远程医疗在未确诊罕见疾病个体评估中是有效的:一项未确诊疾病网络研究。

IF 1.7 4区 生物学 Q3 GENETICS & HEREDITY
Queenie K-G Tan, Allyn McConkie-Rosell, Rachel Mahoney, Rebecca C Spillmann, Kelly Schoch, Sirisak Chanprasert, Maria T Acosta, Camilo Toro, Jill A Rosenfeld, James P Orengo, Daryl A Scott, Jorge L Granadillo, Kathleen Sisco, Daniel J Wegner, Mustafa Tekin, Stephanie Bivona, LéShon Peart, Lance Rodan, Devon Bonner, Matthew T Wheeler, Jonathan A Bernstein, Maura Ruzhnikov, David R Adams, Fuki M Hisama, Vandana Shashi
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引用次数: 0

摘要

未确诊和/或罕见疾病的患者经常表现为畸形和神经系统特征。缺乏关于远程保健在评估这些疾病方面的有效性的信息。因此,我们比较了未确诊个体的无辅助虚拟体检(PE)和面对面体检,并评估了参与者的远程医疗满意度。26名参加未确诊疾病网络研究的个体接受了由同一名临床医生进行的家庭同步虚拟PE和随后的面对面PE。参与者完成了关于远程医疗可用性和提供者移情的调查。在PE方面,远程医疗和现场评估的总体外观和颅面特征几乎完全一致(κ = 0.81-1.00)。神经学检查的具体组成部分显示了实质性的一致(言语、步态、协调;κ > 0.61),而其他人则有中等程度的一致性(肌张力、力量;κ = 0.41-0.60),少数没有或轻微一致(皮肤;κ
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Telehealth Is Effective in the Evaluation of Individuals With Undiagnosed Rare Disorders: An Undiagnosed Diseases Network Study.

Patients with undiagnosed and/or rare disorders frequently manifest dysmorphic and neurological features. There is a lack of information on the effectiveness of telehealth in the evaluation of these disorders. We thus compared an unassisted virtual physical examination (PE) with an in-person PE in undiagnosed individuals and also assessed participant telehealth satisfaction. Twenty-six individuals enrolled in the Undiagnosed Diseases Network study underwent an in-home synchronous virtual PE, and a subsequent in-person PE, by the same clinician. The participants completed surveys on telehealth usability and provider empathy. On PE, general appearance and craniofacial features showed near perfect agreement (κ = 0.81-1.00) between the telehealth and in-person evaluations. Specific components of the neurological examination demonstrated substantial agreement (speech, gait, coordination; κ > 0.61), whereas others had moderate agreement (muscle tone, strength; κ = 0.41-0.60), and a few had none to slight agreement (skin; κ < 0.20). Some systems could not be examined in the virtual PE. Importantly, features relevant to diagnosis or management were missed on the virtual PE in only 2/26 individuals. The participants were satisfied with the quality of the telehealth interaction, as well as empathy demonstrated by providers in the virtual interface. Telehealth is effective for PEs in undiagnosed diseases and is acceptable to affected individuals.

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来源期刊
CiteScore
3.50
自引率
5.00%
发文量
432
审稿时长
2-4 weeks
期刊介绍: The American Journal of Medical Genetics - Part A (AJMG) gives you continuous coverage of all biological and medical aspects of genetic disorders and birth defects, as well as in-depth documentation of phenotype analysis within the current context of genotype/phenotype correlations. In addition to Part A , AJMG also publishes two other parts: Part B: Neuropsychiatric Genetics , covering experimental and clinical investigations of the genetic mechanisms underlying neurologic and psychiatric disorders. Part C: Seminars in Medical Genetics , guest-edited collections of thematic reviews of topical interest to the readership of AJMG .
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