenatal cytogenetics, including molecular studies and array CGH; prenatal screening studies; fetal cells and cell-free nucleic acids in maternal blood and other fluids; preimplantation genetic diagnosis (PGD); prenatal diagnosis of single gene disorders, including metabolic disorders; fetal therapy; fetal and placental development and pathology; development and evaluation of laboratory services for prenatal diagnosis; psychosocial, legal, ethical and economic aspects of prenatal diagnosis; prenatal genetic counseling
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